Literature DB >> 27014968

Features of 847 Childhood-Onset Systemic Lupus Erythematosus Patients in Three Age Groups at Diagnosis: A Brazilian Multicenter Study.

Roberta C Gomes1, Marco F Silva1, Katia Kozu1, Eloisa Bonfá1, Rosa M Pereira1, Maria T Terreri2, Claudia S Magalhães3, Silvana B Sacchetti4, Roberto Marini5, Melissa Fraga2, Luciana M Carvalho6, Cássia M Barbosa7, Magda Carneiro-Sampaio1, Clovis A Silva8.   

Abstract

OBJECTIVE: To evaluate demographic data and clinical and laboratory features at disease diagnosis in 3 different age groups of childhood-onset systemic lupus erythematosus (SLE): group A, early-onset (<6 years); group B, school age (≥6 to <12 years); and group C, adolescent (≥12 to <18 years).
METHODS: This was a Brazilian multicenter cohort retrospective study in 10 pediatric rheumatology centers, including 847 childhood-onset SLE patients.
RESULTS: Patients were divided into 3 groups: group A with 39 patients (4%), group B with 395 patients (47%), and group C with 413 patients (49%). Of 39 childhood-onset SLE patients in group A, 3 (8%) were ages <2 years, 4 (10%) were ≥2 to <3 years, and 32 (82%) were ≥3 and <6 years. A total of 74 childhood-onset SLE patients were analyzed for C1q levels, and complete C1q deficiency was observed in 3 of 74 patients (4%), all in group A. Groups were similar regarding high frequencies of female sex, nephritis, neuropsychiatric involvement, Systemic Lupus Erythematosus Disease Activity Index 2000 score ≥8, autoantibody profile, elevated acute phase proteins, and low complement levels (P > 0.05). However, the frequency of fever (78% versus 61% versus 47%; P < 0.0001), hepatomegaly (42% versus 29% versus 14%; P < 0.0001), splenomegaly (28% versus 12% versus 4%; P < 0.0001), and discoid lupus (13% versus 4% versus 4%; P = 0.020) was significantly higher in group A compared to groups B and C. The frequency of weight loss >2 kg (19% versus 28% versus 36%; P = 0.017), photosensitivity (34% versus 41% versus 51%; P = 0.006), leukopenia <4,000/mm3 (14% versus 25% versus 30%; P = 0.048), and lymphopenia <1,500/mm3 (22% versus 41% versus 47%; P = 0.011) was significantly lower in group A.
CONCLUSION: Our large multicenter study identified the finding that the initial appearance of childhood-onset SLE is characterized by comparable high frequency of internal organ involvement and some distinct clinical and laboratory features in early-onset and adolescent groups.
© 2016, American College of Rheumatology.

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Year:  2016        PMID: 27014968     DOI: 10.1002/acr.22881

Source DB:  PubMed          Journal:  Arthritis Care Res (Hoboken)        ISSN: 2151-464X            Impact factor:   4.794


  14 in total

1.  Uveitis in childhood-onset systemic lupus erythematosus patients: a multicenter survey.

Authors:  Paola Pinheiro Kahwage; Mariana Paes Leme Ferriani; João M Furtado; Luciana Martins de Carvalho; Gecilmara Salviato Pileggi; Francisco Hugo Rodrigues Gomes; Maria Teresa Terreri; Claudia Saad Magalhães; Rosa Maria Rodrigues Pereira; Silvana Brasilia Sacchetti; Roberto Marini; Eloisa Bonfá; Clovis Artur Silva; Virgínia Paes Leme Ferriani
Journal:  Clin Rheumatol       Date:  2017-01-09       Impact factor: 2.980

2.  Epidemiology and management practices for childhood-onset systemic lupus erythematosus patients: a survey in Latin America.

Authors:  Juliana C O A Ferreira; Vitor C Trindade; Graciela Espada; Zoilo Morel; Eloisa Bonfá; Claudia S Magalhães; Clovis Artur Silva
Journal:  Clin Rheumatol       Date:  2018-08-09       Impact factor: 2.980

3.  Paediatric rheumatic disease: Phenotype and prognosis of juvenile systemic lupus erythematosus.

Authors:  Rolando Cimaz
Journal:  Nat Rev Rheumatol       Date:  2016-06-16       Impact factor: 20.543

4.  Disease presentation of 1312 childhood-onset systemic lupus erythematosus: influence of ethnicity.

Authors:  Fernanda J Fiorot; Aline G Islabão; Rosa M Pereira; Maria T Terreri; Claudia Saad-Magalhães; Glaucia V Novak; Beatriz C Molinari; Ana P Sakamoto; Nadia E Aikawa; Lucia M Campos; Octavio A Peracchi; Simone Appenzeller; Virgínia P Ferriani; Marco F Silva; Adriana R Fonseca; Flávio R Sztajnbok; Luciana B Paim; Melissa M Fraga; Eunice M Okuda; Blanca E Bica; Evaldo G Sena; Ana J Moraes; Ana M Rolim; Paulo F Spelling; Iloite M Scheibel; André S Cavalcanti; Erica N Matos; Teresa C Robazzi; Luciano J Guimarães; Flávia P Santos; Valeria C Ramos; Magda Carneiro-Sampaio; Eloisa Bonfá; Clovis A Silva
Journal:  Clin Rheumatol       Date:  2019-06-13       Impact factor: 2.980

Review 5.  The complement system as a potential therapeutic target in rheumatic disease.

Authors:  Leendert A Trouw; Matthew C Pickering; Anna M Blom
Journal:  Nat Rev Rheumatol       Date:  2017-08-10       Impact factor: 20.543

6.  Clinical and laboratory features of African-Brazilian patients with systemic sclerosis.

Authors:  Cristiane Mendes; Vilma S T Viana; Sandra G Pasoto; Elaine P Leon; Eloisa Bonfa; Percival D Sampaio-Barros
Journal:  Clin Rheumatol       Date:  2019-05-07       Impact factor: 2.980

7.  Characterization of chronic arthritis in a multicenter study of 852 childhood-onset systemic lupus erythematosus patients.

Authors:  Ana Paula Sakamoto; Clovis Artur Silva; Mariana Paes Leme Ferriani; Rosa Maria Rodrigues Pereira; Eloisa Bonfá; Claudia Saad-Magalhães; Eunice Okuda; Simone Appenzeller; Francisco Hugo Gomes; Ana Luiza Garcia Cunha; Mirna Henriques Tomich Salume; Daniela Petry Piotto; Maria Teresa Terreri
Journal:  Rheumatol Int       Date:  2016-09-14       Impact factor: 2.631

Review 8.  Monogenic systemic lupus erythematosus: insights in pathophysiology.

Authors:  Ezgi Deniz Batu
Journal:  Rheumatol Int       Date:  2018-05-15       Impact factor: 2.631

Review 9.  Splenomegaly in Children and Adolescents.

Authors:  Meinolf Suttorp; Carl Friedrich Classen
Journal:  Front Pediatr       Date:  2021-07-09       Impact factor: 3.418

10.  An Update on the Management of Childhood-Onset Systemic Lupus Erythematosus.

Authors:  Vitor Cavalcanti Trindade; Magda Carneiro-Sampaio; Eloisa Bonfa; Clovis Artur Silva
Journal:  Paediatr Drugs       Date:  2021-07-10       Impact factor: 3.022

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