| Literature DB >> 26995359 |
Judith Altmann1,2, Boriana Büchner3, Aleksandra Nadaj-Pakleza4, Jochen Schäfer5, Sandra Jackson5, Diana Lehmann6, Marcus Deschauer6,7, Robert Kopajtich8,9, Ronald Lautenschläger10, Klaus A Kuhn10, Kathrin Karle11, Ludger Schöls11, Jörg B Schulz1,12, Joachim Weis2, Holger Prokisch8,9, Cornelia Kornblum13,14, Kristl G Claeys15,16,17, Thomas Klopstock3,18,19.
Abstract
The m.8344A>G mutation in the MTTK gene, which encodes the mitochondrial transfer RNA for lysine, is traditionally associated with myoclonic epilepsy and ragged-red fibres (MERRF), a multisystemic mitochondrial disease that is characterised by myoclonus, seizures, cerebellar ataxia, and mitochondrial myopathy with ragged-red fibres. We studied the clinical and paraclinical phenotype of 34 patients with the m.8344A>G mutation, mainly derived from the nationwide mitoREGISTER, the multicentric registry of the German network for mitochondrial disorders (mitoNET). Mean age at symptom onset was 24.5 years ±10.9 (6-48 years) with adult onset in 75 % of the patients. In our cohort, the canonical features seizures, myoclonus, cerebellar ataxia and ragged-red fibres that are traditionally associated with MERRF, occurred in only 61, 59, 70, and 63 % of the patients, respectively. In contrast, other features such as hearing impairment were even more frequently present (72 %). Other common features in our cohort were migraine (52 %), psychiatric disorders (54 %), respiratory dysfunction (45 %), gastrointestinal symptoms (38 %), dysarthria (36 %), and dysphagia (35 %). Brain MRI revealed cerebral and/or cerebellar atrophy in 43 % of our patients. There was no correlation between the heteroplasmy level in blood and age at onset or clinical phenotype. Our findings further broaden the clinical spectrum of the m.8344A>G mutation, document the large clinical variability between carriers of the same mutation, even within families and indicate an overlap of the phenotype with other mitochondrial DNA-associated syndromes.Entities:
Keywords: Ataxia; Epilepsy; Hearing impairment; Myoclonus; Psychiatric; Ragged-red fibres
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Year: 2016 PMID: 26995359 DOI: 10.1007/s00415-016-8086-3
Source DB: PubMed Journal: J Neurol ISSN: 0340-5354 Impact factor: 4.849