Literature DB >> 26995359

Expanded phenotypic spectrum of the m.8344A>G "MERRF" mutation: data from the German mitoNET registry.

Judith Altmann1,2, Boriana Büchner3, Aleksandra Nadaj-Pakleza4, Jochen Schäfer5, Sandra Jackson5, Diana Lehmann6, Marcus Deschauer6,7, Robert Kopajtich8,9, Ronald Lautenschläger10, Klaus A Kuhn10, Kathrin Karle11, Ludger Schöls11, Jörg B Schulz1,12, Joachim Weis2, Holger Prokisch8,9, Cornelia Kornblum13,14, Kristl G Claeys15,16,17, Thomas Klopstock3,18,19.   

Abstract

The m.8344A>G mutation in the MTTK gene, which encodes the mitochondrial transfer RNA for lysine, is traditionally associated with myoclonic epilepsy and ragged-red fibres (MERRF), a multisystemic mitochondrial disease that is characterised by myoclonus, seizures, cerebellar ataxia, and mitochondrial myopathy with ragged-red fibres. We studied the clinical and paraclinical phenotype of 34 patients with the m.8344A>G mutation, mainly derived from the nationwide mitoREGISTER, the multicentric registry of the German network for mitochondrial disorders (mitoNET). Mean age at symptom onset was 24.5 years ±10.9 (6-48 years) with adult onset in 75 % of the patients. In our cohort, the canonical features seizures, myoclonus, cerebellar ataxia and ragged-red fibres that are traditionally associated with MERRF, occurred in only 61, 59, 70, and 63 % of the patients, respectively. In contrast, other features such as hearing impairment were even more frequently present (72 %). Other common features in our cohort were migraine (52 %), psychiatric disorders (54 %), respiratory dysfunction (45 %), gastrointestinal symptoms (38 %), dysarthria (36 %), and dysphagia (35 %). Brain MRI revealed cerebral and/or cerebellar atrophy in 43 % of our patients. There was no correlation between the heteroplasmy level in blood and age at onset or clinical phenotype. Our findings further broaden the clinical spectrum of the m.8344A>G mutation, document the large clinical variability between carriers of the same mutation, even within families and indicate an overlap of the phenotype with other mitochondrial DNA-associated syndromes.

Entities:  

Keywords:  Ataxia; Epilepsy; Hearing impairment; Myoclonus; Psychiatric; Ragged-red fibres

Mesh:

Substances:

Year:  2016        PMID: 26995359     DOI: 10.1007/s00415-016-8086-3

Source DB:  PubMed          Journal:  J Neurol        ISSN: 0340-5354            Impact factor:   4.849


  24 in total

1.  The typical MERRF (A8344G) mutation of the mitochondrial DNA associated with depressive mood disorders.

Authors:  Mari Judit Molnar; Jozsef Perenyi; Eva Siska; George Nemeth; Zoltan Nagy
Journal:  J Neurol       Date:  2009-03-05       Impact factor: 4.849

2.  Familial mitochondrial encephalomyopathy (MERRF): genetic, pathophysiological, and biochemical characterization of a mitochondrial DNA disease.

Authors:  D C Wallace; X X Zheng; M T Lott; J M Shoffner; J A Hodge; R I Kelley; C M Epstein; L C Hopkins
Journal:  Cell       Date:  1988-11-18       Impact factor: 41.582

3.  Clinical features associated with the A-->G transition at nucleotide 8344 of mtDNA ("MERRF mutation").

Authors:  G Silvestri; E Ciafaloni; F M Santorelli; S Shanske; S Servidei; W D Graf; M Sumi; S DiMauro
Journal:  Neurology       Date:  1993-06       Impact factor: 9.910

4.  Neuronal hyperexcitability in stroke-like episodes of MELAS syndrome.

Authors:  T Iizuka; F Sakai; N Suzuki; T Hata; S Tsukahara; M Fukuda; Y Takiyama
Journal:  Neurology       Date:  2002-09-24       Impact factor: 9.910

Review 5.  Mitochondrial disorders.

Authors:  Salvatore DiMauro; Antoni L Andreu; Darryl C De Vivo
Journal:  J Child Neurol       Date:  2002-12       Impact factor: 1.987

6.  Association of the mitochondrial 8344 MERRF mutation with maternally inherited spinocerebellar degeneration and Leigh disease.

Authors:  N Howell; I Kubacka; R Smith; F Frerman; J K Parks; W D Parker
Journal:  Neurology       Date:  1996-01       Impact factor: 9.910

7.  Reliability and validity of the scale for the assessment and rating of ataxia: a study in 64 ataxia patients.

Authors:  Anja Weyer; Michael Abele; Tanja Schmitz-Hübsch; Beate Schoch; Markus Frings; Dagmar Timmann; Thomas Klockgether
Journal:  Mov Disord       Date:  2007-08-15       Impact factor: 10.338

8.  Leigh syndrome: clinical features and biochemical and DNA abnormalities.

Authors:  S Rahman; R B Blok; H H Dahl; D M Danks; D M Kirby; C W Chow; J Christodoulou; D R Thorburn
Journal:  Ann Neurol       Date:  1996-03       Impact factor: 10.422

9.  Myoclonus epilepsy associated with ragged-red fibres (mitochondrial abnormalities ): disease entity or a syndrome? Light-and electron-microscopic studies of two cases and review of literature.

Authors:  N Fukuhara; S Tokiguchi; K Shirakawa; T Tsubaki
Journal:  J Neurol Sci       Date:  1980-07       Impact factor: 3.181

10.  "Myo-cardiomyopathy" is commonly associated with the A8344G "MERRF" mutation.

Authors:  Michela Catteruccia; Donato Sauchelli; Giacomo Della Marca; Guido Primiano; Cristina Cuccagna; Daniela Bernardo; Milena Leo; Antonella Camporeale; Tommaso Sanna; Alessandro Cianfoni; Serenella Servidei
Journal:  J Neurol       Date:  2015-01-06       Impact factor: 4.849

View more
  20 in total

1.  Beyond cervical lipomas: myoclonus, gait disorder and multisystem involvement leading to mitochondrial disease.

Authors:  Roberto López-Blanco; Ana Rojo-Sebastián; Maria Henedina Torregrosa-Martínez; Alberto Blazquez
Journal:  BMJ Case Rep       Date:  2017-06-19

Review 2.  Cerebral imaging in paediatric mitochondrial disorders.

Authors:  Josef Finsterer; Sinda Zarrouk-Mahjoub
Journal:  Neuroradiol J       Date:  2018-07-06

3.  Phenotypic spectrum of the m.8344A>G mutation.

Authors:  Josef Finsterer; Sinda Zarrouk-Mahjoub
Journal:  J Neurol       Date:  2016-04-28       Impact factor: 4.849

Review 4.  Patient care standards for primary mitochondrial disease: a consensus statement from the Mitochondrial Medicine Society.

Authors:  Sumit Parikh; Amy Goldstein; Amel Karaa; Mary Kay Koenig; Irina Anselm; Catherine Brunel-Guitton; John Christodoulou; Bruce H Cohen; David Dimmock; Gregory M Enns; Marni J Falk; Annette Feigenbaum; Richard E Frye; Jaya Ganesh; David Griesemer; Richard Haas; Rita Horvath; Mark Korson; Michael C Kruer; Michelangelo Mancuso; Shana McCormack; Marie Josee Raboisson; Tyler Reimschisel; Ramona Salvarinova; Russell P Saneto; Fernando Scaglia; John Shoffner; Peter W Stacpoole; Carolyn M Sue; Mark Tarnopolsky; Clara Van Karnebeek; Lynne A Wolfe; Zarazuela Zolkipli Cunningham; Shamima Rahman; Patrick F Chinnery
Journal:  Genet Med       Date:  2017-07-27       Impact factor: 8.822

Review 5.  Myoclonus-Ataxia Syndromes: A Diagnostic Approach.

Authors:  Malco Rossi; Sterre van der Veen; Marcelo Merello; Marina A J Tijssen; Bart van de Warrenburg
Journal:  Mov Disord Clin Pract       Date:  2020-11-03

6.  Mitochondrial DNA mutation load in a family with the m.8344A>G point mutation and lipomas: a case study.

Authors:  Tina Dysgaard Jeppesen; Noor Al-Hashimi; Morten Duno; Flemming Wibrand; Grete Andersen; John Vissing
Journal:  Clin Case Rep       Date:  2017-11-02

7.  Phenotypic heterogeneity in m.3243A>G mitochondrial disease: The role of nuclear factors.

Authors:  Sarah J Pickett; John P Grady; Yi Shiau Ng; Gráinne S Gorman; Andrew M Schaefer; Ian J Wilson; Heather J Cordell; Doug M Turnbull; Robert W Taylor; Robert McFarland
Journal:  Ann Clin Transl Neurol       Date:  2018-02-07       Impact factor: 4.511

8.  A Novel Mutation of Mitochondrial T14709C Causes Myoclonic Epilepsy with Ragged Red Fibers Syndrome in a Chinese Patient.

Authors:  Rui Ban; Jun-Hong Guo; Chuan-Qiang Pu; Qiang Shi; Hua-Xu Liu; Yu-Tong Zhang
Journal:  Chin Med J (Engl)       Date:  2018-07-05       Impact factor: 2.628

9.  Lipomatosis Incidence and Characteristics in an Italian Cohort of Mitochondrial Patients.

Authors:  Olimpia Musumeci; Emanuele Barca; Costanza Lamperti; Serenella Servidei; Giacomo Pietro Comi; Maurizio Moggio; Tiziana Mongini; Gabriele Siciliano; Massimiliano Filosto; Elena Pegoraro; Guido Primiano; Dario Ronchi; Liliana Vercelli; Daniele Orsucci; Luca Bello; Massimo Zeviani; Michelangelo Mancuso; Antonio Toscano
Journal:  Front Neurol       Date:  2019-02-27       Impact factor: 4.086

Review 10.  The metabolic face of migraine - from pathophysiology to treatment.

Authors:  Elena C Gross; Marco Lisicki; Dirk Fischer; Peter S Sándor; Jean Schoenen
Journal:  Nat Rev Neurol       Date:  2019-10-04       Impact factor: 42.937

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.