Literature DB >> 26971970

[Ganulomatosis with polyangiitis revealed by a cutaneous ulceration mimicking a pyoderma gangrenosum: Two patients].

G de Cambourg1, A Mahé2, S Banea2, C Moulinas3, G Blaison4.   

Abstract

INTRODUCTION: Granulomatosis with polyangiitis is a systemic and necrotizing vasculitis, and cutaneous involvement is uncommon. We report two cases of skin ulceration mimicking a pyoderma gangrenosum, and revealing granulomatosis with polyangiitis. CASE REPORTS: We report two patients who presented with atypical cutaneous ulcerations, with a chronic course. These wounds were large ulcerations with abrupt edges, with purulent and hemorrhagic exudates. The first hypothesis was a pyoderma gangrenosum, but the biopsies were not specific. New biopsies performed distant from the edges showed a necrotizing vasculitis associated with giant cells granuloma, typical from granulomatosis with polyangiitis.
CONCLUSION: Cutaneous manifestations are uncommon in granulomatosis with polyangiitis, and can be misleading as they may precede the systemic symptoms. We report two cases of granulomatosis with polyangiitis revealed by cutaneous symptoms mimicking a pyoderma gangrenosum. Repetition of the skin biopsies were necessary to obtain the diagnosis.
Copyright © 2015 Société Nationale Française de Médecine Interne (SNFMI). Published by Elsevier SAS. All rights reserved.

Entities:  

Keywords:  Granulomatose avec polyangéite; Granulomatosis with polyangiitis; Maladie de Wegener; Plaie cutanée; Pyoderma gangrenosum; Skin wound; Wegener's granulomatosis

Mesh:

Year:  2016        PMID: 26971970     DOI: 10.1016/j.revmed.2015.12.010

Source DB:  PubMed          Journal:  Rev Med Interne        ISSN: 0248-8663            Impact factor:   0.728


  4 in total

Review 1.  Pyoderma gangrenosum-like ulcerations in granulomatosis with polyangiitis: two cases and literature review.

Authors:  Giovanni Genovese; Simona Tavecchio; Emilio Berti; Franco Rongioletti; Angelo Valerio Marzano
Journal:  Rheumatol Int       Date:  2018-05-02       Impact factor: 2.631

2.  When a wound is the harbinger of a serious underlying systemic illness.

Authors:  Shweta Kishore; Varun Mittal; Shradha Ahuja; Vikas Majithia
Journal:  BMJ Case Rep       Date:  2018-01-31

3.  Efficacy of Rituximab for Refractory Pyoderma Gangrenosum-Like Ulcers in Granulomatosis With Polyangiitis Associated to Antiphospholipid Antibodies.

Authors:  Julia Riera; Jorge Musuruana; Cecilia Costa; Javier Cavallasca
Journal:  Arch Rheumatol       Date:  2020-01-08       Impact factor: 1.472

4.  Cutaneous Manifestations of Granulomatosis with Polyangiitis: A Case Series Study.

Authors:  Trinidad Montero-Vilchez; Antonio Martinez-Lopez; Luis Salvador-Rodriguez; Maria Del Carmen Ramírez-Barberena; Jesus Tercedor-Sanchez; Alejandro Molina-Leyva; Salvador Arias-Santiago
Journal:  Acta Derm Venereol       Date:  2020-05-28       Impact factor: 3.875

  4 in total

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