| Literature DB >> 26915362 |
Yi-Hong Shao1, Karine Choquet1,2, Roberta La Piana1, Martine Tétreault2,3, Marie-Josée Dicaire1, Kym M Boycott4, Jacek Majewski2,3, Bernard Brais5,6.
Abstract
Mutations in GALC cause Krabbe disease. This autosomal recessive leukodystrophy generally presents in early infancy as a severe disorder, but sometimes manifests as a milder adult-onset disease with spastic paraplegia as the main symptom. We recruited a family with five affected individuals presenting with adult-onset predominant cerebellar ataxia with mild spasticity. Whole exome sequencing (WES) revealed one novel and one previously reported compound heterozygous variants in GALC. Magnetic resonance imaging (MRI) confirmed the presence of typical Krabbe features. Our findings expand the phenotypic spectrum of adult-onset Krabbe disease and demonstrate the usefulness of combining WES and pattern-specific MRI for the diagnosis of neurodegenerative diseases.Entities:
Keywords: Cerebellar ataxia; Exome sequencing; GALC; Krabbe leukodystrophy
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Year: 2016 PMID: 26915362 DOI: 10.1007/s10048-016-0476-2
Source DB: PubMed Journal: Neurogenetics ISSN: 1364-6745 Impact factor: 2.660