Literature DB >> 26899947

Collagen VII Half-Life at the Dermal-Epidermal Junction Zone: Implications for Mechanisms and Therapy of Genodermatoses.

Tobias Kühl1, Markus Mezger2, Ingrid Hausser3, Lin T Guey4, Rupert Handgretinger2, Leena Bruckner-Tuderman1, Alexander Nyström5.   

Abstract

The tissue half-life of proteins largely determines treatment frequency of non-gene-editing-based therapies targeting the cause of genodermatoses. Surprisingly, such knowledge is missing for a vast number of proteins involved in pathologies. The dermal-epidermal junction zone is believed to be a rather static structure, but to our knowledge no detailed analysis of the stability of proteins within this zone has been performed. Here, we addressed the in vivo half-life of collagen type VII using genetic ablation of its expression and therapeutic introduction of exogenous collagen VII in a preclinical model. A similar in vivo stability of collagen VII was observed in the skin, tongue, and esophagus, with a half-life of about 1 month. Collagen VII expressed by intradermally injected mesenchymal stromal cells also exhibited a similar half-life. Our study provides key information needed for the development of protein replacement or cell-based therapies for dystrophic epidermolysis bullosa caused by genetic deficiency of collagen VII. Moreover, by showing what we define as an intermediate half-life of collagen VII, our study challenges the view of the dermal-epidermal junction zone as a static structure with very slow turnover.
Copyright © 2016 The Authors. Published by Elsevier Inc. All rights reserved.

Entities:  

Mesh:

Substances:

Year:  2016        PMID: 26899947     DOI: 10.1016/j.jid.2016.02.002

Source DB:  PubMed          Journal:  J Invest Dermatol        ISSN: 0022-202X            Impact factor:   8.551


  13 in total

1.  Impaired lymphoid extracellular matrix impedes antibacterial immunity in epidermolysis bullosa.

Authors:  Alexander Nyström; Olivier Bornert; Tobias Kühl; Christine Gretzmeier; Kerstin Thriene; Jörn Dengjel; Andrea Pfister-Wartha; Dimitra Kiritsi; Leena Bruckner-Tuderman
Journal:  Proc Natl Acad Sci U S A       Date:  2018-01-05       Impact factor: 11.205

2.  Analysis of the functional consequences of targeted exon deletion in COL7A1 reveals prospects for dystrophic epidermolysis bullosa therapy.

Authors:  Olivier Bornert; Tobias Kühl; Jeroen Bremer; Peter C van den Akker; Anna Mg Pasmooij; Alexander Nyström
Journal:  Mol Ther       Date:  2016-05-09       Impact factor: 11.454

Review 3.  Amlexanox Enhances Premature Termination Codon Read-Through in COL7A1 and Expression of Full Length Type VII Collagen: Potential Therapy for Recessive Dystrophic Epidermolysis Bullosa.

Authors:  Velina S Atanasova; Qiujie Jiang; Marco Prisco; Christina Gruber; Josefina Piñón Hofbauer; Mei Chen; Cristina Has; Leena Bruckner-Tuderman; John A McGrath; Jouni Uitto; Andrew P South
Journal:  J Invest Dermatol       Date:  2017-05-24       Impact factor: 8.551

4.  Fludarabine modulates expression of type VII collagen during haematopoietic stem cell transplantation for recessive dystrophic epidermolysis bullosa.

Authors:  M Vanden Oever; D Muldoon; W Mathews; J Tolar
Journal:  Br J Dermatol       Date:  2021-03-08       Impact factor: 11.113

5.  VPS33B and VIPAR are essential for epidermal lamellar body biogenesis and function.

Authors:  Clare Rogerson; Paul Gissen
Journal:  Biochim Biophys Acta Mol Basis Dis       Date:  2018-01-31       Impact factor: 5.187

Review 6.  Recent advances in understanding and managing epidermolysis bullosa.

Authors:  Dimitra Kiritsi; Alexander Nyström
Journal:  F1000Res       Date:  2018-07-17

7.  Detection of Type VII collagen in odontogenic keratocyst: An immunohistochemical study.

Authors:  Jochima-Eudora Cota; Anita Spadigam; Anita Dhupar
Journal:  J Clin Exp Dent       Date:  2019-04-01

Review 8.  Epidermolysis bullosa: Advances in research and treatment.

Authors:  Christine Prodinger; Julia Reichelt; Johann W Bauer; Martin Laimer
Journal:  Exp Dermatol       Date:  2019-08-08       Impact factor: 3.960

Review 9.  The genetics and biomechanics of thoracic aortic diseases.

Authors:  Amer Harky; Ka Siu Fan; Ka Hay Fan
Journal:  Vasc Biol       Date:  2019-10-15

10.  Efficacy of Human Placental-Derived Stem Cells in Collagen VII Knockout (Recessive Dystrophic Epidermolysis Bullosa) Animal Model.

Authors:  Yanling Liao; Larisa Ivanova; Rajarajeswari Sivalenka; Trevor Plumer; Hongwen Zhu; Xiaokui Zhang; Angela M Christiano; John A McGrath; Jodi P Gurney; Mitchell S Cairo
Journal:  Stem Cells Transl Med       Date:  2018-05-10       Impact factor: 6.940

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.