| Literature DB >> 26601801 |
Gandham SriLakshmi Bhavani1, Hitesh Shah2, Anju Shukla1, Neerja Gupta3, Kalpana Gowrishankar4, Anand P Rao5, Madhulika Kabra3, Meenal Agarwal6, Prajnya Ranganath7,8, Alka V Ekbote9, Shubha R Phadke6, Asha Kamath10, Ashwin Dalal8, Katta Mohan Girisha1.
Abstract
Multicentric osteolysis nodulosis and arthropathy (MONA) is an infrequently described autosomal recessive skeletal dysplasia characterized by progressive osteolysis and arthropathy. Inactivating mutations in MMP2, encoding matrix metalloproteinase-2, are known to cause this disorder. Fifteen families with mutations in MMP2 have been reported in literature. In this study we screened thirteen individuals from eleven families for MMP2 mutations and identified eight mutations (five novel and three known variants). We characterize the clinical, radiographic and molecular findings in all individuals with molecularly proven MONA from the present cohort and previous reports, and provide a comprehensive review of the MMP2 related disorders.Entities:
Keywords: MMP2; Torg-Winchester syndrome; multicentric osteolysis nodulosis and arthropathy
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Year: 2015 PMID: 26601801 DOI: 10.1002/ajmg.a.37447
Source DB: PubMed Journal: Am J Med Genet A ISSN: 1552-4825 Impact factor: 2.802