Literature DB >> 26453174

Phenotype, genotype and gender identity in a large cohort of patients from India with 5α-reductase 2 deficiency.

I Shabir1, M L Khurana1, A A Joseph2, M Eunice1, M Mehta2, A C Ammini1.   

Abstract

Deficiency of the 5α-reductase 2 enzyme impairs the conversion of testosterone to dihydrotestosterone (DHT) and differentiation of external genitalia, seminal vesicles and prostate in males. The present study describes the phenotype, genotype and gender identity in a large cohort of patients with 5αRD2. All patients underwent detailed clinical evaluation, hormonal profile, karyotyping and molecular analysis of the SRD5A2 gene. The molecular analysis of the SRD5A2 gene showed the presence of mutant alleles in 24 patients. We found 6 novel mutations IVS(1-2) T>C, p.A52T, 188-189insTA, 904-905ins A, p.A12T and p.E57X in our patients. All patients had ambiguous genitalia and the degrees of under-virilization ranged from penoscrotal hypospadias and microphallus to clitoromegaly. The position of gonads was variable in patients with same mutation. All the patients with mutations in the SRD5A2 gene had male gender identity. Those reared as female had gender dysphoria and underwent gender reassignment. Though a specific genotype-phenotype correlation could not be established in our patient but confirming the diagnosis of 5αRD2 with assessment of the SRD5A2 gene may help in appropriate gender assignment.
© 2015 American Society of Andrology and European Academy of Andrology.

Entities:  

Keywords:  5α-reductase 2 deficiency; SRD5A2 gene; dihydrotestosterone; testosterone

Mesh:

Substances:

Year:  2015        PMID: 26453174     DOI: 10.1111/andr.12108

Source DB:  PubMed          Journal:  Andrology        ISSN: 2047-2919            Impact factor:   3.842


  7 in total

Review 1.  Controversies of Sex Re-assignment in Genetic Males with Congenital Inadequacy of the Penis.

Authors:  Venkatachalam Raveenthiran
Journal:  Indian J Pediatr       Date:  2017-07-08       Impact factor: 1.967

2.  Identification of a novel mutation in the SRD5A2 gene of one patient with 46,XY disorder of sex development.

Authors:  Shu-Ping Li; Li-Wei Li; Ming-Xia Sun; Xin-Xin Chen; Xiu-Feng Wang; Zeng-Kui Li; Sheng-Yun Zhou; Dong-Cai Zhai; Shu-Xia Geng; Shu-Jun Li; Xiao-Wei Dou
Journal:  Asian J Androl       Date:  2018 Sep-Oct       Impact factor: 3.285

3.  Clinical characteristics and genotype-phenotype correlations of 130 Chinese children in a high-homogeneity single-center cohort with 5α-reductase 2 deficiency.

Authors:  Lijun Fan; Yanning Song; Michel Polak; Lele Li; Xiaoya Ren; Beibei Zhang; Di Wu; Chunxiu Gong
Journal:  Mol Genet Genomic Med       Date:  2020-07-26       Impact factor: 2.183

4.  "Congruency the ART of Being Real" - 46XY DSD Due to 5 α Reductase Deficiency - Challenges in Decision Making.

Authors:  Sridhar Subbiah; Raghavendran Priyanka; Sangumani Jayaraman
Journal:  Indian J Endocrinol Metab       Date:  2022-01-12

5.  Mutations in AR or SRD5A2 Genes: Clinical Findings, Endocrine Pitfalls, and Genetic Features of Children with 46,XY DSD

Authors:  Neşe Akcan; Oya Uyguner; Firdevs Baş; Umut Altunoğlu; Güven Toksoy; Birsen Karaman; Şahin Avcı; Zehra Yavaş Abalı; Şükran Poyrazoğlu; Agharza Aghayev; Volkan Karaman; Rüveyde Bundak; Seher Başaran; Feyza Darendeliler
Journal:  J Clin Res Pediatr Endocrinol       Date:  2022-02-09

6.  Accuracy of Urinary Etiocholanolone/Androsterone Ratio as Alternative to Serum Testosterone/Dihydrotestosterone Ratio for Diagnosis of 5 Alpha-reductase Type 2 Deficiency Patients and Carriers in Indonesia.

Authors:  Nanis Sacharina Marzuki; Firman Pratama Idris; Hannie Kartapradja; Shirley Renata; Alida Harahap; Jose Rizal Latief Batubara
Journal:  Int J Endocrinol Metab       Date:  2021-04-18

7.  Characterising SRD5A2 Gene Variants in 37 Indonesian Patients with 5-Alpha-Reductase Type 2 Deficiency.

Authors:  Nanis S Marzuki; Firman P Idris; Hannie D Kartapradja; Alida R Harahap; Jose R L Batubara
Journal:  Int J Endocrinol       Date:  2019-12-01       Impact factor: 3.257

  7 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.