Literature DB >> 26335952

Personalized medicine for cystic fibrosis: establishing human model systems.

Hongmei Mou1,2,3, Karissa Brazauskas3, Jayaraj Rajagopal1,2,4.   

Abstract

With over 1,500 identifiable mutations in the cystic fibrosis transmembrane conductance regulator (CFTR) gene that result in distinct functional and phenotypical abnormalities, it is virtually impossible to perform randomized clinical trials to identify the best therapeutics for all patients. Therefore, a personalized medicine approach is essential. The only way to realistically accomplish this is through the development of improved in vitro human model systems. The lack of a readily available and infinite supply of human CFTR-expressing airway epithelial cells is a key bottleneck. We propose that a concerted two-pronged approach is necessary for patient-specific cystic fibrosis research to continue to prosper and realize its potential: (1) more effective culture and differentiation conditions for growing primary human airway and nasal epithelial cells and (2) the development of collective protocols for efficiently differentiating disease- and patient-specific induced pluripotent stem cells (iPSC) into pure populations of adult epithelial cells. Ultimately, we need a personalized human model system for cystic fibrosis with the capacity for uncomplicated bankability, widespread availability, and universal applicability for patient-specific disease modeling, novel pharmacotherapy investigation and screening, and readily executable genetic modification.
© 2015 Wiley Periodicals, Inc.

Entities:  

Keywords:  airway and lung cell biology; cystic fibrosis (CF); individualized medicine; induced pluripotent stem cells; organoids; stem cells

Mesh:

Substances:

Year:  2015        PMID: 26335952     DOI: 10.1002/ppul.23233

Source DB:  PubMed          Journal:  Pediatr Pulmonol        ISSN: 1099-0496


  16 in total

1.  Detection of CFTR function and modulation in primary human nasal cell spheroids.

Authors:  John J Brewington; Erin T Filbrandt; F J LaRosa; Alicia J Ostmann; Lauren M Strecker; Rhonda D Szczesniak; John P Clancy
Journal:  J Cyst Fibros       Date:  2017-07-13       Impact factor: 5.482

2.  Generation of Human Nasal Epithelial Cell Spheroids for Individualized Cystic Fibrosis Transmembrane Conductance Regulator Study.

Authors:  John J Brewington; Erin T Filbrandt; Francis J LaRosa; Jessica D Moncivaiz; Alicia J Ostmann; Lauren M Strecker; John P Clancy
Journal:  J Vis Exp       Date:  2018-04-11       Impact factor: 1.355

3.  Ivacaftor Reverses Airway Mucus Abnormalities in a Rat Model Harboring a Humanized G551D-CFTR.

Authors:  Susan E Birket; Joy M Davis; Courtney M Fernandez-Petty; Alexander G Henderson; Ashley M Oden; LiPing Tang; Hui Wen; Jeong Hong; Lianwu Fu; Andre Chambers; Alvin Fields; Gojun Zhao; Guillermo J Tearney; Eric J Sorscher; Steven M Rowe
Journal:  Am J Respir Crit Care Med       Date:  2020-11-01       Impact factor: 21.405

Review 4.  New Therapeutic Approaches to Modulate and Correct Cystic Fibrosis Transmembrane Conductance Regulator.

Authors:  Thida Ong; Bonnie W Ramsey
Journal:  Pediatr Clin North Am       Date:  2016-08       Impact factor: 3.278

5.  Air-liquid interface cultures of the healthy and diseased human respiratory tract: promises, challenges and future directions.

Authors:  Domizia Baldassi; Bettina Gabold; Olivia Merkel
Journal:  Adv Nanobiomed Res       Date:  2021-05-06

Review 6.  CFTR modulator theratyping: Current status, gaps and future directions.

Authors:  John Paul Clancy; Calvin U Cotton; Scott H Donaldson; George M Solomon; Donald R VanDevanter; Michael P Boyle; Martina Gentzsch; Jerry A Nick; Beate Illek; John C Wallenburg; Eric J Sorscher; Margarida D Amaral; Jeffrey M Beekman; Anjaparavanda P Naren; Robert J Bridges; Philip J Thomas; Garry Cutting; Steven Rowe; Anthony G Durmowicz; Martin Mense; Kris D Boeck; William Skach; Christopher Penland; Elizabeth Joseloff; Hermann Bihler; John Mahoney; Drucy Borowitz; Katherine L Tuggle
Journal:  J Cyst Fibros       Date:  2018-06-20       Impact factor: 5.482

7.  Brushed nasal epithelial cells are a surrogate for bronchial epithelial CFTR studies.

Authors:  John J Brewington; Erin T Filbrandt; F J LaRosa; Jessica D Moncivaiz; Alicia J Ostmann; Lauren M Strecker; John P Clancy
Journal:  JCI Insight       Date:  2018-07-12

8.  Personalized Medicine Based on Nasal Epithelial Cells: Comparative Studies with Rectal Biopsies and Intestinal Organoids.

Authors:  Iris A L Silva; Violeta Railean; Aires Duarte; Margarida D Amaral
Journal:  J Pers Med       Date:  2021-05-16

Review 9.  Drug Discovery via Human-Derived Stem Cell Organoids.

Authors:  Fangkun Liu; Jing Huang; Bo Ning; Zhixiong Liu; Shen Chen; Wei Zhao
Journal:  Front Pharmacol       Date:  2016-09-22       Impact factor: 5.810

Review 10.  Stem and Progenitor Cells in Human Cardiopulmonary Development and Regeneration.

Authors:  Silvana Bardelli; Marco Moccetti
Journal:  Stem Cells Int       Date:  2017-09-17       Impact factor: 5.443

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.