Literature DB >> 26204294

Diagnostic Performance of Whole-Body MRI as a Tool for Cancer Screening in Children With Genetic Cancer-Predisposing Conditions.

Sudha A Anupindi1,2, Maria A Bedoya1, Robert B Lindell3, Siri J Rambhatla1,4, Kristin Zelley5, Kim E Nichols5,6, Nancy A Chauvin1,2.   

Abstract

OBJECTIVE: Children with cancer-predisposing conditions are at increased risk to develop and die of cancer. Limited data exist on the utility of whole-body MRI as a cancer screening tool in children. In this study, we examined the diagnostic performance of whole-body MRI as a mechanism of tumor surveillance for children at increased genetic risk for cancer.
MATERIALS AND METHODS: Twenty-four children (six boys and 18 girls) with a mean age of 11.2 years (range, 2.1-18.2 years) underwent 50 unenhanced whole-body MRI examinations over a 5-year period. Scans were retrospectively reviewed and assessed for image quality; sequences performed; and the presence of osseous, soft-tissue, or solid organ abnormalities. Findings suggestive of a malignancy were stratified by risk as low (< 20% chance for cancer), moderate (20-80%), or high (> 80%). MRI findings were correlated with medical records, biopsy results, or additional follow-up imaging; biopsy and follow-up were considered as the reference standards.
RESULTS: Forty-eight of 50 (96%) examinations were of very good quality. Nine findings suspicious for malignancy were identified, including two high-risk, two moderate-risk, and five low-risk lesions. One high-risk lesion was proven by biopsy to be a papillary thyroid carcinoma, with the remaining lesions deemed nonmalignant. The sensitivity of whole-body MRI was 100%; specificity, 94%; positive predictive value, 25%; and negative predictive value (NPV), 100%.
CONCLUSION: Unenhanced whole-body MRI is safe and produces excellent images. The high sensitivity, specificity, and NPV make whole-body MRI a valuable cancer screening tool in children with a genetic predisposition for cancer.

Entities:  

Keywords:  Li-Fraumeni syndrome; cancer predisposition; children; hereditary paraganglioma-pheochromocytoma syndrome; whole-body MRI

Mesh:

Year:  2015        PMID: 26204294     DOI: 10.2214/AJR.14.13663

Source DB:  PubMed          Journal:  AJR Am J Roentgenol        ISSN: 0361-803X            Impact factor:   3.959


  26 in total

1.  Prevalence of Cancer at Baseline Screening in the National Cancer Institute Li-Fraumeni Syndrome Cohort.

Authors:  Phuong L Mai; Payal P Khincha; Jennifer T Loud; Rosamma M DeCastro; Renée C Bremer; June A Peters; Chia-Ying Liu; David A Bluemke; Ashkan A Malayeri; Sharon A Savage
Journal:  JAMA Oncol       Date:  2017-12-01       Impact factor: 31.777

2.  Cost-effectiveness of early cancer surveillance for patients with Li-Fraumeni syndrome.

Authors:  Casey R Tak; Eman Biltaji; Wendy Kohlmann; Luke Maese; Pierre Hainaut; Anita Villani; David Malkin; Catherine M T Sherwin; Diana I Brixner; Joshua D Schiffman
Journal:  Pediatr Blood Cancer       Date:  2019-02-04       Impact factor: 3.167

Review 3.  Magnetic resonance imaging of the mediastinum, chest wall and pleura in children.

Authors:  David E Manson
Journal:  Pediatr Radiol       Date:  2016-05-26

Review 4.  Whole-body magnetic resonance imaging in children: technique and clinical applications.

Authors:  Eric P Eutsler; Geetika Khanna
Journal:  Pediatr Radiol       Date:  2016-05-26

Review 5.  Recommendations for Long-Term Follow-up of Adults with Heritable Retinoblastoma.

Authors:  Emily S Tonorezos; Danielle Novetsky Friedman; Dana Barnea; Machteld I Bosscha; Guillermo Chantada; Charlotte J Dommering; Pim de Graaf; Ira J Dunkel; Armida W M Fabius; Jasmine H Francis; Mary-Louise C Greer; Ruth A Kleinerman; Wijnanda A Kors; Suzanne Laughlin; Annette C Moll; Lindsay M Morton; Petra Temming; Margaret A Tucker; Flora E van Leeuwen; Michael F Walsh; Kevin C Oeffinger; David H Abramson
Journal:  Ophthalmology       Date:  2020-05-15       Impact factor: 12.079

6.  Whole-body magnetic resonance imaging as surveillance for subsequent malignancies in preadolescent, adolescent, and young adult survivors of germline retinoblastoma: An update.

Authors:  Danielle Novetsky Friedman; Meier Hsu; Chaya S Moskowitz; Jasmine H Francis; Eric Lis; Megan Harlan Fleischut; Kevin C Oeffinger; Michael Walsh; Emily S Tonorezos; Charles A Sklar; David H Abramson; Ira J Dunkel
Journal:  Pediatr Blood Cancer       Date:  2020-05-09       Impact factor: 3.167

7.  Estimating TP53 Mutation Carrier Probability in Families with Li-Fraumeni Syndrome Using LFSPRO.

Authors:  Gang Peng; Jasmina Bojadzieva; Mandy L Ballinger; Jialu Li; Amanda L Blackford; Phuong L Mai; Sharon A Savage; David M Thomas; Louise C Strong; Wenyi Wang
Journal:  Cancer Epidemiol Biomarkers Prev       Date:  2017-01-30       Impact factor: 4.254

8.  Pediatric imaging in DICER1 syndrome.

Authors:  Marta Tijerin Bueno; Claudia Martínez-Ríos; Alejandro De la Puente Gregorio; Rayan A Ahyad; Anita Villani; Harriet Druker; Kalene van Engelen; Bailey Gallinger; Laura Aronoff; Ronald Grant; David Malkin; Mary-Louise C Greer
Journal:  Pediatr Radiol       Date:  2017-05-04

Review 9.  Imaging of cancer predisposition syndromes.

Authors:  Mary-Louise C Greer
Journal:  Pediatr Radiol       Date:  2018-08-04

10.  Whole body magnetic resonance imaging (WB-MRI) and brain MRI baseline surveillance in TP53 germline mutation carriers: experience from the Li-Fraumeni Syndrome Education and Early Detection (LEAD) clinic.

Authors:  Jasmina Bojadzieva; Behrang Amini; Suzanne F Day; Tiffiny L Jackson; Parijatham S Thomas; Brandy J Willis; Whitney R Throckmorton; Najat C Daw; Therese B Bevers; Louise C Strong
Journal:  Fam Cancer       Date:  2018-04       Impact factor: 2.375

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