Literature DB >> 25811668

Determination of 21-hydroxylase autoantibodies: inter-laboratory concordance in the Euradrenal International Serum Exchange Program.

Alberto Falorni, Vittorio Bini, Corrado Betterle, Annalisa Brozzetti, Luis Castaño, Marta Fichna, Olle Kämpe, Gunnar Mellgren, Pärt Peterson, Shu Chen, Johan Rönnelid, Jochen Seissler, Claudio Tiberti, Raivo Uibo, Liping Yu, Åke Lernmark, Eystein Husebye.   

Abstract

BACKGROUND: 21-Hydroxylase autoantibodies (21OHAb) are markers of an adrenal autoimmune process that identifies individuals with autoimmune Addison's disease (AAD). Quality and inter-laboratory agreement of various 21OHAb tests are incompletely known. The objective of the study was to determine inter-laboratory concordance for 21OHAb determinations.
METHODS: Sixty-nine sera from 51 patients with AAD and 51 sera from 51 healthy subjects were blindly coded by a randomization center and distributed to 14 laboratories that determined 21OHAb, either by an "in-house" assay (n=9) using in vitro-translated (35)S-21OH or luciferase-labeled 21OH or a commercial kit with (125)I-21OH (n=5). Main outcome measures were diagnostic accuracy of each participating laboratory and inter-laboratory agreement of 21OHAb assays.
RESULTS: Intra-assay coefficient of variation ranged from 2.6% to 5.3% for laboratories using the commercial kit and from 5.1% to 23% for laboratories using "in-house" assays. Diagnostic accuracy, expressed as area under ROC curve (AUC), varied from 0.625 to 0.947 with the commercial kit and from 0.562 to 0.978 with "in-house" methods. Cohen's κ of inter-rater agreement was 0.603 among all 14 laboratories, 0.691 among "in-house" laboratories, and 0.502 among commercial kit users. Optimized cutoff levels, calculated on the basis of AUCs, increased the diagnostic accuracy of every laboratory (AUC >0.9 for 11/14 laboratories) and increased the Cohen's κ of inter-rater agreement. Discrepancies in quantitation of 21OHAb levels among different laboratories increased with increasing autoantibody levels.
CONCLUSIONS: The quality of 21OHAb analytical procedures is mainly influenced by selection of cutoff value and correct handling of assay materials. A standardization program is needed to identify common standard sera and common measuring units.

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Year:  2015        PMID: 25811668     DOI: 10.1515/cclm-2014-1106

Source DB:  PubMed          Journal:  Clin Chem Lab Med        ISSN: 1434-6621            Impact factor:   3.694


  7 in total

Review 1.  Fertility and pregnancy in women with primary adrenal insufficiency.

Authors:  Sophie Bensing; Roberta Giordano; Alberto Falorni
Journal:  Endocrine       Date:  2020-05-29       Impact factor: 3.633

2.  The natural history of 21-hydroxylase autoantibodies in autoimmune Addison's disease.

Authors:  Anette Boe Wolff; Lars Breivik; Karl Ove Hufthammer; Marianne Aardal Grytaas; Eirik Bratland; Eystein Sverre Husebye; Bergithe Eikeland Oftedal
Journal:  Eur J Endocrinol       Date:  2021-04       Impact factor: 6.664

Review 3.  Epidemiology, pathogenesis, and diagnosis of Addison's disease in adults.

Authors:  C Betterle; F Presotto; J Furmaniak
Journal:  J Endocrinol Invest       Date:  2019-07-18       Impact factor: 5.467

4.  Common genetic variation in the autoimmune regulator (AIRE) locus is associated with autoimmune Addison's disease in Sweden.

Authors:  Daniel Eriksson; Matteo Bianchi; Nils Landegren; Frida Dalin; Jakob Skov; Lina Hultin-Rosenberg; Argyri Mathioudaki; Jessika Nordin; Åsa Hallgren; Göran Andersson; Karolina Tandre; Solbritt Rantapää Dahlqvist; Peter Söderkvist; Lars Rönnblom; Anna-Lena Hulting; Jeanette Wahlberg; Per Dahlqvist; Olov Ekwall; Jennifer R S Meadows; Kerstin Lindblad-Toh; Sophie Bensing; Gerli Rosengren Pielberg; Olle Kämpe
Journal:  Sci Rep       Date:  2018-05-30       Impact factor: 4.379

5.  Heritability of Addison's disease and prevalence of associated autoimmunity in a cohort of 112,100 Swedish twins.

Authors:  Jakob Skov; Jonas Höijer; Patrik K E Magnusson; Jonas F Ludvigsson; Olle Kämpe; Sophie Bensing
Journal:  Endocrine       Date:  2017-10-16       Impact factor: 3.633

6.  A Wide Spectrum of Autoimmune Manifestations and Other Symptoms Suggesting Immune Dysregulation in Patients With Cartilage-Hair Hypoplasia.

Authors:  Svetlana Vakkilainen; Riikka Mäkitie; Paula Klemetti; Helena Valta; Mervi Taskinen; Eystein Sverre Husebye; Outi Mäkitie
Journal:  Front Immunol       Date:  2018-10-25       Impact factor: 7.561

7.  Coexistence of Congenital Adrenal Hyperplasia and Autoimmune Addison's Disease.

Authors:  Sigrid Aslaksen; Paal Methlie; Magnus D Vigeland; Dag E Jøssang; Anette B Wolff; Ying Sheng; Bergithe E Oftedal; Beate Skinningsrud; Dag E Undlien; Kaja K Selmer; Eystein S Husebye; Eirik Bratland
Journal:  Front Endocrinol (Lausanne)       Date:  2019-09-27       Impact factor: 5.555

  7 in total

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