Literature DB >> 25701269

Networking Across Borders for Individuals with Organic Acidurias and Urea Cycle Disorders: The E-IMD Consortium.

Stefan Kölker1, Dries Dobbelaere, Johannes Häberle, Peter Burgard, Florian Gleich, Marshall L Summar, Steven Hannigan, Samantha Parker, Anupam Chakrapani, Matthias R Baumgartner.   

Abstract

BACKGROUND: Patients with organic acidurias (OAD) and urea cycle disorders (UCD) are at increased risk of disability, impaired quality of life and reduced life expectancy. Clinical care in any one centre is constrained by small patient numbers; and furthermore diagnostic and treatment strategies vary between metabolic centres and countries, resulting in significant inequalities and disparity in patient outcome. AIMS/
METHODS: The overall objective of the EU-funded activity 'European registry and network for intoxication type metabolic diseases' (E-IMD) is to collect systematic data to improve the knowledge of these diseases, to develop consensus care guidelines and to provide detailed information materials for families and professionals.
RESULTS: Within three years E-IMD has (1) established a network of 87 partners in 25 countries (2) set up a patient registry of more than 1,000 individuals with OAD and UCD, (3) launched a website ( www.e-imd.org ) including detailed information materials in 11 languages, (4) developed guidelines for OAD and UCD, (5) organised two teaching courses and various scientific meetings, (6) extended the IT platform clustering with other inherited metabolic diseases (IMD) and (7) strengthened the collaboration with other international scientific consortia.
CONCLUSIONS: E-IMD has made important steps towards improving and sharing knowledge on OAD and UCD and harmonisation of diagnostic and therapeutic strategies. Through the establishment of a modular patient registry, clustering with other IMD and stepwise extension of the network, E-IMD has implemented the core components of a European Reference Network for rare diseases.

Entities:  

Year:  2015        PMID: 25701269      PMCID: PMC4486274          DOI: 10.1007/8904_2015_408

Source DB:  PubMed          Journal:  JIMD Rep        ISSN: 2192-8304


  39 in total

1.  Influence of phenylalanine intake on phenylketonuria.

Authors:  H BICKEL; J GERRARD; E M HICKMANS
Journal:  Lancet       Date:  1953-10-17       Impact factor: 79.321

2.  Guideline for the diagnosis and management of glutaryl-CoA dehydrogenase deficiency (glutaric aciduria type I).

Authors:  S Kölker; E Christensen; J V Leonard; C R Greenberg; A B Burlina; A P Burlina; M Dixon; M Duran; S I Goodman; D M Koeller; E Müller; E R Naughten; E Neumaier-Probst; J G Okun; M Kyllerman; R A Surtees; B Wilcken; G F Hoffmann; P Burgard
Journal:  J Inherit Metab Dis       Date:  2007-01-03       Impact factor: 4.982

3.  Development of clinical guidelines for inborn errors of metabolism: commentary.

Authors:  Jerry Vockley; Kimberly A Chapman; Georgianne L Arnold
Journal:  Mol Genet Metab       Date:  2013-01-30       Impact factor: 4.797

4.  Natural history, outcome, and treatment efficacy in children and adults with glutaryl-CoA dehydrogenase deficiency.

Authors:  Stefan Kölker; Sven F Garbade; Cheryl R Greenberg; James V Leonard; Jean-Marie Saudubray; Antonia Ribes; H Serap Kalkanoglu; Allan M Lund; Begoña Merinero; Moacir Wajner; Mónica Troncoso; Monique Williams; John H Walter; Jaume Campistol; Milagros Martí-Herrero; Melissa Caswill; Alberto B Burlina; Florian Lagler; Esther M Maier; Bernd Schwahn; Aysegul Tokatli; Ali Dursun; Turgay Coskun; Ronald A Chalmers; David M Koeller; Johannes Zschocke; Ernst Christensen; Peter Burgard; Georg F Hoffmann
Journal:  Pediatr Res       Date:  2006-04-26       Impact factor: 3.756

5.  Evaluation of Implementation, Adaptation and Use of the Recently Proposed Urea Cycle Disorders Guidelines.

Authors:  Johannes Häberle; Martina Huemer
Journal:  JIMD Rep       Date:  2015-02-18

6.  Social economic costs and health-related quality of life in patients with degenerative cerebellar ataxia in Spain.

Authors:  Julio López-Bastida; Lilisbeth Perestelo-Pérez; Fernando Montón-Alvarez; Pedro Serrano-Aguilar
Journal:  Mov Disord       Date:  2008-01-30       Impact factor: 10.338

7.  Social economic costs and health-related quality of life in patients with amyotrophic lateral sclerosis in Spain.

Authors:  Julio López-Bastida; Lilisbeth Perestelo-Pérez; Fernando Montón-Alvarez; Pedro Serrano-Aguilar; Jose Luis Alfonso-Sanchez
Journal:  Amyotroph Lateral Scler       Date:  2009-08

8.  Screening newborns for inborn errors of metabolism by tandem mass spectrometry.

Authors:  Bridget Wilcken; Veronica Wiley; Judith Hammond; Kevin Carpenter
Journal:  N Engl J Med       Date:  2003-06-05       Impact factor: 91.245

9.  Survival after treatment with phenylacetate and benzoate for urea-cycle disorders.

Authors:  Gregory M Enns; Susan A Berry; Gerard T Berry; William J Rhead; Saul W Brusilow; Ada Hamosh
Journal:  N Engl J Med       Date:  2007-05-31       Impact factor: 91.245

10.  Decline of acute encephalopathic crises in children with glutaryl-CoA dehydrogenase deficiency identified by newborn screening in Germany.

Authors:  Stefan Kölker; Sven F Garbade; Nikolas Boy; Esther M Maier; Thomas Meissner; Chris Mühlhausen; Julia B Hennermann; Thomas Lücke; Johannes Häberle; Jochen Baumkötter; Wolfram Haller; Edith Muller; Johannes Zschocke; Peter Burgard; Georg F Hoffmann
Journal:  Pediatr Res       Date:  2007-09       Impact factor: 3.756

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  13 in total

1.  Neonatal mortality and outcome at the end of the first year of life in early onset urea cycle disorders--review and meta-analysis of observational studies published over more than 35 years.

Authors:  Peter Burgard; Stefan Kölker; Gisela Haege; Martin Lindner; Georg F Hoffmann
Journal:  J Inherit Metab Dis       Date:  2015-12-03       Impact factor: 4.982

2.  The phenotypic spectrum of organic acidurias and urea cycle disorders. Part 1: the initial presentation.

Authors:  Stefan Kölker; Angeles Garcia-Cazorla; Angeles Garcia Cazorla; Vassili Valayannopoulos; Allan M Lund; Alberto B Burlina; Jolanta Sykut-Cegielska; Frits A Wijburg; Elisa Leão Teles; Jiri Zeman; Carlo Dionisi-Vici; Ivo Barić; Daniela Karall; Persephone Augoustides-Savvopoulou; Lise Aksglaede; Jean-Baptiste Arnoux; Paula Avram; Matthias R Baumgartner; Javier Blasco-Alonso; Brigitte Chabrol; Anupam Chakrapani; Kimberly Chapman; Elisenda Cortès I Saladelafont; Maria L Couce; Linda de Meirleir; Dries Dobbelaere; Veronika Dvorakova; Francesca Furlan; Florian Gleich; Wanda Gradowska; Stephanie Grünewald; Anil Jalan; Johannes Häberle; Gisela Haege; Robin Lachmann; Alexander Laemmle; Eveline Langereis; Pascale de Lonlay; Diego Martinelli; Shirou Matsumoto; Chris Mühlhausen; Hélène Ogier de Baulny; Carlos Ortez; Luis Peña-Quintana; Danijela Petković Ramadža; Esmeralda Rodrigues; Sabine Scholl-Bürgi; Etienne Sokal; Christian Staufner; Marshall L Summar; Nicholas Thompson; Roshni Vara; Inmaculada Vives Pinera; John H Walter; Monique Williams; Peter Burgard
Journal:  J Inherit Metab Dis       Date:  2015-04-15       Impact factor: 4.982

3.  The phenotypic spectrum of organic acidurias and urea cycle disorders. Part 2: the evolving clinical phenotype.

Authors:  Stefan Kölker; Vassili Valayannopoulos; Alberto B Burlina; Jolanta Sykut-Cegielska; Frits A Wijburg; Elisa Leão Teles; Jiri Zeman; Carlo Dionisi-Vici; Ivo Barić; Daniela Karall; Jean-Baptiste Arnoux; Paula Avram; Matthias R Baumgartner; Javier Blasco-Alonso; S P Nikolas Boy; Marlene Bøgehus Rasmussen; Peter Burgard; Brigitte Chabrol; Anupam Chakrapani; Kimberly Chapman; Elisenda Cortès I Saladelafont; Maria L Couce; Linda de Meirleir; Dries Dobbelaere; Francesca Furlan; Florian Gleich; Maria Julieta González; Wanda Gradowska; Stephanie Grünewald; Tomas Honzik; Friederike Hörster; Hariklea Ioannou; Anil Jalan; Johannes Häberle; Gisela Haege; Eveline Langereis; Pascale de Lonlay; Diego Martinelli; Shirou Matsumoto; Chris Mühlhausen; Elaine Murphy; Hélène Ogier de Baulny; Carlos Ortez; Consuelo C Pedrón; Guillem Pintos-Morell; Luis Pena-Quintana; Danijela Petković Ramadža; Esmeralda Rodrigues; Sabine Scholl-Bürgi; Etienne Sokal; Marshall L Summar; Nicholas Thompson; Roshni Vara; Inmaculada Vives Pinera; John H Walter; Monique Williams; Allan M Lund; Angeles Garcia-Cazorla; Angeles Garcia Cazorla
Journal:  J Inherit Metab Dis       Date:  2015-04-15       Impact factor: 4.982

4.  Behavioural and emotional problems, intellectual impairment and health-related quality of life in patients with organic acidurias and urea cycle disorders.

Authors:  Dagmar Jamiolkowski; Stefan Kölker; Esther M Glahn; Ivo Barić; Jiri Zeman; Matthias R Baumgartner; Chris Mühlhausen; Angels Garcia-Cazorla; Florian Gleich; Gisela Haege; Peter Burgard
Journal:  J Inherit Metab Dis       Date:  2015-08-27       Impact factor: 4.982

5.  Impact of age at onset and newborn screening on outcome in organic acidurias.

Authors:  Jana Heringer; Vassili Valayannopoulos; Allan M Lund; Frits A Wijburg; Peter Freisinger; Ivo Barić; Matthias R Baumgartner; Peter Burgard; Alberto B Burlina; Kimberly A Chapman; Elisenda Cortès I Saladelafont; Daniela Karall; Chris Mühlhausen; Victoria Riches; Manuel Schiff; Jolanta Sykut-Cegielska; John H Walter; Jiri Zeman; Brigitte Chabrol; Stefan Kölker
Journal:  J Inherit Metab Dis       Date:  2015-12-21       Impact factor: 4.982

6.  Age at disease onset and peak ammonium level rather than interventional variables predict the neurological outcome in urea cycle disorders.

Authors:  Roland Posset; Angeles Garcia-Cazorla; Vassili Valayannopoulos; Elisa Leão Teles; Carlo Dionisi-Vici; Anaïs Brassier; Alberto B Burlina; Peter Burgard; Elisenda Cortès-Saladelafont; Dries Dobbelaere; Maria L Couce; Jolanta Sykut-Cegielska; Johannes Häberle; Allan M Lund; Anupam Chakrapani; Manuel Schiff; John H Walter; Jiri Zeman; Roshni Vara; Stefan Kölker
Journal:  J Inherit Metab Dis       Date:  2016-04-22       Impact factor: 4.982

7.  Transatlantic combined and comparative data analysis of 1095 patients with urea cycle disorders-A successful strategy for clinical research of rare diseases.

Authors:  Roland Posset; Sven F Garbade; Nikolas Boy; Alberto B Burlina; Carlo Dionisi-Vici; Dries Dobbelaere; Angeles Garcia-Cazorla; Pascale de Lonlay; Elisa Leão Teles; Roshni Vara; Nicholas Ah Mew; Mark L Batshaw; Matthias R Baumgartner; Shawn E McCandless; Jennifer Seminara; Marshall Summar; Georg F Hoffmann; Stefan Kölker; Peter Burgard
Journal:  J Inherit Metab Dis       Date:  2019-01       Impact factor: 4.982

8.  Impact of Diagnosis and Therapy on Cognitive Function in Urea Cycle Disorders.

Authors:  Roland Posset; Andrea L Gropman; Sandesh C S Nagamani; Lindsay C Burrage; Jirair K Bedoyan; Derek Wong; Gerard T Berry; Matthias R Baumgartner; Marc Yudkoff; Matthias Zielonka; Georg F Hoffmann; Peter Burgard; Andreas Schulze; Shawn E McCandless; Angeles Garcia-Cazorla; Jennifer Seminara; Sven F Garbade; Stefan Kölker
Journal:  Ann Neurol       Date:  2019-05-13       Impact factor: 10.422

9.  Clinical course of 63 patients with neonatal onset urea cycle disorders in the years 2001-2013.

Authors:  Caroline Unsinn; Anibh Das; Vassili Valayannopoulos; Eva Thimm; Skadi Beblo; Alberto Burlina; Vassiliki Konstantopoulou; Sebene Mayorandan; Pascale de Lonlay; Jörg Rennecke; Jens Derbinski; Georg F Hoffmann; Johannes Häberle
Journal:  Orphanet J Rare Dis       Date:  2016-08-19       Impact factor: 4.123

10.  Early prediction of phenotypic severity in Citrullinemia Type 1.

Authors:  Matthias Zielonka; Stefan Kölker; Florian Gleich; Nicolas Stützenberger; Sandesh C S Nagamani; Andrea L Gropman; Georg F Hoffmann; Sven F Garbade; Roland Posset
Journal:  Ann Clin Transl Neurol       Date:  2019-08-30       Impact factor: 4.511

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