Literature DB >> 25608121

Mowat-Wilson syndrome: neurological and molecular study in seven patients.

José Albino da Paz1, Chong Ae Kim1, Michael Goossens2, Irina Giurgea2, Maria Joaquina Marques-Dias3.   

Abstract

OBJECTIVE: To present a seven-cases serie of Mowat-Wilson syndrome (MWS).
METHOD: All patients with positive mutation for the ZEB2 were evaluated by a geneticist and a neurologist, with clinical and laboratorial characterization.
RESULTS: A peculiar facies and mental retardation were present in all patients. The Denver II scale showed intense delay in all aspects, especially fine motor and adaptive. Acquired microcephaly was observed in five patients. Only one patient did not present epilepsy. Epilepsy was focal and predominating in sleep, with status epilepticus in three patients. The initial seizure was associated with fever in most patients (4/6). The EEG showed epileptic focal activity (5/7). The imaging studies revealed total agenesis (4/7) and partial agenesis of the corpus callosum (1/7).
CONCLUSION: Physicians who care for patients with mental retardation and epilepsy should be aware of SMW.

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Year:  2015        PMID: 25608121     DOI: 10.1590/0004-282X20140182

Source DB:  PubMed          Journal:  Arq Neuropsiquiatr        ISSN: 0004-282X            Impact factor:   1.420


  6 in total

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Authors:  Johannes W Duess; Prem Puri
Journal:  Pediatr Surg Int       Date:  2015-07-09       Impact factor: 1.827

Review 2.  Hirschsprung's disease in children with Mowat-Wilson syndrome.

Authors:  David Coyle; Prem Puri
Journal:  Pediatr Surg Int       Date:  2015-07-09       Impact factor: 1.827

3.  A Chinese Boy with Mowat-Wilson Syndrome Caused by a 10 bp Deletion in the ZEB2 Gene.

Authors:  Lin Wei; Xiao Han; Xue Li; Bingjuan Han; Wenying Nie
Journal:  Pharmgenomics Pers Med       Date:  2021-08-23

4.  Analysis of gene variants in the GASH/Sal model of epilepsy.

Authors:  Elena Díaz-Casado; Ricardo Gómez-Nieto; José M de Pereda; Luis J Muñoz; María Jara-Acevedo; Dolores E López
Journal:  PLoS One       Date:  2020-03-13       Impact factor: 3.240

5.  Hyperactivity of Rac1-GTPase pathway impairs neuritogenesis of cortical neurons by altering actin dynamics.

Authors:  Valentina Zamboni; Maria Armentano; Gaia Berto; Elisa Ciraolo; Alessandra Ghigo; Donatella Garzotto; Alessandro Umbach; Ferdinando DiCunto; Elena Parmigiani; Marina Boido; Alessandro Vercelli; Nadia El-Assawy; Alessandro Mauro; Lorenzo Priano; Luisa Ponzoni; Luca Murru; Maria Passafaro; Emilio Hirsch; Giorgio R Merlo
Journal:  Sci Rep       Date:  2018-05-08       Impact factor: 4.379

6.  Brain size reductions associated with endothelin B receptor mutation, a cause of Hirschsprung's disease.

Authors:  Ko-Chin Chen; Zan-Min Song; Geoffrey D Croaker
Journal:  BMC Neurosci       Date:  2021-06-19       Impact factor: 3.288

  6 in total

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