| Literature DB >> 25565634 |
Sophie Vildy1, Julie Macher2, Claire Abasq-Thomas3, Catherine Le Rouzic-Dartoy4, Francis Brunelle5, Dominique Hamel-Teillac5, Franck Duteille6, Christophe Perret6, Pierre Perrot6, Elisabeth Cassagnau7, Anne Chauty-Frondas2, Helene Aubert1, Sébastien Barbarot1.
Abstract
IMPORTANCE: Congenital hemangiomas (CHs) are rare benign vascular tumors that differ from common infantile hemangiomas in that they grow in utero and are fully developed at birth. While ulceration is a common, predominantly benign complication in infantile hemangioma, little is known about the prognosis of ulcerated CH. However, it has been observed that ulcerated CH may be complicated by life-threatening bleeding episodes. OBSERVATIONS: We report 2 cases of ulcerated rapidly involuting congenital hemangiomas (RICH) that were complicated by life-threatening bleeding episodes in the neonatal period. In both cases, the CHs were fed by high-flow vessels and the ensuing massive bleeding was due to superficial vessel wall erosion induced by the ulceration. Both patients were successfully treated with intravascular embolization; one patient underwent additional hemostatic surgery. CONCLUSIONS AND RELEVANCE: These 2 cases highlight the importance of closely monitoring children with ulcerated CH because of the risk of severe bleeding. Embolization is the treatment of choice in the case of severe bleeding, as the natural history of RICH is to spontaneously regress.Entities:
Mesh:
Year: 2015 PMID: 25565634 DOI: 10.1001/jamadermatol.2014.3666
Source DB: PubMed Journal: JAMA Dermatol ISSN: 2168-6068 Impact factor: 10.282