| Literature DB >> 25542977 |
Christian Geis1, Christian Ritter2, Christoph Ruschil2, Andreas Weishaupt2, Benedikt Grünewald3, Guido Stoll2, Trygve Holmoy4, Tatsuro Misu5, Kazuo Fujihara5, Bernhard Hemmer6, Christine Stadelmann7, Jeffrey L Bennett8, Claudia Sommer2, Klaus V Toyka2.
Abstract
Neuromyelitis optica (NMO) is causally linked to autoantibodies (ABs) against aquaporin 4 (AQP4). Here, we focused on the pathogenic effects exclusively mediated by human ABs to AQP4 in vivo. We performed cell-free intrathecal (i.th.) passive transfer experiments in Lewis rats using purified patient NMO immunoglobulin G (IgG) and various recombinant human anti-AQP4 IgG-ABs via implanted i.th. catheters. Repetitive application of patient NMO IgG fractions and of recombinant human anti-AQP4 ABs induced signs of spinal cord disease. Magnetic resonance imaging (MRI) revealed longitudinal spinal cord lesions at the site of application of anti-AQP4 IgG. Somatosensory evoked potential amplitudes were reduced in symptomatic animals corroborating the observed functional impairment. Spinal cord histology showed specific IgG deposition in the grey and white matter in the affected areas. We did not find inflammatory cell infiltration nor activation of complement in spinal cord areas of immunoglobulin deposition. Moreover, destructive lesions showing axon or myelin damage and loss of astrocytes and oligodendrocytes were all absent. Immunoreactivity to AQP4 and to the excitatory amino acid transporter 2 (EAAT2) was markedly reduced whereas immunoreactivity to the astrocytic marker glial fibrillary acid protein (GFAP) was preserved. The expression of the NMDA-receptor NR1 subunit was downregulated in areas of IgG deposition possibly induced by sustained glutamatergic overexcitation. Disease signs and histopathology were reversible within weeks after stopping injections. We conclude that in vivo application of ABs directed at AQP 4 can induce a reversible spinal cord disease in recipient rats by inducing distinct histopathological abnormalities. These findings may be the experimental correlate of "penumbra-like" lesions recently reported in NMO patients adjacent to effector-mediated tissue damage.Entities:
Keywords: Aquaporin 4; Astrocyte; EAAT2; Intrathecal passive transfer; NMDA receptor; Neuromyelitis optica
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Year: 2014 PMID: 25542977 PMCID: PMC4382207 DOI: 10.1016/j.expneurol.2014.12.015
Source DB: PubMed Journal: Exp Neurol ISSN: 0014-4886 Impact factor: 5.330