| Literature DB >> 25500575 |
Rachel Straussberg1, Esther Ganelin-Cohen2, Hadassah Goldberg-Stern3, Shay Tzur4, Doron M Behar5, Pola Smirin-Yosef6, Mali Salmon-Divon7, Lina Basel-Vanagaite8.
Abstract
We describe two siblings born to consanguineous Arab-Muslim parents who presented in early infancy with myoclonic seizures, hypertonia and contractures, arrested head growth, inability to swallow, and bouts of apnea-bradycardia, culminating in cardiac arrest and death. Whole-genome sequencing yielded a c.1173delG mutation in the BRAT1 gene. Three recent reports identified mutations in the same gene in three infants from three Amish sibships, one Mexican neonate and two Japanese siblings with similar clinical manifestations. The authors speculated that the destabilization of the encoded protein may underlie the catastrophic epilepsy and corticobasal neuronal degeneration. We suggest that BRAT1 be added to the growing list of genes that are related to severe early infantile (neonatal) epileptic encephalopathy.Entities:
Keywords: Apnea; Bradycardia; Epilepsy; Hypertonicity; Infancy; Seizures
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Year: 2014 PMID: 25500575 DOI: 10.1016/j.ejpn.2014.11.004
Source DB: PubMed Journal: Eur J Paediatr Neurol ISSN: 1090-3798 Impact factor: 3.140