Literature DB >> 2536938

A major insertion accounts for a significant proportion of mutations underlying human lipoprotein lipase deficiency.

S Langlois1, S Deeb, J D Brunzell, J J Kastelein, M R Hayden.   

Abstract

Lipoprotein lipase (LPL; triacylglyceroprotein acylhydrolase, EC 3.1.1.34) is an important enzyme involved in triacylglycerol metabolism. Primary LPL deficiency is a genetic disorder that is usually manifested by a severe elevation in triacylglycerol levels. We have used a recently isolated LPL cDNA clone to study 15 probands from 11 families with this inherited disorder. Surprisingly, 7 of the probands from 4 families, of different ancestries, had a similar insertion in their LPL gene. In contrast to other human genetic disorders, where insertions are rare causes of mutation, this insertion accounts for a significant proportion of the alleles causing LPL deficiency. Detailed restriction mapping of the insertion revealed that it was unlikely to be a duplication of neighboring DNA and that it was not similar to the consensus sequence of human L1 repetitive elements. This suggests that there must be other mechanisms of insertional mutagenesis in human genetic disease besides transposition of mobile L1 repetitive elements.

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Year:  1989        PMID: 2536938      PMCID: PMC286596          DOI: 10.1073/pnas.86.3.948

Source DB:  PubMed          Journal:  Proc Natl Acad Sci U S A        ISSN: 0027-8424            Impact factor:   11.205


  23 in total

1.  Preferential deletion of exons in Duchenne and Becker muscular dystrophies.

Authors:  S M Forrest; G S Cross; A Speer; D Gardner-Medwin; J Burn; K E Davies
Journal:  Nature       Date:  1987 Oct 15-21       Impact factor: 49.962

2.  Human adipose tissue lipoprotein lipase: changes with feeding and relation to postheparin plasma enzyme.

Authors:  P H Iverius; J D Brunzell
Journal:  Am J Physiol       Date:  1985-07

Review 3.  Molecular genetics of hemophilia A in man (factor VIII deficiency).

Authors:  S E Antonarakis; H Youssoufian; H H Kazazian
Journal:  Mol Biol Med       Date:  1987-04

4.  Molecular cloning and sequence of a cDNA coding for bovine lipoprotein lipase.

Authors:  M Senda; K Oka; W V Brown; P K Qasba; Y Furuichi
Journal:  Proc Natl Acad Sci U S A       Date:  1987-07       Impact factor: 11.205

5.  DNA polymorphisms in and around the Apo-A1-CIII genes and genetic hyperlipidemias.

Authors:  M R Hayden; H Kirk; C Clark; J Frohlich; S Rabkin; R McLeod; J Hewitt
Journal:  Am J Hum Genet       Date:  1987-05       Impact factor: 11.025

6.  Two polymorphisms in the human lipoprotein lipase (LPL) gene.

Authors:  K L Fisher; G A FitzGerald; R M Lawn
Journal:  Nucleic Acids Res       Date:  1987-09-25       Impact factor: 16.971

7.  Direct detection of more than 50% of the Duchenne muscular dystrophy mutations by field inversion gels.

Authors:  J T den Dunnen; E Bakker; E G Breteler; P L Pearson; G J van Ommen
Journal:  Nature       Date:  1987 Oct 15-21       Impact factor: 49.962

Review 8.  Insertional mutagenesis of the Drosophila genome with single P elements.

Authors:  L Cooley; R Kelley; A Spradling
Journal:  Science       Date:  1988-03-04       Impact factor: 47.728

9.  Hind III RFLP in the lipoprotein lipase gene, (LPL).

Authors:  H Funke; J Klug; G Assmann
Journal:  Nucleic Acids Res       Date:  1987-11-11       Impact factor: 16.971

10.  Origin of the human L1 elements: proposed progenitor genes deduced from a consensus DNA sequence.

Authors:  A F Scott; B J Schmeckpeper; M Abdelrazik; C T Comey; B O'Hara; J P Rossiter; T Cooley; P Heath; K D Smith; L Margolet
Journal:  Genomics       Date:  1987-10       Impact factor: 5.736

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  21 in total

Review 1.  Genetic basis of lipoprotein disorders.

Authors:  J L Breslow
Journal:  J Clin Invest       Date:  1989-08       Impact factor: 14.808

2.  Lipoprotein lipase deficiency resulting from a nonsense mutation in exon 3 of the lipoprotein lipase gene.

Authors:  M Emi; A Hata; M Robertson; P H Iverius; R Hegele; J M Lalouel
Journal:  Am J Hum Genet       Date:  1990-07       Impact factor: 11.025

3.  The genetic aspects of atherosclerosis and hyperlipidemia.

Authors:  M R Hayden
Journal:  CMAJ       Date:  1989-07-15       Impact factor: 8.262

4.  Lipoprotein lipaseBethesda: a single amino acid substitution (Ala-176----Thr) leads to abnormal heparin binding and loss of enzymic activity.

Authors:  O U Beg; M S Meng; S I Skarlatos; L Previato; J D Brunzell; H B Brewer; S S Fojo
Journal:  Proc Natl Acad Sci U S A       Date:  1990-05       Impact factor: 11.205

5.  Phenotypic expression of heterozygous lipoprotein lipase deficiency in the extended pedigree of a proband homozygous for a missense mutation.

Authors:  D E Wilson; M Emi; P H Iverius; A Hata; L L Wu; E Hillas; R R Williams; J M Lalouel
Journal:  J Clin Invest       Date:  1990-09       Impact factor: 14.808

6.  DNA polymorphism haplotypes of the human lipoprotein lipase gene: possible association with high density lipoprotein levels.

Authors:  C Heizmann; T Kirchgessner; P O Kwiterovich; J A Ladias; C Derby; S E Antonarakis; A J Lusis
Journal:  Hum Genet       Date:  1991-04       Impact factor: 4.132

7.  Amino acid substitution (Ile194----Thr) in exon 5 of the lipoprotein lipase gene causes lipoprotein lipase deficiency in three unrelated probands. Support for a multicentric origin.

Authors:  H E Henderson; Y Ma; M F Hassan; M V Monsalve; A D Marais; F Winkler; K Gubernator; J Peterson; J D Brunzell; M R Hayden
Journal:  J Clin Invest       Date:  1991-06       Impact factor: 14.808

8.  No prescription for despair.

Authors:  A Robinson
Journal:  CMAJ       Date:  1993-09-01       Impact factor: 8.262

9.  Partial gene duplication involving exon-Alu interchange results in lipoprotein lipase deficiency.

Authors:  R H Devlin; S Deeb; J Brunzell; M R Hayden
Journal:  Am J Hum Genet       Date:  1990-01       Impact factor: 11.025

10.  Heterogeneous mutations in the human lipoprotein lipase gene in patients with familial lipoprotein lipase deficiency.

Authors:  T Gotoda; N Yamada; M Kawamura; K Kozaki; N Mori; S Ishibashi; H Shimano; F Takaku; Y Yazaki; Y Furuichi; T Murase
Journal:  J Clin Invest       Date:  1991-12       Impact factor: 14.808

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