Literature DB >> 25366522

Familial hypomagnesemia with hypercalciuria and nephrocalcinosis: variable phenotypic expression in three affected sisters from Mexican ancestry.

María E Arteaga1, Walter Hunziker, Audrey S M Teo, Axel M Hillmer, Osvaldo M Mutchinick.   

Abstract

Familial hypomagnesemia with hypercalciuria and nephrocalcinosis is a rare autosomal recessive renal disease caused by mutations in genes for the tight junction transmembrane proteins Claudin-16 (CLDN16) and Claudin-19 (CLDN19). We present the first case report of a Mexican family with three affected sisters carrying a p.Gly20Asp mutation in CLDN19 whose heterozygous mother showed evident hypercalciuria and normal low magnesemia without any other clinical, laboratory, and radiological symptoms of renal disease making of her an unsuitable donor. The affected sisters showed variable phenotypic expression including age of first symptoms, renal urinary tract infections, nephrolithiasis, nephrocalcinosis, and eye symptoms consisting in retinochoroiditis, strabismus, macular scars, bilateral anisocoria, and severe myopia and astigmatism. End stage renal disease due to renal failure needed kidney transplantation in the three of them. Interesting findings were a heterozygous mother with asymptomatic hypercalciuria warning on the need of carefully explore clinical, laboratory, kidney ultrasonograpy, and mutation status in first degree asymptomatic relatives to avoid inappropriate kidney donors; an evident variable phenotypic expression among patients; the identification of a mutation almost confined to Spanish cases and a 3.5 Mb block of genomic homozygosis strongly suggesting a common remote parental ancestor for the gene mutation reported.

Entities:  

Keywords:  CLDN19 mutation; FHHNC; variable phenotypic expression

Mesh:

Substances:

Year:  2014        PMID: 25366522     DOI: 10.3109/0886022X.2014.977141

Source DB:  PubMed          Journal:  Ren Fail        ISSN: 0886-022X            Impact factor:   2.606


  8 in total

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2.  Recurrent urinary tract infection and nephrocalcinosis: Answers.

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Journal:  Pediatr Nephrol       Date:  2020-06-23       Impact factor: 3.714

Review 3.  The genetics of kidney stone disease and nephrocalcinosis.

Authors:  Prince Singh; Peter C Harris; David J Sas; John C Lieske
Journal:  Nat Rev Nephrol       Date:  2021-12-14       Impact factor: 28.314

Review 4.  Familial hypomagnesemia with hypercalciuria and nephrocalcinosis.

Authors:  Mònica Vall-Palomar; Leire Madariaga; Gema Ariceta
Journal:  Pediatr Nephrol       Date:  2021-02-17       Impact factor: 3.714

5.  Heterogeneity is a common ground in familial hypomagnesemia with hypercalciuria and nephrocalcinosis caused by CLDN19 gene mutations.

Authors:  Mònica Vall-Palomar; Carla Burballa; Félix Claverie-Martín; Anna Meseguer; Gema Ariceta
Journal:  J Nephrol       Date:  2021-04-30       Impact factor: 3.902

Review 6.  Claudins in Renal Physiology and Pathology.

Authors:  Caroline Prot-Bertoye; Pascal Houillier
Journal:  Genes (Basel)       Date:  2020-03-10       Impact factor: 4.096

7.  Familial hypomagnesaemia with hypercalciuria and nephrocalcinosis: clinical and molecular characteristics.

Authors:  Felix Claverie-Martin
Journal:  Clin Kidney J       Date:  2015-09-01

8.  Establishment of urinary exosome-like vesicles isolation protocol for FHHNC patients and evaluation of different exosomal RNA extraction methods.

Authors:  M Vall-Palomar; J Arévalo; G Ariceta; A Meseguer
Journal:  J Transl Med       Date:  2018-10-11       Impact factor: 5.531

  8 in total

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