Literature DB >> 25315683

Seizure-dependent mTOR activation in 5-HT neurons promotes autism-like behaviors in mice.

John J McMahon1, Wilson Yu1, Jun Yang2, Haihua Feng1, Meghan Helm1, Elizabeth McMahon1, Xinjun Zhu2, Damian Shin1, Yunfei Huang3.   

Abstract

Epilepsy and autism spectrum disorder (ASD) are common comorbidities of one another. Despite the prevalent correlation between the two disorders, few studies have been able to elucidate a mechanistic link. We demonstrate that forebrain specific Tsc1 deletion in mice causes epilepsy and autism-like behaviors, concomitant with disruption of 5-HT neurotransmission. We find that epileptiform activity propagates to the raphe nuclei, resulting in seizure-dependent hyperactivation of mTOR in 5-HT neurons. To dissect whether mTOR hyperactivity in 5-HT neurons alone was sufficient to recapitulate an autism-like phenotype we utilized Tsc1flox/flox;Slc6a4-cre mice, in which mTOR is restrictively hyperactivated in 5-HT neurons. Tsc1flox/flox;Slc6a4-cre mice displayed alterations of the 5-HT system and autism-like behaviors, without causing epilepsy. Rapamycin treatment in these mice was sufficient to rescue the phenotype. We conclude that the spread of seizure activity to the brainstem is capable of promoting hyperactivation of mTOR in the raphe nuclei, which in turn promotes autism-like behaviors. Thus our study provides a novel mechanism describing how epilepsy can contribute to the development of autism-like behaviors, suggesting new therapeutic strategies for autism.
Copyright © 2015 Elsevier Inc. All rights reserved.

Entities:  

Keywords:  5-HT; Autism; Epilepsy; TSC; mTOR

Mesh:

Substances:

Year:  2014        PMID: 25315683      PMCID: PMC4394017          DOI: 10.1016/j.nbd.2014.10.004

Source DB:  PubMed          Journal:  Neurobiol Dis        ISSN: 0969-9961            Impact factor:   5.996


  57 in total

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Review 5.  Current Approaches and Future Directions for the Treatment of mTORopathies.

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Review 6.  Cellular and Circuitry Bases of Autism: Lessons Learned from the Temporospatial Manipulation of Autism Genes in the Brain.

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