| Literature DB >> 25217881 |
Stephan Borte1, Anders Fasth2, Ulrika von Döbeln3, Jacek Winiarski4, Lennart Hammarström5.
Abstract
The lack or marked reduction of recently formed T and B cells provides a basis for neonatal screening for severe combined immunodeficiencies (SCID) and X-linked agammaglobulinemia (XLA). Newborns with other conditions are also identified if a severe T or B cell lymphopenia is present at birth. We retrospectively analyzed Guthrie card samples from 11 children with Wiskott-Aldrich syndrome (WAS), a rare disease that requires early diagnosis and treatment, to determine whether combined T-cell receptor excision circle (TREC) and kappa-deleting recombination excision circle (KREC) screening could identify these patients. 4 of 11 patients showed markedly reduced TREC or KREC copy numbers in their DBS as compared to storage-time matched controls and prospectively screened Swedish and German newborns. No correlation was observed between the WAS gene mutations, the clinical severity/course and the result of the screening assay. A diagnosis of WAS should thus be considered in newborns with positive TREC or KREC screening results.Entities:
Keywords: Kappa-deleting recombination excision circles;; Newborn screening;; Severe combined immunodeficiency; T cell receptor excision circles;; Wiskott–Aldrich syndrome;
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Year: 2014 PMID: 25217881 DOI: 10.1016/j.clim.2014.09.003
Source DB: PubMed Journal: Clin Immunol ISSN: 1521-6616 Impact factor: 3.969