Literature DB >> 25145510

Familial hypercholesterolemia: developments in diagnosis and treatment.

Gerald Klose1, Ulrich Laufs2, Winfried März3, Eberhard Windler4.   

Abstract

BACKGROUND: Familial hypercholesterolemia (FH) is a congenital disorder of lipid metabolism characterized by a marked elevation of the plasma concentration of LDL (low-density lipoprotein) cholesterol beginning in childhood and by the early onset of coronary heart disease. It is among the commonest genetic disorders, with an estimated prevalence in Germany of at least 1 per 500 persons.
METHOD: Review of pertinent literature retrieved by a selective search.
RESULTS: FH is underdiagnosed and undertreated in Germany. It is clinically diagnosed on the basis of an elevated LDL cholesterol concentration (>190 mg/dL [4.9 mmol/L]), a family history of hypercholesterolemia, and early coronary heart disease, or the demonstration of xanthomas. The gold standard of diagnosis is the identification of the underlying genetic defect, which is possible in 80% of cases and enables the identification of affected relatives of the index patient. The recommended goals of treatment, based on the results of observational studies, are to lower the LDL cholesterol concentration by at least 50% or to less than 100 mg/dL (2.6 mmol/L) (for children: <135 mg/dL [3.5 mmol/L]). The target value is lower for patients with clinically overt atherosclerosis (<70 mg/dL [1.8 mmol/L]). Statins, combined with a health-promoting lifestyle, are the treatment of choice. Lipoprotein apheresis is used in very severe cases; its therapeutic effects on clinical endpoints and its side effect profile have not yet been documented in randomized controlled trials.
CONCLUSION: Familial hypercholesterolemia is a common disease that can be diagnosed simply and reliably on clinical grounds and by molecular genetic testing. Timely diagnosis and appropriate treatment can lower the risk of atherosclerosis in heterozygous patients to that of the general population.

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Year:  2014        PMID: 25145510      PMCID: PMC4148715          DOI: 10.3238/arztebl.2014.0523

Source DB:  PubMed          Journal:  Dtsch Arztebl Int        ISSN: 1866-0452            Impact factor:   5.594


  79 in total

1.  Impact of statin treatment on the clinical fate of heterozygous familial hypercholesterolemia.

Authors:  Mariko Harada-Shiba; Takako Sugisawa; Hisashi Makino; Mitsuru Abe; Motoo Tsushima; Yasunao Yoshimasa; Takahiro Yamashita; Yoshihiro Miyamoto; Akira Yamamoto; Hitonobu Tomoike; Shinji Yokoyama
Journal:  J Atheroscler Thromb       Date:  2010-06-04       Impact factor: 4.928

2.  Cholesterol deposition around small joints of the hands in familial hypercholesterolemia mimicking "Bouchard's and Heberden's nodes" of osteoarthritis.

Authors:  Eman Alfadhli
Journal:  Intern Med       Date:  2010-08-02       Impact factor: 1.271

Review 3.  Statins for children with familial hypercholesterolemia.

Authors:  Alpo Vuorio; Jaana Kuoppala; Petri T Kovanen; Steve E Humphries; Timo Strandberg; Serena Tonstad; Helena Gylling
Journal:  Cochrane Database Syst Rev       Date:  2010-07-07

4.  Effect of a monoclonal antibody to PCSK9, REGN727/SAR236553, to reduce low-density lipoprotein cholesterol in patients with heterozygous familial hypercholesterolaemia on stable statin dose with or without ezetimibe therapy: a phase 2 randomised controlled trial.

Authors:  Evan A Stein; Dan Gipe; Jean Bergeron; Daniel Gaudet; Robert Weiss; Robert Dufour; Richard Wu; Robert Pordy
Journal:  Lancet       Date:  2012-05-26       Impact factor: 79.321

Review 5.  Lipoprotein apheresis: state of the art and novelties.

Authors:  C Stefanutti; U Julius
Journal:  Atheroscler Suppl       Date:  2013-01       Impact factor: 3.235

6.  Regulation of 3-hydroxy-3-methylglutaryl coenzyme A reductase activity in cultured human fibroblasts. Comparison of cells from a normal subject and from a patient with homozygous familial hypercholesterolemia.

Authors:  M S Brown; S E Dana; J L Goldstein
Journal:  J Biol Chem       Date:  1974-02-10       Impact factor: 5.157

7.  Homozygous familial hypercholesterolemia among French Canadians in Québec Province.

Authors:  S Moorjani; M Roy; C Gagné; J Davignon; D Brun; M Toussaint; M Lambert; L Campeau; S Blaichman; P Lupien
Journal:  Arteriosclerosis       Date:  1989 Mar-Apr

8.  Efficacy and safety of a microsomal triglyceride transfer protein inhibitor in patients with homozygous familial hypercholesterolaemia: a single-arm, open-label, phase 3 study.

Authors:  Marina Cuchel; Emma A Meagher; Hendrik du Toit Theron; Dirk J Blom; A David Marais; Robert A Hegele; Maurizio R Averna; Cesare R Sirtori; Prediman K Shah; Daniel Gaudet; Claudia Stefanutti; Giovanni B Vigna; Anna M E Du Plessis; Kathleen J Propert; William J Sasiela; LeAnne T Bloedon; Daniel J Rader
Journal:  Lancet       Date:  2012-11-02       Impact factor: 79.321

9.  Estimation of the prevalence of familial hypercholesterolaemia in a rural Afrikaner community by direct screening for three Afrikaner founder low density lipoprotein receptor gene mutations.

Authors:  K Steyn; Y P Goldberg; M J Kotze; M Steyn; A S Swanepoel; J M Fourie; G A Coetzee; D R Van der Westhuyzen
Journal:  Hum Genet       Date:  1996-10       Impact factor: 4.132

10.  Familial hypercholesterolaemia: a pressing issue for European health care.

Authors:  Philippa Brice; Hilary Burton; Christopher W Edwards; Steve E Humphries; Timothy J Aitman
Journal:  Atherosclerosis       Date:  2013-10-02       Impact factor: 5.162

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  14 in total

1.  Low-fat diet and exercise are more important.

Authors:  Peter Pommer
Journal:  Dtsch Arztebl Int       Date:  2015-03-13       Impact factor: 5.594

2.  Low-fat diet and exercise are more important. In reply.

Authors:  Gerald Klose; Ulrich Laufs; Winfried März; Eberhard Windler
Journal:  Dtsch Arztebl Int       Date:  2015-03-13       Impact factor: 5.594

Review 3.  [Congenital disorders of lipoprotein metabolism].

Authors:  W März; T B Grammer; G Delgado; M E Kleber
Journal:  Herz       Date:  2017-08       Impact factor: 1.443

Review 4.  [Dyslipidemias : Diagnostics and management].

Authors:  D Sinning; U Landmesser
Journal:  Herz       Date:  2017-09       Impact factor: 1.443

Review 5.  [Introduction of PCSK9 inhibitors : New perspectives in treatment and practical implementation].

Authors:  G Klose
Journal:  Herz       Date:  2016-06       Impact factor: 1.443

Review 6.  [PCSK9 inhibitors : Recommendations for patient selection].

Authors:  U Laufs; F Custodis; C Werner
Journal:  Herz       Date:  2016-06       Impact factor: 1.443

7.  Treatment Preferences in Germany Differ Among Apheresis Patients with Severe Hypercholesterolemia.

Authors:  Axel C Mühlbacher; Andrew Sadler; Franz-Werner Dippel; Christin Juhnke
Journal:  Pharmacoeconomics       Date:  2018-04       Impact factor: 4.981

Review 8.  Tendon Pathology in Hypercholesterolemia and Familial Hypercholesterolemia.

Authors:  Brittany Taylor; Adnan Cheema; Louis Soslowsky
Journal:  Curr Rheumatol Rep       Date:  2017-11-04       Impact factor: 4.592

9.  Developing implementation strategies to improve uptake of guideline-recommended treatments for individuals with familial hypercholesterolemia: A protocol.

Authors:  Laney K Jones; Samuel S Gidding; Terry L Seaton; Anne Goldberg; Christina Gregor; Amy C Sturm; Ross C Brownson; Alanna Kulchak Rahm; Marc S Williams
Journal:  Res Social Adm Pharm       Date:  2019-06-15

10.  Prevalence of high-risk cardiovascular patients with therapy-resistant hypercholesterolemia.

Authors:  Karel Kostev; Klaus G Parhofer; Franz-Werner Dippel
Journal:  Cardiovasc Endocrinol       Date:  2016-10-14
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