Literature DB >> 24832020

Mutation screening of the neurexin 1 gene in thai patients with intellectual disability and autism spectrum disorder.

Supaporn Yangngam1, Oradawan Plong-On, Thanya Sripo, Rawiwan Roongpraiwan, Tippawan Hansakunachai, Juthamas Wirojanan, Tasnawat Sombuntham, Nichara Ruangdaraganon, Pornprot Limprasert.   

Abstract

AIM: Neurexin 1 has two major protein isoforms using alternative promoters, coding for the alpha-neurexin 1 (α-NRXN1) and beta-neurexin 1 (β-NRXN1) genes. This study is to explore the possibility that variants of the NRXN1 gene predispose to intellectual disability (ID) and autism spectrum disorder (ASD).
METHODS: The coding regions in 24 exons and exon-intron boundaries of the NRXN1 gene were investigated in 115 Thai patients with ID and ASD by direct DNA sequencing.
RESULTS: Nine novel variants of the NRXN1 gene were identified. Four novel variants were found in the β-NRXN1 gene, one variant of six GGC repeats in exon 1, and three variants at the 5'UTR. Five novel variants were identified in the α-NRXN1 gene, four intronic variants and one missense variant in exon 14 (c.2713T>A or p.F905I).
CONCLUSION: Mutation screening of the NRXN1gene in patients with ID and ASD may be useful to identify potential variants predisposing to ID and ASD. However, further studies utilizing protein functional analysis of the novel variants are required for a more definite conclusion.

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Year:  2014        PMID: 24832020      PMCID: PMC4094023          DOI: 10.1089/gtmb.2014.0003

Source DB:  PubMed          Journal:  Genet Test Mol Biomarkers        ISSN: 1945-0257


  21 in total

1.  Mutations of the X-linked genes encoding neuroligins NLGN3 and NLGN4 are associated with autism.

Authors:  Stéphane Jamain; Hélène Quach; Catalina Betancur; Maria Råstam; Catherine Colineaux; I Carina Gillberg; Henrik Soderstrom; Bruno Giros; Marion Leboyer; Christopher Gillberg; Thomas Bourgeron
Journal:  Nat Genet       Date:  2003-05       Impact factor: 38.330

2.  High frequency of neurexin 1beta signal peptide structural variants in patients with autism.

Authors:  Jinong Feng; Richard Schroer; Jin Yan; Wenjia Song; Chunmei Yang; Anke Bockholt; Edwin H Cook; Cindy Skinner; Charles E Schwartz; Steve S Sommer
Journal:  Neurosci Lett       Date:  2006-10-10       Impact factor: 3.046

3.  Screening of NLGN3 and NLGN4X genes in Thai children with autism spectrum disorder.

Authors:  Anna Mikhailov; Alanna Fennell; Oradawan Plong-on; Thanya Sripo; Tippawan Hansakunachai; Rawiwan Roongpraiwan; Tasnawat Sombuntham; Nichara Ruangdaraganon; John B Vincent; Pornprot Limprasert
Journal:  Psychiatr Genet       Date:  2014-02       Impact factor: 2.458

4.  Neurexin 1alpha structural variants associated with autism.

Authors:  Jin Yan; Katie Noltner; Jinong Feng; Wenyan Li; Richard Schroer; Cindy Skinner; Wenqi Zeng; Charles E Schwartz; Steve S Sommer
Journal:  Neurosci Lett       Date:  2008-04-25       Impact factor: 3.046

Review 5.  Consensus statement: chromosomal microarray is a first-tier clinical diagnostic test for individuals with developmental disabilities or congenital anomalies.

Authors:  David T Miller; Margaret P Adam; Swaroop Aradhya; Leslie G Biesecker; Arthur R Brothman; Nigel P Carter; Deanna M Church; John A Crolla; Evan E Eichler; Charles J Epstein; W Andrew Faucett; Lars Feuk; Jan M Friedman; Ada Hamosh; Laird Jackson; Erin B Kaminsky; Klaas Kok; Ian D Krantz; Robert M Kuhn; Charles Lee; James M Ostell; Carla Rosenberg; Stephen W Scherer; Nancy B Spinner; Dimitri J Stavropoulos; James H Tepperberg; Erik C Thorland; Joris R Vermeesch; Darrel J Waggoner; Michael S Watson; Christa Lese Martin; David H Ledbetter
Journal:  Am J Hum Genet       Date:  2010-05-14       Impact factor: 11.025

6.  Analysis of the human neurexin genes: alternative splicing and the generation of protein diversity.

Authors:  Lee Rowen; Janet Young; Brian Birditt; Amardeep Kaur; Anup Madan; Dana L Philipps; Shizhen Qin; Patrick Minx; Richard K Wilson; Leroy Hood; Brenton R Graveley
Journal:  Genomics       Date:  2002-04       Impact factor: 5.736

7.  Effect of GGC (glycine) repeat length polymorphism in the human androgen receptor on androgen action.

Authors:  Dacheng Ding; Lihua Xu; Mani Menon; G Prem Veer Reddy; Evelyn R Barrack
Journal:  Prostate       Date:  2005-02-01       Impact factor: 4.104

8.  CNTNAP2 and NRXN1 are mutated in autosomal-recessive Pitt-Hopkins-like mental retardation and determine the level of a common synaptic protein in Drosophila.

Authors:  Christiane Zweier; Eiko K de Jong; Markus Zweier; Alfredo Orrico; Lilian B Ousager; Amanda L Collins; Emilia K Bijlsma; Merel A W Oortveld; Arif B Ekici; André Reis; Annette Schenck; Anita Rauch
Journal:  Am J Hum Genet       Date:  2009-11-05       Impact factor: 11.025

9.  Disruption of neurexin 1 associated with autism spectrum disorder.

Authors:  Hyung-Goo Kim; Shotaro Kishikawa; Anne W Higgins; Ihn-Sik Seong; Diana J Donovan; Yiping Shen; Eric Lally; Lauren A Weiss; Juliane Najm; Kerstin Kutsche; Maria Descartes; Lynn Holt; Stephen Braddock; Robin Troxell; Lee Kaplan; Fred Volkmar; Ami Klin; Katherine Tsatsanis; David J Harris; Ilse Noens; David L Pauls; Mark J Daly; Marcy E MacDonald; Cynthia C Morton; Bradley J Quade; James F Gusella
Journal:  Am J Hum Genet       Date:  2008-01       Impact factor: 11.025

10.  X-linked mental retardation and autism are associated with a mutation in the NLGN4 gene, a member of the neuroligin family.

Authors:  Frédéric Laumonnier; Frédérique Bonnet-Brilhault; Marie Gomot; Romuald Blanc; Albert David; Marie-Pierre Moizard; Martine Raynaud; Nathalie Ronce; Eric Lemonnier; Patrick Calvas; Béatrice Laudier; Jamel Chelly; Jean-Pierre Fryns; Hans-Hilger Ropers; Ben C J Hamel; Christian Andres; Catherine Barthélémy; Claude Moraine; Sylvain Briault
Journal:  Am J Hum Genet       Date:  2004-02-12       Impact factor: 11.025

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  6 in total

1.  Hippocampal Transcriptomic and Proteomic Alterations in the BTBR Mouse Model of Autism Spectrum Disorder.

Authors:  Caitlin M Daimon; Joan M Jasien; William H Wood; Yongqing Zhang; Kevin G Becker; Jill L Silverman; Jacqueline N Crawley; Bronwen Martin; Stuart Maudsley
Journal:  Front Physiol       Date:  2015-11-24       Impact factor: 4.566

2.  Shedding of neurexin 3β ectodomain by ADAM10 releases a soluble fragment that affects the development of newborn neurons.

Authors:  Erika Borcel; Magda Palczynska; Marine Krzisch; Mitko Dimitrov; Giorgio Ulrich; Nicolas Toni; Patrick C Fraering
Journal:  Sci Rep       Date:  2016-12-19       Impact factor: 4.379

Review 3.  Fundamental Elements in Autism: From Neurogenesis and Neurite Growth to Synaptic Plasticity.

Authors:  James Gilbert; Heng-Ye Man
Journal:  Front Cell Neurosci       Date:  2017-11-20       Impact factor: 5.505

4.  Significance of neurexin and neuroligin polymorphisms in regulating risk of Hirschsprung's disease.

Authors:  Yanhong Li; Hui Liu; Yubin Dong
Journal:  J Investig Med       Date:  2018-04-04       Impact factor: 2.895

5.  Screening for FMR1 CGG Repeat Expansion in Thai Patients with Autism Spectrum Disorder.

Authors:  Areerat Hnoonual; Charunee Jankittunpaiboon; Pornprot Limprasert
Journal:  Biomed Res Int       Date:  2021-12-08       Impact factor: 3.411

6.  A missense mutation in the CSTF2 gene that impairs the function of the RNA recognition motif and causes defects in 3' end processing is associated with intellectual disability in humans.

Authors:  Petar N Grozdanov; Elahe Masoumzadeh; Vera M Kalscheuer; Thierry Bienvenu; Pierre Billuart; Marie-Ange Delrue; Michael P Latham; Clinton C MacDonald
Journal:  Nucleic Acids Res       Date:  2020-09-25       Impact factor: 16.971

  6 in total

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