Literature DB >> 24746362

Novel α-synuclein mutation A53E associated with atypical multiple system atrophy and Parkinson's disease-type pathology.

Petra Pasanen1, Liisa Myllykangas2, Maija Siitonen3, Anna Raunio4, Seppo Kaakkola5, Jukka Lyytinen5, Pentti J Tienari6, Minna Pöyhönen7, Anders Paetau4.   

Abstract

We describe the clinical, neuropathological, and genetic features of a Finnish patient with a novel α-synuclein (SNCA) mutation A53E. The patient was clinically diagnosed with atypical Parkinson's disease (PD) with age of onset at 36 years. In the neuropathological analysis performed at the age of 60 years, highly abundant SNCA pathology was observed throughout the brain and spinal cord showing features of multiple system atrophy and PD. Neuronal and glial (including oligodendroglial) SNCA inclusions and neurites were found to be particularly prominent in the putamen, caudatus, amygdala, temporal and insular cortices, gyrus cinguli, and hippocampus CA2-3 region. These areas as well as the substantia nigra and locus coeruleus showed neuronal loss and gliosis. We also found TDP-43 positive but mostly SNCA negative perinuclear inclusions in the dentate fascia of the hippocampus. The A53E mutation was found in 2 other relatives who had parkinsonism. Our results suggest that the novel SNCA A53E substitution is a causative mutation resulting clinically in parkinsonism and pathologically in severe multiple system atrophy- and PD-type phenotype.
Copyright © 2014 Elsevier Inc. All rights reserved.

Entities:  

Keywords:  A53E; Genetics; Neuropathology; Parkinsonism; SNCA; Synucleinopathy

Mesh:

Substances:

Year:  2014        PMID: 24746362     DOI: 10.1016/j.neurobiolaging.2014.03.024

Source DB:  PubMed          Journal:  Neurobiol Aging        ISSN: 0197-4580            Impact factor:   4.673


  181 in total

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