Literature DB >> 24731791

Selective screening for inborn errors of metabolism by tandem mass spectrometry in Egyptian children: a 5 year report.

Laila A Selim1, Sawsan Abdel-Hady Hassan2, Fadia Salem3, Azza Orabi1, Fayza A Hassan4, Fatma El-Mougy4, Iman Gamal-Eldin Mahmoud5, Amira El-Badawy5, Marian Y Girgis1, Mohamed A Elmonem6, Dina Mehaney4.   

Abstract

OBJECTIVE: In order to enhance awareness and promote registry for inborn errors of metabolism (IEMs) in Egypt, we aimed to evaluate the prevalence and main clinical findings of IEMs detectable by tandem mass spectrometry (MS/MS) among high risk pediatric patients presenting to our tertiary care facility at Cairo University Children's Hospital over a period of 5 years and to compare the disease burden in Egypt in the absence of a national screening program for inherited metabolic disorders with other populations.
METHODS: During this period 3380 Egyptian children were suspected of having IEMs based on clinical/laboratory presentation and were analyzed by MS/MS. Confirmatory testing was performed according to flagged analyte by MS/MS using a different sample type such as plasma or urine or by a different technique such as GC/MS.
RESULTS: A relatively high number of patients (203/3380 (6%)) were confirmed with 17 different types of IEMs. Averages for age at diagnosis for different disorders ranged from 2.5 months to 6.6 years with general developmental delay and irreversible neurological damage being the most common presenting features (75.9% and 65.5%, respectively). Amino acid disorders (127/203 (62.6%)), mainly phenylketonuria (100/203 (49.3%)), were the most encountered, followed by organic acidemias (69/203 (34%)), while fatty acid oxidation defects (7/203 (3.4%)) were relatively rare. 88% of patients were born to consanguineous parents.
CONCLUSIONS: The development of a nationwide screening program for IEMs is mandatory for early detection of these potentially treatable disorders, prompt and properly timed therapeutic intervention and prevention of the devastating neurological outcomes.
Copyright © 2014 The Canadian Society of Clinical Chemists. Published by Elsevier Inc. All rights reserved.

Entities:  

Keywords:  Children; Inborn errors; Metabolic disorders; Selective screening; Tandem mass spectrometry

Mesh:

Substances:

Year:  2014        PMID: 24731791     DOI: 10.1016/j.clinbiochem.2014.04.002

Source DB:  PubMed          Journal:  Clin Biochem        ISSN: 0009-9120            Impact factor:   3.281


  10 in total

1.  Clinical and neurophysiological characterization of early neuromuscular involvement in children and adolescents with nephropathic cystinosis.

Authors:  Nour Elkhateeb; Rasha Selim; Neveen A Soliman; Fatma M Atia; Ihab Ibrahim Abouelwoun; Mohamed A Elmonem; Rasha Helmy
Journal:  Pediatr Nephrol       Date:  2021-11-18       Impact factor: 3.651

2.  Lysosomal Storage Disorders in Egyptian Children.

Authors:  Mohamed A Elmonem; Iman G Mahmoud; Dina A Mehaney; Sahar A Sharaf; Sawsan A Hassan; Azza Orabi; Fadia Salem; Marian Y Girgis; Amira El-Badawy; Magy Abdelwahab; Zeinab Salah; Neveen A Soliman; Fayza A Hassan; Laila A Selim
Journal:  Indian J Pediatr       Date:  2016-02-02       Impact factor: 1.967

Review 3.  Screening newborns for metabolic disorders based on targeted metabolomics using tandem mass spectrometry.

Authors:  Hye-Ran Yoon
Journal:  Ann Pediatr Endocrinol Metab       Date:  2015-09-30

4.  Demographic and clinical characteristics of the children with aminoacidopathy in Isfahan Province, Central Iran in 2007-2015.

Authors:  Reza Najafi; Mahin Hashemipour; Omid Yaghini; Fatemeh Najafi; Amirsalar Rashidianfar
Journal:  Indian J Endocrinol Metab       Date:  2016 Sep-Oct

5.  Metabolic screening and its impact in children with nonsyndromic intellectual disability.

Authors:  Yasser F Ali; Salah El-Morshedy; Riad M Elsayed; Amr M El-Sherbini; Saber Am El-Sayed; Nasser Ismail A Abdelrahman; Abdulbasit Abdulhalim Imam
Journal:  Neuropsychiatr Dis Treat       Date:  2017-04-19       Impact factor: 2.570

Review 6.  The Prevalence of Phenylketonuria in Arab Countries, Turkey, and Iran: A Systematic Review.

Authors:  Ashraf El-Metwally; Lujane Yousef Al-Ahaidib; Alaa Ayman Sunqurah; Khaled Al-Surimi; Mowafa Househ; Ali Alshehri; Omar B Da'ar; Hira Abdul Razzak; Ali Nasser AlOdaib
Journal:  Biomed Res Int       Date:  2018-04-18       Impact factor: 3.411

Review 7.  Global birth prevalence and mortality from inborn errors of metabolism: a systematic analysis of the evidence.

Authors:  Donald Waters; Davies Adeloye; Daisy Woolham; Elizabeth Wastnedge; Smruti Patel; Igor Rudan
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8.  Spectrum of mutations underlying Propionic acidemia and further insight into a genotype-phenotype correlation for the common mutation in Saudi Arabia.

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9.  Global prevalence of classic phenylketonuria based on Neonatal Screening Program Data: systematic review and meta-analysis.

Authors:  Hamid Reza Shoraka; Ali Akbar Haghdoost; Mohammad Reza Baneshi; Zohre Bagherinezhad; Farzaneh Zolala
Journal:  Clin Exp Pediatr       Date:  2020-02-06

10.  Clinical and biochemical spectrum of metabolic cardiomyopathy in Egyptian children.

Authors:  Zeinab Salah Seliem; Dina Ahmed Mehaney; Laila Abd Elmoteleb Selim; Sonia Ali El-Saiedi; Reem Ibrahim Ismail; Nihal Magdi Almenabawy; Rasha Ibrahim Ammar; Inas AbdElsattar Saad; Mohammed Mosad Soliman; Mohamed A Elmonem
Journal:  Afr Health Sci       Date:  2022-03       Impact factor: 1.108

  10 in total

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