| Literature DB >> 24284555 |
Gena Heidary1, Laurel Calderwood, Gerald F Cox, Caroline D Robson, Lisa A Teot, Jennifer Mullon, Irina Anselm.
Abstract
Combined oxidative phosphorylation deficiency type 7 (COXPD7) is a rare disorder of mitochondrial metabolism that results in optic atrophy and Leigh syndrome-like disease. We describe 2 siblings with compound heterozygous mutations in the recently identified C12orf65 gene who presented with optic atrophy and mild developmental delays and subsequently developed bilateral, symmetric lesions in the brainstem reminiscent of Leigh syndrome. Repeat neuroimaging demonstrated reversibility of the findings in 1 sibling and persistent metabolic stroke in the other. This article highlights the phenotypic manifestations from a novel mutation in the C12orf65 gene and reviews the clinical presentation of the 5 other individuals reported to date who carry mutations in this gene.Entities:
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Year: 2014 PMID: 24284555 DOI: 10.1097/WNO.0000000000000076
Source DB: PubMed Journal: J Neuroophthalmol ISSN: 1070-8022 Impact factor: 3.042