Literature DB >> 24179628

Rapunzel syndrome: A rare presentation with multiple small intestinal intussusceptions.

Bidarahalli Krishna Prasanna1, Kuppusamy Sasikumar, Uppinakudru Gurunandan, Gubbi Shamanna Sreenath, Vikram Kate.   

Abstract

Bezoars are usually confined to the stomach which is seen in individuals with psychiatric illness like trichotillomania, trichophagia and gastric dysmotility. Long standing bezoars may extend into the small intestine leading to a condition known as Rapunzel syndrome. Diagnosis can be established by endoscopy, ultrasonography and computed tomography scan. Treatment includes improvement of general condition and removal of bezoar by laparoscopic approach or laparotomy. Psychiatric consultation is necessary to treat and prevent relapse. We report a case of Rapunzel syndrome in a 16-year-old girl with trichotillomania. She presented with history of epigastric mass for three months and recent onset of pain abdomen, vomiting and early satiety. Skiagram of abdomen was showing distended stomach and endoscopy revealed trichobezoar. At laparotomy, stomach was distended with trichobezoar and there were multiple small intestinal intussusceptions. Gastrotomy and manual reduction of intussusceptions with the removal of trichobezoar with its tail was done. Patient recovered completely after the procedure.

Entities:  

Keywords:  Intussusception; Rapunzel syndrome; Trichobezoar; Trichotillomania

Year:  2013        PMID: 24179628      PMCID: PMC3812444          DOI: 10.4240/wjgs.v5.i10.282

Source DB:  PubMed          Journal:  World J Gastrointest Surg


  9 in total

1.  Untreated trichotillomania and trichophagia: surgical emergency in a teenage girl.

Authors:  Karriem Salaam; Joel Carr; Harsh Grewal; Ellen Sholevar; David Baron
Journal:  Psychosomatics       Date:  2005 Jul-Aug       Impact factor: 2.386

2.  [Rapunzel syndrome associated with small bowel intussusception, acute pancreatitis and bile duct dilatation].

Authors:  Bruno Godart; Marc Wangermez; Carole Doucet; Jean-Pierre Faure; Michel Beauchant
Journal:  Gastroenterol Clin Biol       Date:  2006-11

3.  Rapunzel syndrome: a case report and review of literature.

Authors:  R Harikumar; Simi Kumar; Bobby Kumar; V Balakrishnan
Journal:  Trop Gastroenterol       Date:  2007 Jan-Mar

4.  Trichobezoar can be treated laparoscopically.

Authors:  Guillermo Hernández-Peredo-Rezk; Pastor Escárcega-Fujigaki; Zoila Virginia Campillo-Ojeda; Maria Elena Sánchez-Martínez; Miguel A Rodríguez-Santibáñez; Alejandro Del Angel-Aguilar; Carlos Rodríguez-Gutiérrez
Journal:  J Laparoendosc Adv Surg Tech A       Date:  2009-02       Impact factor: 1.878

5.  The Rapunzel syndrome. An unusual complication of intestinal bezoar.

Authors:  E D Vaughan; J L Sawyers; H W Scott
Journal:  Surgery       Date:  1968-02       Impact factor: 3.982

6.  The fascinating history of bezoars.

Authors:  R S Williams
Journal:  Med J Aust       Date:  1986 Dec 1-15       Impact factor: 7.738

7.  Respiratory arrest due to airway obstruction following endoscopic removal of Trichobezoar.

Authors:  Mohammad Reza Haji Esmaili; Hamid Reza Abbasi; Mohammad Hosein Baradaranfar
Journal:  J Pak Med Assoc       Date:  2011-07       Impact factor: 0.781

8.  Endoscopic retrieval of a gastric trichobezoar.

Authors:  Hironori Konuma; Kuangi Fu; Takashi Morimoto; Takayoshi Shimizu; Yuko Izumi; Satoko Shiyanagi; Masahiko Urao; Akihisa Miyazaki; Sumio Watanabe
Journal:  World J Gastrointest Endosc       Date:  2011-01-16

9.  Laparoscopic intragastric removal of giant trichobezoar.

Authors:  Harry F Dorn; John L Gillick; Gustavo Stringel
Journal:  JSLS       Date:  2010 Apr-Jun       Impact factor: 2.172

  9 in total
  9 in total

1.  Gastric bezoar with small bowel obstruction.

Authors:  Ayvaz Ulaş Urgancı; Ebru Akıncılar
Journal:  Ulus Cerrahi Derg       Date:  2015-06-19

2.  Rapunzel syndrome presenting as jejuno-jejunal intussusception.

Authors:  Sanjay Marwah; Siddharth Pandey; Abhishek Raj; Mahavir Singh Jangra; Himanshu Sharma
Journal:  Clin J Gastroenterol       Date:  2015-06-25

3.  Rapunzel syndrome: a rare cause of hypoproteinaemia and review of literature.

Authors:  Waqas Ullah; Kaiser Saleem; Ejaz Ahmad; Faiz Anwer
Journal:  BMJ Case Rep       Date:  2016-09-26

4.  Trichophagia along with trichobezoar in the absence of trichotillomania.

Authors:  Aseem Mehra; Ajit Avasthi; Vikas Gupta; Sandeep Grover
Journal:  J Neurosci Rural Pract       Date:  2014-11

5.  Making sense of the role of sense organs in trichotillomania.

Authors:  Anil Kakunje; T S Sathyanarayana Rao
Journal:  Indian J Psychiatry       Date:  2017 Apr-Jun       Impact factor: 1.759

6.  Surgical outcome of jejunum-jejunum intussusception secondary to Rapunzel syndrome: a case report.

Authors:  Martín Adrián Bolívar-Rodríguez; Rodolfo Fierro-López; Adrián Pamanes-Lozano; Marcel Antonio Cazarez-Aguilar; Benny Alonso Osuna-Wong; José Cándido Ortiz-Bojórquez
Journal:  J Med Case Rep       Date:  2018-12-07

7.  Gastric trichobezoar: An uncommon cause of epigastric pain: A case report.

Authors:  Rahma Daoud; Ahmed Tlili; Sami Fendri; Amira Akrout; Aymen Trigui; Salah Boujelbene
Journal:  Clin Case Rep       Date:  2022-04-04

8.  An Unusual Case of Primary Ileal Trichobezoar Causing Intussusception.

Authors:  Mitchell M Won; Marla A Sacks; Rebekah Leigh; Yomara S Mendez; Laura F Goodman; Edward Tagge; Andrei Radulescu
Journal:  Am J Case Rep       Date:  2022-07-28

9.  Trichobezoar presenting as a gastric outlet obstruction: A case report.

Authors:  Eugene Nwankwo; Edward Daniele; Erin Woller; John Fitzwater; Thomas McGill; Steven E Brooks
Journal:  Int J Surg Case Rep       Date:  2017-03-16
  9 in total

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