Literature DB >> 23816439

Malignant arrhythmogenic right ventricular dysplasia/cardiomyopathy with a normal 12-lead electrocardiogram: a rare but underrecognized clinical entity.

Anneline S J M te Riele1, Cynthia A James, Aditya Bhonsale, Judith A Groeneweg, Christian F Camm, Brittney Murray, Crystal Tichnell, Jeroen F van der Heijden, Dennis Dooijes, Daniel P Judge, Richard N W Hauer, Harikrishna Tandri, Hugh Calkins.   

Abstract

BACKGROUND: In Arrhythmogenic Right Ventricular Dysplasia/Cardiomyopathy (ARVD/C), a normal electrocardiogram (ECG) is considered reassuring. However, some patients with ARVD/C experiencing ventricular arrhythmias have a normal ECG.
OBJECTIVES: To estimate how often patients with ARVD/C experiencing ventricular arrhythmias have a normal ECG during sinus rhythm, and to provide a clinical profile of these patients.
METHODS: We included 145 patients with ARVD/C experiencing a documented sustained ventricular arrhythmia. Conventional 12-lead sinus rhythm ECGs within 6 months of the event were reviewed for diagnostic Task Force Criteria (TFC). ECGs were classified as abnormal (≥1 TFC), nonspecific (abnormal, no TFC), or normal. Cardiologic investigations within 6 months of the event were evaluated as per TFC in those with a nonspecific or normal ECG.
RESULTS: The ECG was nonspecific or normal in 17 of 145 (12%) subjects. Mean age of these patients was 41.3 ± 12.4 years and 14 (82%) were men, comparable to those with an abnormal ECG. Most patients with a nonspecific or normal ECG showed ≥1 TFC on Holter monitoring (n = 9 of 10) and signal-averaged ECG (n = 4 of 5), and all had nonsustained ventricular tachycardia recorded. Among 15 patients who underwent structural evaluation, 11 (73%) showed structural TFC (9 major and 2 minor).
CONCLUSIONS: Although most patients with ARVD/C experiencing arrhythmias have an abnormal ECG, a nonspecific or normal ECG does not preclude ARVD/C diagnosis. All patients with a nonspecific or normal ECG had alternative evidence of disease expression. These results alert the physician not to rely exclusively on ECG in ARVD/C, but to assess arrhythmic risk by comprehensive clinical evaluation.
© 2013 Heart Rhythm Society. All rights reserved.

Entities:  

Keywords:  ARVD/C; Arrhythmogenic Right Ventricular Dysplasia/Cardiomyopathy; CMR; Cardiomyopathy; Concealed; Diagnosis; ECG; Electrocardiogram; PKP2; PVC; Plakophilin-2; RV; Risk stratification; SAECG; TAD; TFC; Task Force Criteria; VF; VT; Ventricular arrhythmias; cardiac magnetic resonance; electrocardiogram/electrocardiographic; premature ventricular complex; right ventricular; signal-averaged electrocardiogram; terminal activation duration; ventricular fibrillation; ventricular tachycardia

Mesh:

Year:  2013        PMID: 23816439     DOI: 10.1016/j.hrthm.2013.06.022

Source DB:  PubMed          Journal:  Heart Rhythm        ISSN: 1547-5271            Impact factor:   6.343


  15 in total

1.  Arrhythmic risk assessment in genotyped families with arrhythmogenic right ventricular cardiomyopathy.

Authors:  Alexandros Protonotarios; Aris Anastasakis; Demosthenes B Panagiotakos; Loizos Antoniades; Petros Syrris; Apostolos Vouliotis; Christodoulos Stefanadis; Adalena Tsatsopoulou; William J McKenna; Nikos Protonotarios
Journal:  Europace       Date:  2015-03-29       Impact factor: 5.214

2.  2017 ISHNE-HRS expert consensus statement on ambulatory ECG and external cardiac monitoring/telemetry.

Authors:  Jonathan S Steinberg; Niraj Varma; Iwona Cygankiewicz; Peter Aziz; Paweł Balsam; Adrian Baranchuk; Daniel J Cantillon; Polychronis Dilaveris; Sergio J Dubner; Nabil El-Sherif; Jaroslaw Krol; Malgorzata Kurpesa; Maria Teresa La Rovere; Suave S Lobodzinski; Emanuela T Locati; Suneet Mittal; Brian Olshansky; Ewa Piotrowicz; Leslie Saxon; Peter H Stone; Larisa Tereshchenko; Mintu P Turakhia; Gioia Turitto; Neil J Wimmer; Richard L Verrier; Wojciech Zareba; Ryszard Piotrowicz
Journal:  Ann Noninvasive Electrocardiol       Date:  2017-05       Impact factor: 1.468

3.  Prevalence and Electronic Health Record-Based Phenotype of Loss-of-Function Genetic Variants in Arrhythmogenic Right Ventricular Cardiomyopathy-Associated Genes.

Authors:  Eric D Carruth; Wilson Young; Dominik Beer; Cynthia A James; Hugh Calkins; Linyuan Jing; Sushravya Raghunath; Dustin N Hartzel; Joseph B Leader; H Lester Kirchner; Diane T Smelser; David J Carey; Melissa A Kelly; Amy C Sturm; Amro Alsaid; Brandon K Fornwalt; Christopher M Haggerty
Journal:  Circ Genom Precis Med       Date:  2019-10-22

Review 4.  Right bundle branch block and conduction disturbances in Brugada syndrome and arrhythmogenic right ventricular cardiomyopathy.

Authors:  Leonardo Calò; Annamaria Martino; Emilia Goanta; Yasuo Okumura; Ermenegildo de Ruvo
Journal:  J Interv Card Electrophysiol       Date:  2018-05-26       Impact factor: 1.900

Review 5.  Arrhythmogenic ventricular cardiomyopathy: A paradigm shift from right to biventricular disease.

Authors:  Ardan M Saguner; Corinna Brunckhorst; Firat Duru
Journal:  World J Cardiol       Date:  2014-04-26

6.  Yield of serial evaluation in at-risk family members of patients with ARVD/C.

Authors:  Anneline S J M te Riele; Cynthia A James; Neda Rastegar; Aditya Bhonsale; Brittney Murray; Crystal Tichnell; Daniel P Judge; David A Bluemke; Stefan L Zimmerman; Ihab R Kamel; Hugh Calkins; Harikrishna Tandri
Journal:  J Am Coll Cardiol       Date:  2014-07-22       Impact factor: 24.094

Review 7.  Current controversies in pre-participation cardiovascular screening for young competitive athletes.

Authors:  Bradley J Petek; Aaron L Baggish
Journal:  Expert Rev Cardiovasc Ther       Date:  2020-07-07

8.  A novel noninvasive surface ECG analysis using interlead QRS dispersion in arrhythmogenic right ventricular cardiomyopathy.

Authors:  Wan-Hsin Hsieh; Chin-Yu Lin; Abigail Louise D Te; Men-Tzung Lo; Cheng-I Wu; Fa-Po Chung; Yi-Chung Chang; Shih-Lin Chang; Chen Lin; Li-Wei Lo; Yu-Feng Hu; Jo-Nan Liao; Yun-Yu Chen; Shih-Jie Jhuo; Sunu Budhi Raharjo; Yenn-Jiang Lin; Shih-Ann Chen
Journal:  PLoS One       Date:  2017-08-03       Impact factor: 3.240

9.  Diagnostic dilemmas for underlying pathophysiology of arrhythmias originating from the right ventricle.

Authors:  Serkan Cay; Nurdan Cay; Ugur Canpolat; Ozcan Ozeke; Baris Sensoy
Journal:  Indian Pacing Electrophysiol J       Date:  2014-03-12

10.  Arrhythmogenic Right Ventricle in Left Ventricular Non-compaction - In Response to the Letter to the Editor "Diagnostic Dilemmas for Underlying Pathophysiology of Arrhythmias Originating from the Right Ventricle".

Authors:  Shohreh Honarbakhsh; Irina Suman-Horduna; Lilian Mantziari; Sabine Ernst
Journal:  Indian Pacing Electrophysiol J       Date:  2014-03-12
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