Literature DB >> 23553478

Hyperdopaminergic crises in familial dysautonomia: a randomized trial of carbidopa.

Lucy Norcliffe-Kaufmann1, Jose Martinez, Felicia Axelrod, Horacio Kaufmann.   

Abstract

OBJECTIVE: The purpose of this study was to determine whether carbidopa (Lodosyn), an inhibitor of dopa-decarboxylase that blocks the synthesis of dopamine outside the brain, is an effective antiemetic in patients with familial dysautonomia (FD) and hyperdopaminergic nausea/retching/vomiting attacks.
METHODS: We enrolled 12 patients with FD in an open-label titration and treatment study to assess the safety of carbidopa. We then conducted a randomized, double-blind, placebo-controlled, crossover study to evaluate its antiemetic efficacy.
RESULTS: Previous fundoplication surgery in each patient studied prevented vomiting, but all of the subjects experienced severe cyclical nausea and uncontrollable retching that was refractory to standard treatments. Carbidopa at an average daily dose of 480 mg (range 325-600 mg/day) was well tolerated. In the double-blind phase, patients experienced significantly less nausea and retching while on carbidopa than on placebo (p < 0.03 and p < 0.02, respectively). Twenty-four-hour urinary dopamine excretion was significantly lower while on carbidopa (147 ± 32 µg/gCr) than while on placebo (222 ± 41µg/gCr, p < 0.05).
CONCLUSIONS: Carbidopa is a safe and effective antiemetic in patients with FD, likely by reducing the formation of dopamine outside the brain. CLASSIFICATION OF EVIDENCE: This study provides Class II evidence that carbidopa is effective in reducing nausea/retching/vomiting in patients with FD.

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Year:  2013        PMID: 23553478      PMCID: PMC3662326          DOI: 10.1212/WNL.0b013e31828f18f0

Source DB:  PubMed          Journal:  Neurology        ISSN: 0028-3878            Impact factor:   9.910


  23 in total

1.  Tyrosine hydroxylase immunoreactivity in familial dysautonomia.

Authors:  J Pearson; L Brandeis; M Goldstein
Journal:  Science       Date:  1979-10-05       Impact factor: 47.728

2.  Cyclic vomiting associated with excessive dopamine in Riley-day syndrome.

Authors:  Lucy J Norcliffe-Kaufmann; Felicia B Axelrod; Horacio Kaufmann
Journal:  J Clin Gastroenterol       Date:  2013-02       Impact factor: 3.062

3.  Modification of Parkinsonism--chronic treatment with L-dopa.

Authors:  G C Cotzias; P S Papavasiliou; R Gellene
Journal:  N Engl J Med       Date:  1969-02-13       Impact factor: 91.245

4.  Reduced plasma dopamine-beta-hydroxylase activity in familial dysautonomia.

Authors:  R M Weinshilboum; J Axelrod
Journal:  N Engl J Med       Date:  1971-10-21       Impact factor: 91.245

Review 5.  Rating scales for affective disorders: their validity and consistency.

Authors:  P Bech
Journal:  Acta Psychiatr Scand Suppl       Date:  1981

6.  Intranasal midazolam as a treatment of autonomic crisis in patients with familial dysautonomia.

Authors:  E Lahat; M Goldman; J Barr; T Bistritzer; M Berkovitch
Journal:  Pediatr Neurol       Date:  2000-01       Impact factor: 3.372

Review 7.  The area postrema and vomiting.

Authors:  A D Miller; R A Leslie
Journal:  Front Neuroendocrinol       Date:  1994-12       Impact factor: 8.606

Review 8.  Diagnostic significance of dopamine estimation using plasma and urine in patients with adrenal and renal insufficiency, renal transplantation and hypertension.

Authors:  M Yoshimura; T Komori; M Nishimura; Y Habuchi; N Fujita; T Nakanishi; T Yasumura; H Takahashi
Journal:  Hypertens Res       Date:  1995-06       Impact factor: 3.872

9.  Treatment of familial dysautonomia with bethanecol (urecholine).

Authors:  F B Axelrod; N Branom; M Becker; R Nachtigall; J Dancis
Journal:  J Pediatr       Date:  1972-09       Impact factor: 4.406

Review 10.  Metoclopramide-induced movement disorders. Clinical findings with a review of the literature.

Authors:  L G Miller; J Jankovic
Journal:  Arch Intern Med       Date:  1989-11
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  15 in total

Review 1.  Hereditary Sensory and Autonomic Neuropathies: Adding More to the Classification.

Authors:  Coreen Schwartzlow; Mohamed Kazamel
Journal:  Curr Neurol Neurosci Rep       Date:  2019-06-20       Impact factor: 5.081

2.  Norepinephrine deficiency with normal blood pressure control in congenital insensitivity to pain with anhidrosis.

Authors:  Lucy Norcliffe-Kaufmann; Stuart D Katz; Felicia Axelrod; Horacio Kaufmann
Journal:  Ann Neurol       Date:  2015-03-13       Impact factor: 10.422

3.  Cyclic vomiting syndrome: the nervous system has the guts.

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Journal:  Clin Auton Res       Date:  2018-02-22       Impact factor: 4.435

4.  Ambulatory blood pressure profiles in familial dysautonomia.

Authors:  Lior Goldberg; Bat-El Bar-Aluma; Alex Krauthammer; Ori Efrati; Yehonatan Sharabi
Journal:  Clin Auton Res       Date:  2018-02-12       Impact factor: 4.435

5.  A Controlled Trial of Inhaled Bronchodilators in Familial Dysautonomia.

Authors:  Bat-El Bar-Aluma; Ori Efrati; Horacio Kaufmann; Jose-Alberto Palma; Lucy Norcliffe-Kaufmann
Journal:  Lung       Date:  2017-12-12       Impact factor: 2.584

Review 6.  Current treatments in familial dysautonomia.

Authors:  Jose-Alberto Palma; Lucy Norcliffe-Kaufmann; Cristina Fuente-Mora; Leila Percival; Carlos Mendoza-Santiesteban; Horacio Kaufmann
Journal:  Expert Opin Pharmacother       Date:  2014-10-17       Impact factor: 3.889

7.  Dexmedetomidine for refractory adrenergic crisis in familial dysautonomia.

Authors:  Ryan C Dillon; Jose-Alberto Palma; Christy L Spalink; Diana Altshuler; Lucy Norcliffe-Kaufmann; David Fridman; John Papadopoulos; Horacio Kaufmann
Journal:  Clin Auton Res       Date:  2016-10-17       Impact factor: 4.435

8.  Intranasal dexmedetomidine for adrenergic crisis in familial dysautonomia.

Authors:  Christy L Spalink; Erin Barnes; Jose-Alberto Palma; Lucy Norcliffe-Kaufmann; Horacio Kaufmann
Journal:  Clin Auton Res       Date:  2017-07-03       Impact factor: 4.435

9.  Carbidopa for Afferent Baroreflex Failure in Familial Dysautonomia: A Double-Blind Randomized Crossover Clinical Trial.

Authors:  Lucy Norcliffe-Kaufmann; Jose-Alberto Palma; Jose Martinez; Horacio Kaufmann
Journal:  Hypertension       Date:  2020-07-13       Impact factor: 10.190

10.  Chewing-induced hypertension in afferent baroreflex failure: a sympathetic response?

Authors:  Cristina Fuente Mora; Lucy Norcliffe-Kaufmann; Jose-Alberto Palma; Horacio Kaufmann
Journal:  Exp Physiol       Date:  2015-10-14       Impact factor: 2.969

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