Literature DB >> 235012

Lipid storage myopathy with normal carnitine levels.

F Jerusalem, H Spiess, G Baumgartner.   

Abstract

A 28-year-old female, who showed a floppy baby syndrome during early infancy, had a non-progressive proximal muscle weakness with easy fatiguability since childhood. Two muscle specimens biopsied at the age of 28 years revealed myriads of 1-3-mum wide abnormal spaces containing neutral fat in type I and type II fibers. Both biopsies demonstrated a type I fiber preponderance. Electron microscopy demonstrated lipid excess and normal mitochondria by simple inspection. The mitochondrial area and sarcotubular membrane profile concentration in morphometry of longitudinal sections were also normal. Cross-sections, however, revealed a slight decrease of the individual mitochondrial size and of the sarcotubular membrane profile concentration . Serum and muscle carnitine levels and the muscle carnitine palmityltransferase level were all within normal range. Besides carnitine deficiency other biochemical defects can occur in lipid storage myopathy, which represents a syndrome rather than a unique disease entity.

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Year:  1975        PMID: 235012     DOI: 10.1016/0022-510x(75)90247-6

Source DB:  PubMed          Journal:  J Neurol Sci        ISSN: 0022-510X            Impact factor:   3.181


  8 in total

1.  Carnitine deficiency: clinical, morphological, and biochemical observations in a fatal case.

Authors:  A G Engel; B Q Banker; R M Eiben
Journal:  J Neurol Neurosurg Psychiatry       Date:  1977-04       Impact factor: 10.154

Review 2.  Primary lipid cardiomyopathy.

Authors:  A Zimmermann; P Wyss; F Stocker
Journal:  Virchows Arch A Pathol Anat Histopathol       Date:  1990

3.  [Diagnostic significance of muscle biopsies in metabolic myopathies. II. Clinical biochemistry].

Authors:  T Deufel; I Paetzke; D Pongratz; G Hübner; O H Wieland
Journal:  Klin Wochenschr       Date:  1984-07-16

4.  Fatal lipid storage myopathy with deficiency of cytochrome-c-oxidase and carnitine. A contribution to the combined cytochemical-finestructural identification of cytochrome-c-oxidase in longterm frozen muscle.

Authors:  J Müller-Höcker; D Pongratz; T Deufel; J M Trijbels; W Endres; G Hübner
Journal:  Virchows Arch A Pathol Anat Histopathol       Date:  1983

5.  A hereditary case of lipid storage myopathy with carnitine deficiency. Ultrastructural observation of muscle tissue in parents.

Authors:  G Pellegrini; G Scarlato; M Moggio
Journal:  J Neurol       Date:  1980       Impact factor: 4.849

6.  Lipid storage myopathy: successful treatment with propranolol.

Authors:  C Martyn; E H Jellinek; J N Webb
Journal:  Br Med J (Clin Res Ed)       Date:  1981-06-20

Review 7.  Lipid storage myopathies. A review of metabolic defect and of treatment.

Authors:  C Angelini
Journal:  J Neurol       Date:  1976-11-26       Impact factor: 4.849

8.  [Clinical, morphological and biochemical studies on muscle carnitine deficiency (author's transl)].

Authors:  D Pongratz; G Hübner; T Deufel; O Wieland; E Pongratz; R Liphardt
Journal:  Klin Wochenschr       Date:  1979-09-17
  8 in total

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