Literature DB >> 23457019

Alpha-synuclein p.H50Q, a novel pathogenic mutation for Parkinson's disease.

Silke Appel-Cresswell1, Carles Vilarino-Guell, Mary Encarnacion, Holly Sherman, Irene Yu, Brinda Shah, David Weir, Christina Thompson, Chelsea Szu-Tu, Joanne Trinh, Jan O Aasly, Alex Rajput, Ali H Rajput, A Jon Stoessl, Matthew J Farrer.   

Abstract

BACKGROUND: Alpha-synuclein plays a central role in the pathophysiology of Parkinson's disease. Three missense mutations in SNCA, the gene encoding alpha-synuclein, as well as genomic multiplications have been identified as causes for autosomal-dominantly inherited Parkinsonism.
METHODS: Here, we describe a novel missense mutation in exon 4 of SNCA encoding a H50Q substitution in a patient with dopa-responsive Parkinson's disease with a family history of parkinsonism and dementia.
RESULTS: The variant was not observed in public databases or identified in unrelated subjects.
CONCLUSIONS: The substitution's evolutionary conservation and protein modeling provide additional support for pathogenicity as the amino acid perturbs the same amphipathic alpha helical structure as the previously described pathogenic mutations.
Copyright © 2013 Movement Disorder Society.

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Year:  2013        PMID: 23457019     DOI: 10.1002/mds.25421

Source DB:  PubMed          Journal:  Mov Disord        ISSN: 0885-3185            Impact factor:   10.338


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