Literature DB >> 23327823

Autoimmune polyglandular syndrome type 1 with reversible dilated cardiomyopathy: complete recovery after correction of hypocalcemia and hypocortisolemia.

Arshad Iqbal Wani1, Khalid Jamal Farooqui, Mir Iftikhar Bashir, Shahnaz Ahmad Mir, Ajaz Ahmad Lone, Shariq Rashid Masoodi.   

Abstract

Autoimmune polyglandular syndrome type 1 (APS1) - characterized by the triad of mucocutaneous candidiasis, hypoparathyroidism, and primary adrenal insufficiency - is an uncommon entity. In this case report we describe the case of a young girl who presented with classic features of APS1 and dilated cardiomyopathy, which were missed during her presentation to the children's hospital. Her condition improved only when appropriate replacement therapy in the form of calcium, calcitriol and hydrocortisone was instituted. Hypocalcemia and hypocortisol state are curable causes of myocardial dysfunction and subsequent congestive cardiac failure, and should always be considered in the differential diagnosis of resistant congestive cardiac failure, especially in children. To the best of our knowledge, cardiomyopathy in the setting of APS1 has never been described previously and can remain unrecognized for a long time and present with life threatening complications.

Entities:  

Mesh:

Substances:

Year:  2013        PMID: 23327823     DOI: 10.1515/jpem-2012-0201

Source DB:  PubMed          Journal:  J Pediatr Endocrinol Metab        ISSN: 0334-018X            Impact factor:   1.634


  2 in total

Review 1.  Autoimmune polyendocrine syndrome type 1 (APECED) in the Indian population: case report and review of a series of 45 patients.

Authors:  A Fierabracci; A Arena; F Toto; N Gallo; A Puel; M Migaud; M Kumar; K G Chengappa; R Gulati; V S Negi; C Betterle
Journal:  J Endocrinol Invest       Date:  2020-08-07       Impact factor: 4.256

2.  Reversible dilated cardiomyopathy as a complication of adrenal cortex insufficiency: a case report.

Authors:  Mohammad Alkhateeb; Mohammad Alsakkal; Mohammad Nour Alfauri; Diana Alasmar
Journal:  J Med Case Rep       Date:  2018-11-21
  2 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.