Literature DB >> 23234876

Pattern of peripheral nerve involvement in Machado-Joseph disease: neuronopathy or distal axonopathy? A clinical and neurophysiological evaluation.

Marcio Luiz Escorcio Bezerra1, José Luiz Pedroso, Denise Spinola Pinheiro, Pedro Braga-Neto, Orlando Graziani Povoas Barsottini, Nadia Iandoli de Oliveira Braga, Gilberto Mastrocola Manzano.   

Abstract

OBJECTIVE: Neuropathy is a well-recognized feature in spinocerebellar ataxia type 3 (SCA3) or Machado-Joseph disease (MJD), but the pattern of neuropathy is still a matter of debate. This study aimed to evaluate peripheral nerve involvement in MJD patients. Neurophysiological and clinical data were analyzed to distinguish neuronopathy from length-dependent distal axonopathy.
METHODS: In the present study we evaluated 26 patients with clinical and molecular-proven MJD and investigated their peripheral nerve involvement. Neurophysiological and clinical data were compared and correlated aiming to distinguish neuronopathy from distal axonopathy.
RESULTS: The neurophysiological evaluation showed that 42.3% of the patients had polyneuropathy. Among these patients, 81.8% presented neuronopathy.
CONCLUSION: We concluded that neuronopathy is the most common form of peripheral nerve involvement in MJD patients.
Copyright © 2012 S. Karger AG, Basel.

Entities:  

Mesh:

Year:  2012        PMID: 23234876     DOI: 10.1159/000345274

Source DB:  PubMed          Journal:  Eur Neurol        ISSN: 0014-3022            Impact factor:   1.710


  6 in total

1.  Neurophysiological studies and non-motor symptoms prior to ataxia in a patient with machado-joseph disease: trying to understand the natural history of brain degeneration.

Authors:  José Luiz Pedroso; Edson Bor-Seng-Shu; Pedro Braga-Neto; Rodrigo Souza Ribeiro; Márcio Luiz Escorcio Bezerra; Lucila B F do Prado; Ilza Rosa Batista; Helena Alessi; Manoel Jacobsen Teixeira; Gilberto Mastrocola Manzano; Gilmar Fernandes do Prado; Orlando Graziani Povoas Barsottini
Journal:  Cerebellum       Date:  2014-08       Impact factor: 3.847

2.  Spinal cord damage in Machado-Joseph disease.

Authors:  Camila N Fahl; Lucas Melo T Branco; Felipe P G Bergo; Anelyssa D'Abreu; Iscia Lopes-Cendes; Marcondes C França
Journal:  Cerebellum       Date:  2015-04       Impact factor: 3.847

3.  Pattern of Peripheral Nerve Involvement in Spinocerebellar Ataxia Type 2: a Neurophysiological Assessment.

Authors:  Marcio Luiz Escorcio Bezerra; José Luiz Pedroso; Pedro Braga-Neto; Agessandro Abrahao; Marcus Vinicius Cristino de Albuquerque; Franklin Roberto Pereira Borges; Maria Luiza Saraiva-Pereira; Laura Bannach Jardim; Nadia Iandoli de Oliveira Braga; Gilberto Mastrocola Manzano; Orlando G P Barsottini
Journal:  Cerebellum       Date:  2016-12       Impact factor: 3.847

4.  State biomarkers for Machado Joseph disease: Validation, feasibility and responsiveness to change.

Authors:  Gabriel Vasata Furtado; Camila Maria de Oliveira; Gabriela Bolzan; Jonas Alex Morales Saute; Maria Luiza Saraiva-Pereira; Laura Bannach Jardim
Journal:  Genet Mol Biol       Date:  2019-06-10       Impact factor: 1.771

Review 5.  The Intersection Between Cerebellar Ataxia and Neuropathy: a Proposed Classification and a Diagnostic Approach.

Authors:  Cristina Saade Jaques; Marcio Luiz Escorcio-Bezerra; José Luiz Pedroso; Orlando Graziani Povoas Barsottini
Journal:  Cerebellum       Date:  2021-08-09       Impact factor: 3.847

6.  Mesenchymal stem cell-derived exosomes improve motor function and attenuate neuropathology in a mouse model of Machado-Joseph disease.

Authors:  Hua-Jing You; Shu-Bin Fang; Teng-Teng Wu; Hongyu Zhang; Yu-Kun Feng; Xue-Jiao Li; Hui-Hua Yang; Ge Li; Xun-Hua Li; Chao Wu; Qing-Ling Fu; Zhong Pei
Journal:  Stem Cell Res Ther       Date:  2020-06-08       Impact factor: 6.832

  6 in total

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