| Literature DB >> 23206802 |
Tomas Honzik1, Marketa Tesarova, Kamila Vinsova, Hana Hansikova, Martin Magner, Hana Kratochvilova, Josef Zamecnik, Jiri Zeman, Pavel Jesina.
Abstract
We report the second known family with a very rare, maternally inherited missense m.8851T>C mutation in the mitochondrial MTATP6 gene. A failure to thrive, microcephaly, psychomotor retardation and hypotonia were present in a 3-year-old girl with a high mtDNA mutation load (87-97%). Ataxia and Leigh syndrome were subsequently documented in a neurological examination and brain MRI. A muscle biopsy demonstrated decreased ATP synthase and an accumulation of succinate dehydrogenase products, indicating mitochondrial myopathy. Her 36-year-old mother (68% blood heteroplasmy) developed peripheral neuropathy and muscle weakness at the age of 22 years. Our findings extend the clinical and laboratory phenotype associated with the m.8851T>C mutation.Entities:
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Year: 2012 PMID: 23206802 DOI: 10.1016/j.ymgme.2012.11.002
Source DB: PubMed Journal: Mol Genet Metab ISSN: 1096-7192 Impact factor: 4.797