Literature DB >> 23169617

Novel mutations in the Anoctamin 5 gene (ANO5) associated with limb-girdle muscular dystrophy 2L.

Ann A Little1, Paul E McKeever, Kirsten L Gruis.   

Abstract

INTRODUCTION: We present a Jordanian man with the typical LGMD 2L phenotype of early, asymmetric quadriceps weakness and subsequent biceps brachii weakness.
METHODS: Case report.
RESULTS: Muscle biopsies document a progressive dystrophic pattern unrelated to known sarcolemmal defects associated with muscular dystrophy. Genetic testing revealed novel, heterozygote Anoctamin 5 gene mutations.
CONCLUSIONS: This case report expands the known mutations resulting in LGMD 2L and supports the assertion that Anoctamin 5 mutations are more prevalent than previously recognized.
Copyright © 2012 Wiley Periodicals, Inc.

Entities:  

Mesh:

Substances:

Year:  2012        PMID: 23169617     DOI: 10.1002/mus.23542

Source DB:  PubMed          Journal:  Muscle Nerve        ISSN: 0148-639X            Impact factor:   3.217


  6 in total

1.  Genetic disruption of Ano5 in mice does not recapitulate human ANO5-deficient muscular dystrophy.

Authors:  Jing Xu; Mona El Refaey; Li Xu; Lixia Zhao; Yandi Gao; Kyle Floyd; Tallib Karaze; Paul M L Janssen; Renzhi Han
Journal:  Skelet Muscle       Date:  2015-12-21       Impact factor: 4.912

2.  Clinical and molecular findings in a cohort of ANO5-related myopathy.

Authors:  André M S Silva; Antônio R Coimbra-Neto; Paulo Victor S Souza; Pablo B Winckler; Marcus V M Gonçalves; Eduardo B U Cavalcanti; Alzira A D S Carvalho; Cláudia F D R Sobreira; Clara G Camelo; Rodrigo D H Mendonça; Eduardo D P Estephan; Umbertina C Reed; Marcela C Machado-Costa; Mario E T Dourado-Junior; Vanessa C Pereira; Marcelo M Cruzeiro; Paulo V P Helito; Laís U Aivazoglou; Leonardo V D Camargo; Hudson H Gomes; Amaro J S D Camargo; Wladimir B V D R Pinto; Bruno M L Badia; Luiz H Libardi; Mario T Yanagiura; Acary S B Oliveira; Anamarli Nucci; Jonas A M Saute; Marcondes C França-Junior; Edmar Zanoteli
Journal:  Ann Clin Transl Neurol       Date:  2019-06-11       Impact factor: 4.511

3.  Deficiency of Anoctamin 5/TMEM16E causes nuclear positioning defect and impairs Ca2+ signaling of differentiated C2C12 myotubes.

Authors:  Tam Thi Thanh Phuong; Jieun An; Sun Hwa Park; Ami Kim; Hyun Bin Choi; Tong Mook Kang
Journal:  Korean J Physiol Pharmacol       Date:  2019-10-24       Impact factor: 2.016

Review 4.  Gene Editing in Rabbits: Unique Opportunities for Translational Biomedical Research.

Authors:  Jie Xu; Jifeng Zhang; Dongshan Yang; Jun Song; Brooke Pallas; Chen Zhang; Jiafen Hu; Xuwen Peng; Neil D Christensen; Renzhi Han; Y Eugene Chen
Journal:  Front Genet       Date:  2021-01-28       Impact factor: 4.599

5.  Novel Variants of ANO5 in Two Patients With Limb Girdle Muscular Dystrophy: Case Report.

Authors:  Matthew Katz; Fleur C Garton; Mark Davis; Robert D Henderson; Pamela A McCombe
Journal:  Front Neurol       Date:  2022-04-08       Impact factor: 4.086

6.  Progression to Loss of Ambulation Among Patients with Autosomal Recessive Limb-girdle Muscular Dystrophy: A Systematic Review.

Authors:  Ivana F Audhya; Antoinette Cheung; Shelagh M Szabo; Emma Flint; Conrad C Weihl; Katherine L Gooch
Journal:  J Neuromuscul Dis       Date:  2022
  6 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.