Literature DB >> 23131568

A novel m.12908T>a mutation in the mitochondrial ND5 gene in patient with infantile-onset Pompe disease.

Imen Chamkha1, Olfa Alila-Fersi, Emna Mkaouar-Rebai, Hajer Aloulou, Chamseddine Kifagi, Mongia Hachicha, Faiza Fakhfakh.   

Abstract

Pompe disease is a progressive metabolic myopathy caused by deficiency in lysosomal acid α-glucosidase and results in cellular lysosomal and cytoplasmic glycogen accumulation. A wide spectrum of clinical phenotypes exists from hypotonia and severe cardiac hypertrophy in the first few months of life to a milder form with the onset of symptoms in adulthood. The disease is typically due to severe mutations in GAA gene. In the present study, we described a newborn boy with clinical features of Pompe disease particularly with hypertrophic cardiomyopathy, hypotonia and hepatomegaly. This case was at first misdiagnosed as mitochondrial disorder. Accordingly, we performed a mitochondrial mutational analysis that revealed a novel mutation m.12908T>A in the ND5 gene. Secondary structure analysis of the ND5 protein further supported the deleterious role of the m.12908T>A mutation, as it was found to involve an extended imbalance in its hydrophobicity and affect its function.
Copyright © 2012 Elsevier Inc. All rights reserved.

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Year:  2012        PMID: 23131568     DOI: 10.1016/j.bbrc.2012.10.105

Source DB:  PubMed          Journal:  Biochem Biophys Res Commun        ISSN: 0006-291X            Impact factor:   3.575


  3 in total

1.  Assessing metabolic profiles in human myoblasts from patients with late-onset Pompe disease.

Authors:  Peter Meinke; Sarah Limmer; Stefan Hintze; Benedikt Schoser
Journal:  Ann Transl Med       Date:  2019-07

2.  Mitochondrial Copy Number and D-Loop Variants in Pompe Patients.

Authors:  Fatemeh Bahreini; Massoud Houshmand; Mohammad Hossein Modaresi; Hassan Tonekaboni; Shahriar Nafissi; Ferdoss Nazari; Seyed Mohammad Akrami
Journal:  Cell J       Date:  2016-08-24       Impact factor: 2.479

Review 3.  The aetiology of cardiovascular disease: a role for mitochondrial DNA?

Authors:  Marianne Venter; Francois H van der Westhuizen; Joanna L Elson
Journal:  Cardiovasc J Afr       Date:  2017-08-25       Impact factor: 1.167

  3 in total

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