Literature DB >> 22932948

COL4A1-related disease: raised creatine kinase and cerebral calcification as useful pointers.

Davide Tonduti1, Anna Pichiecchio, Roberta La Piana, John H Livingston, Daniel A Doherty, Anirban Majumdar, Susan Tomkins, Manuele Mine, Mauro Ceroni, Ivana Ricca, Umberto Balottin, Simona Orcesi.   

Abstract

BACKGROUND: Mutations in COL4A1 are responsible for a spectrum of clinical phenotypes characterized by neurological, ocular, and renal involvement. Neurological features are the most prominent but as such are rather nonspecific. CASE
PRESENTATION: Here, we report three new cases that, like five patients we previously described, show the novel common finding of raised creatine kinase (CK) concentration.
CONCLUSION: Raised CK concentration, in addition to intracranial calcification, is to be considered another useful pointer to a final diagnosis of COL4A1-related disease. Thieme Medical Publishers 333 Seventh Avenue, New York, NY 10001, USA.

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Year:  2012        PMID: 22932948     DOI: 10.1055/s-0032-1325116

Source DB:  PubMed          Journal:  Neuropediatrics        ISSN: 0174-304X            Impact factor:   1.947


  8 in total

Review 1.  Genotype-phenotype correlations in pathology caused by collagen type IV alpha 1 and 2 mutations.

Authors:  Marion Jeanne; Douglas B Gould
Journal:  Matrix Biol       Date:  2016-10-26       Impact factor: 11.583

2.  Identification of potential core genes in gastric cancer using bioinformatics analysis.

Authors:  Changjiang Shao; Rong Wang; Dandan Kong; Qian Gao; Chunfang Xu
Journal:  J Gastrointest Oncol       Date:  2021-10

3.  Chronic kidney disease: the "perfect storm" of cardiometabolic risk illuminates genetic diathesis in cardiovascular disease.

Authors:  Dwight A Towler
Journal:  J Am Coll Cardiol       Date:  2013-05-29       Impact factor: 24.094

4.  Allelic heterogeneity contributes to variability in ocular dysgenesis, myopathy and brain malformations caused by Col4a1 and Col4a2 mutations.

Authors:  Debbie S Kuo; Cassandre Labelle-Dumais; Mao Mao; Marion Jeanne; William B Kauffman; Jennifer Allen; Jack Favor; Douglas B Gould
Journal:  Hum Mol Genet       Date:  2013-11-07       Impact factor: 6.150

5.  Neurologic phenotypes associated with COL4A1/2 mutations: Expanding the spectrum of disease.

Authors:  Sara Zagaglia; Christina Selch; Jelena Radic Nisevic; Davide Mei; Zuzanna Michalak; Laura Hernandez-Hernandez; S Krithika; Katharina Vezyroglou; Sophia M Varadkar; Alexander Pepler; Saskia Biskup; Miguel Leão; Jutta Gärtner; Andreas Merkenschlager; Michaela Jaksch; Rikke S Møller; Elena Gardella; Britta Schlott Kristiansen; Lars Kjærsgaard Hansen; Maria Stella Vari; Katherine L Helbig; Sonal Desai; Constance L Smith-Hicks; Naomi Hino-Fukuyo; Tiina Talvik; Rael Laugesaar; Pilvi Ilves; Katrin Õunap; Ingrid Körber; Till Hartlieb; Manfred Kudernatsch; Peter Winkler; Mareike Schimmel; Anette Hasse; Markus Knuf; Jan Heinemeyer; Christine Makowski; Sondhya Ghedia; Gopinath M Subramanian; Pasquale Striano; Rhys H Thomas; Caroline Micallef; Maria Thom; David J Werring; Gerhard Josef Kluger; J Helen Cross; Renzo Guerrini; Simona Balestrini; Sanjay M Sisodiya
Journal:  Neurology       Date:  2018-11-09       Impact factor: 9.910

6.  A novel homozygous variant in JAM3 gene causing hemorrhagic destruction of the brain, subependymal calcification, and congenital cataracts (HDBSCC) with neonatal onset.

Authors:  Domenico Umberto De Rose; Francesca Gallini; Domenica Immacolata Battaglia; Eloisa Tiberi; Simona Gaudino; Ilaria Contaldo; Chiara Veredice; Domenico Marco Romeo; Luca Massimi; Alessia Asaro; Cristina Cereda; Giovanni Vento; Eugenio Maria Mercuri
Journal:  Neurol Sci       Date:  2021-07-22       Impact factor: 3.307

7.  Optic Nerve Hypoplasia, Corpus Callosum Agenesis, Cataract, and Lissencephaly in a Neonate with a NovelCOL4A1 Mutation.

Authors:  Lisa Grego; Silvia Pignatto; Nicolò Rassu; Eva Passone; Paola Cogo; Paolo Lanzetta
Journal:  Case Rep Ophthalmol       Date:  2019-12-17

8.  Intracerebral hemorrhage in a neonate with an intragenic COL4A2 duplication.

Authors:  Saskia Koene; Cacha M P C D Peeters-Scholte; Jeroen Knijnenburg; Linda S de Vries; Phebe N Adama van Scheltema; Marije E Meuwissen; Sylke J Steggerda; Gijs W E Santen
Journal:  Am J Med Genet A       Date:  2020-11-28       Impact factor: 2.578

  8 in total

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