Literature DB >> 22912921

Spectrum of paediatric lysosomal storage disorders in oman.

Almundher A Al-Maawali1, Surendra N Joshi, Roshan L Koul, Ali A Al-Maawali, Hilal S Al-Sedari, Bader M Al-Amri, Amna M Al-Futaisi.   

Abstract

OBJECTIVES: The aim of this study was to look at the spectrum of paediatric lysosomal disorders in Oman. Lysosomal storage disorders (LSDs) are a heterogeneous group of inherited metabolic diseases. Few studies on the birth prevalence and prevalence of LSDs have been reported from the Arabian Peninsula.
METHODS: We studied 86 children with LSDs diagnosed over a period of nine years, from June 1998 to May 2007. Detailed clinical data, including age of onset, sex, age and mode of first presentation, and presence of consanguinity were collected.
RESULTS: Our data showed the combined birth prevalence for all LSDs in Oman to be around 1 in 4,700 live births. Sphingolipidoses was the most common group of disorder encountered (47.7%), followed by neuronal ceroid lipofuscinoses (NCL) (23.2%) and mucopolysaccharidoses (MPS) (23.2%). The proportion of consanguineous marriages in our series was found to be 87.5%.
CONCLUSION: Our data represent the birth prevalence and clinical spectrum of such disorders in Oman, one of the highly consanguineous societies in the Middle East.

Entities:  

Keywords:  Arabs; Lysosomal storage disorders; Oman; Prevalence

Year:  2012        PMID: 22912921      PMCID: PMC3413619          DOI: 10.12816/0003142

Source DB:  PubMed          Journal:  Sultan Qaboos Univ Med J        ISSN: 2075-051X


  22 in total

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2.  International perspectives on newborn screening.

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3.  Prevalence of different types of lysosomal storage diseases in Saudi Arabia.

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6.  The frequency of lysosomal storage diseases in The Netherlands.

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8.  Lysosomal storage diseases in Greece.

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9.  Late infantile neuronal ceroid lipofuscinosis: a new mutation in Arabs.

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Review 10.  Variant late infantile neuronal ceroid lipofuscinosis (CLN6 gene) in Saudi Arabia.

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3.  Epidemiology of Sanfilippo syndrome: results of a systematic literature review.

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