| Literature DB >> 22903682 |
Amandine Crequer1, Capucine Picard, Vincent Pedergnana, Annick Lim, Shen-Ying Zhang, Laurent Abel, Slawomir Majewski, Jean-Laurent Casanova, Stefania Jablonska, Gerard Orth, Emmanuelle Jouanguy.
Abstract
Epidermodysplasia verruciformis (EV) is a rare genodermatosis characterized by persistent flat warts or pityriasis versicolor-like lesions caused by betapapillomaviruses (EV-HPVs). Autosomal recessive EVER1 and EVER2 deficiencies account for EV in most patients. The mechanisms by which mutations in these partners of the Zinc transporter ZnT1 impair host defense against EV-HPVs are still poorly understood. Keratinocytes of EVER-deficient patients display an alteration of zinc homeostasis and an enhanced proliferative activity. Since EVER proteins are highly expressed in T lymphocytes, we aimed to assess the impact of EVER2 deficiency on T-cell development and function. We studied circulating lymphocyte populations in three adult EV patients sharing the same EVER2 mutation (T150fsX3). We found a normal count of CD4(+) and CD8(+) T cells and a normal proliferative capacity in response to anti-CD3 stimulation. However, we observed a significant increase of memory CD4(+) and effector memory CD8(+) T cells, a bias of the TCR Vαβ and Vγδ repertoires and an increase of skin-homing CD4(+) T-cell subsets. Our findings suggest that EVER2-deficient patients display mild T-cell abnormalities. It remains unclear whether these abnormalities result from EVER deficiency, chronic EV-HPV infection, or both.Entities:
Mesh:
Substances:
Year: 2012 PMID: 22903682 PMCID: PMC3733103 DOI: 10.1007/s10875-012-9749-1
Source DB: PubMed Journal: J Clin Immunol ISSN: 0271-9142 Impact factor: 8.317