Literature DB >> 22553651

Arg124Cys mutation of the TGFBI gene in a Chinese pedigree of Reis-Bücklers corneal dystrophy.

Qiao-Na Yang1, Yong-Wang Zhao, Li-Heng Guo, Nai-Hong Yan, Xu-Yang Liu, Su-Ping Cai.   

Abstract

AIM: To analyze mutations in transforming growth factor beta-induced (TGFBI) gene in a Chinese pedigree with Reis-Bücklers corneal dystrophy (RBCD, also known as GCD3).
METHODS: In a five-generation Chinese family, eight members were identified with RBCD and the rest were unaffected. All members of the family underwent complete ophthalmologic examinations. Exons of TGFBI were amplified by polymerase chain reaction, sequenced, and compared with a reference database.
RESULTS: A single heterozygous C>T (R124C) point mutation was found in exon 4 of TGFBI in all the affected members of the pedigree, but not in the unaffected members.
CONCLUSION: R124C which was a known mutation for lattice corneal dystrophy type I, segregated with the RBCD in this pedigree. This elucidated the correlation between genotype and phenotype in a Chinese family of RBCD.

Entities:  

Keywords:  R124C; Reis-Bücklers corneal dystrophy; TGFBI; molecular genetics; mutation

Year:  2011        PMID: 22553651      PMCID: PMC3340806          DOI: 10.3980/j.issn.2222-3959.2011.03.03

Source DB:  PubMed          Journal:  Int J Ophthalmol        ISSN: 2222-3959            Impact factor:   1.779


  16 in total

1.  A novel mutation at codon 124 (R124L) in the BIGH3 gene is associated with a superficial variant of granular corneal dystrophy.

Authors:  Y Mashima; Y Nakamura; K Noda; M Konishi; M Yamada; J Kudoh; N Shimizu
Journal:  Arch Ophthalmol       Date:  1999-01

Review 2.  The molecular genetics of the corneal dystrophies--current status.

Authors:  Gordon K Klintworth
Journal:  Front Biosci       Date:  2003-05-01

3.  BIGH3 mutation spectrum in corneal dystrophies.

Authors:  Francis L Munier; Beatrice E Frueh; Philippe Othenin-Girard; Sylvie Uffer; Pascal Cousin; Ming X Wang; Elise Héon; Graeme C M Black; Maria A Blasi; Emilio Balestrazzi; Birgit Lorenz; Rafael Escoto; Rafael Barraquer; Maria Hoeltzenbein; Balder Gloor; Maurizio Fossarello; Arun D Singh; Yvan Arsenijevic; Léonidas Zografos; Daniel F Schorderet
Journal:  Invest Ophthalmol Vis Sci       Date:  2002-04       Impact factor: 4.799

4.  TGFBI gene mutations causing lattice and granular corneal dystrophies in Indian patients.

Authors:  S V V Kalyana Chakravarthi; Chitra Kannabiran; Mittanamalli S Sridhar; Geeta K Vemuganti
Journal:  Invest Ophthalmol Vis Sci       Date:  2005-01       Impact factor: 4.799

Review 5.  Genetics of anterior and stromal corneal dystrophies.

Authors:  Vasilliki Poulaki; Kathryn Colby
Journal:  Semin Ophthalmol       Date:  2008 Jan-Feb       Impact factor: 1.975

6.  [Analysis of mutation of BIGH3 gene in Chinese patients with corneal dystrophies].

Authors:  Jie Yu; Liu-he Zou; Jiu-cheng He; Ning-pu Liu; Wei Zhang; Lan Lu; Xu-guang Sun; Dong-sheng Dong; Yu-ying Wu; Xiao-tang Yin
Journal:  Zhonghua Yan Ke Za Zhi       Date:  2003-10

7.  Arg124Cys mutation of the TGFBI gene in 2 Chinese families with Thiel-Behnke corneal dystrophy.

Authors:  Liu Chang; Wang Zhiqun; Deng Shijing; Zhang Chen; Liang Qingfeng; Li Li; Sun Xuguang
Journal:  Arch Ophthalmol       Date:  2009-05

Review 8.  The IC3D classification of the corneal dystrophies.

Authors:  Jayne S Weiss; H U Møller; Walter Lisch; Shigeru Kinoshita; Anthony J Aldave; Michael W Belin; Tero Kivelä; Massimo Busin; Francis L Munier; Berthold Seitz; John Sutphin; Cecilie Bredrup; Mark J Mannis; Christopher J Rapuano; Gabriel Van Rij; Eung Kweon Kim; Gordon K Klintworth
Journal:  Cornea       Date:  2008-12       Impact factor: 2.651

9.  An R124C mutation in TGFBI caused lattice corneal dystrophy type I with a variable phenotype in three Chinese families.

Authors:  Zhe Liu; Yi-qiang Wang; Qing-hua Gong; Li-xin Xie
Journal:  Mol Vis       Date:  2008-06-30       Impact factor: 2.367

10.  Anticipation in familial lattice corneal dystrophy type I with R124C mutation in the TGFBI (BIGH3) gene.

Authors:  Pablo Romero; Marlene Vogel; Jose-Manuel Diaz; Maria-Patricia Romero; Luisa Herrera
Journal:  Mol Vis       Date:  2008-05-07       Impact factor: 2.367

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  4 in total

1.  Transforming growth factor β induced mutation-associated phenotype in a Chinese family exhibiting lattice corneal dystrophy.

Authors:  Chao Qu; Man Yu; Xiaoxin Guo; Jing Li; Xiaoqi Liu; Yi Shi; Bo Gong
Journal:  Biomed Rep       Date:  2017-08-30

2.  Corneal histomorphology and electron microscopic observation of R124L mutated corneal dystrophy in a relapsed pedigree.

Authors:  Meng-Jun Fu; Jing Zhao; Shan Duan; Hao-Run Zhang; Jing-Jing Zhao; Li Zeng; Rui Wang; Xing-Tao Zhou
Journal:  Int J Ophthalmol       Date:  2022-09-18       Impact factor: 1.645

3.  Genotypic Homogeneity in Distinctive Transforming Growth Factor-Beta Induced (TGFBI) Protein Phenotypes.

Authors:  Sang Beom Han; Venkatraman Anandalakshmi; Chee Wai Wong; Si Rui Ng; Jodhbir S Mehta
Journal:  Int J Mol Sci       Date:  2021-01-27       Impact factor: 5.923

4.  Analysis of TGFBI Gene Mutations in Three Chinese Families with Corneal Dystrophy.

Authors:  Feng Zhao; Yuan Liu; Tao Guan
Journal:  J Ophthalmol       Date:  2019-01-22       Impact factor: 1.909

  4 in total

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