Literature DB >> 22494260

Gerstmann-Sträussler-Scheinker syndrome with the P102L pathogenic mutation presenting as familial Creutzfeldt-Jakob disease: a case report and review of the literature.

Robert Rusina1, Jindřich Fiala, Karel Holada, Milada Matějčková, Jana Nováková, Radek Ampapa, František Koukolík, Radoslav Matěj.   

Abstract

Gerstmann-Sträussler-Scheinker syndrome is a rare autosomal dominant disease caused by a mutation in the prion gene, usually manifesting as progressive ataxia with late cognitive decline. A 44-year-old woman with a positive family history developed early personality and behavior changes, followed by paresthesias and ataxia, later associated with memory problems, pyramidal signs, anosognosia and very late myoclonus, spasticity, and severe dysexecutive impairment. Magnetic resonance showed caudate, mesio-frontal, and insular hyper-intensities, electroencephalography revealed generalized triphasic periodic complexes. A pathogenic P102L mutation in the prion gene was detected. Our case differed from classical Gerstmann-Sträussler-Scheinker syndrome by rapid progression, severe dementia, abnormal electroencephalography and magnetic resonance findings, which were highly suggestive of familial Creutzfeldt-Jakob disease.

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Year:  2012        PMID: 22494260     DOI: 10.1080/13554794.2011.654215

Source DB:  PubMed          Journal:  Neurocase        ISSN: 1355-4794            Impact factor:   0.881


  3 in total

Review 1.  Myoclonus-Ataxia Syndromes: A Diagnostic Approach.

Authors:  Malco Rossi; Sterre van der Veen; Marcelo Merello; Marina A J Tijssen; Bart van de Warrenburg
Journal:  Mov Disord Clin Pract       Date:  2020-11-03

2.  Transmission Properties of Human PrP 102L Prions Challenge the Relevance of Mouse Models of GSS.

Authors:  Emmanuel A Asante; Andrew Grimshaw; Michelle Smidak; Tatiana Jakubcova; Andrew Tomlinson; Asif Jeelani; Shyma Hamdan; Caroline Powell; Susan Joiner; Jacqueline M Linehan; Sebastian Brandner; Jonathan D F Wadsworth; John Collinge
Journal:  PLoS Pathog       Date:  2015-07-02       Impact factor: 6.823

3.  Detection of the GPI-anchorless prion protein fragment PrP226* in human brain.

Authors:  Eva Dvorakova; Tanja Vranac; Olga Janouskova; Maja Černilec; Simon Koren; Anja Lukan; Jana Nováková; Radoslav Matej; Karel Holada; Vladka Čurin Šerbec
Journal:  BMC Neurol       Date:  2013-09-25       Impact factor: 2.474

  3 in total

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