Literature DB >> 22490985

Concomitant Brugada-like and short QT electrocardiogram linked to SCN5A mutation.

Kui Hong1, Jinzhu Hu, Jianhua Yu, Ramon Brugada.   

Abstract

Mutations in the α-subunit of cardiac sodium channel gene SCN5A can lead to the overlapping phenotypes of both the Brugada and type 3 long QT syndromes. However, the combination of Brugada and a short QT phenotype resulting from mutation in SCN5A has not previously been described. A man with concomitant Brugada-like and short QT electrocardiogram (ECG) was identified and the SCN5A gene was sequenced. Whole-cell patch clamp analysis of human embryo kidney (HEK) 293 cells expressing a SCN5A channel with the patient's sequence was used to investigate the biophysical properties of the channel. The patient with the family history of sudden death showed Brugada-like and short QT interval ECG. Sequence analysis of the coding region of the SCN5A gene, identified a G to A heterozygous missense mutation at nucleotide site 2066 that resulted in a amino-acid substitution of arginine to histidine at amino-acid site 689 (R689H). Patch clamp analysis showed that the R689H failed to generate current when heterologously expressed in HEK293 cells, indicating it was a loss-of-function mutation. Our finding firstly shows that a heterozygous missense mutation R689H in SCN5A gene results in the loss of protein function and the coexistents of the Brugada-like and short QT interval ECG phenotypes.

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Year:  2012        PMID: 22490985      PMCID: PMC3476719          DOI: 10.1038/ejhg.2012.63

Source DB:  PubMed          Journal:  Eur J Hum Genet        ISSN: 1018-4813            Impact factor:   4.246


  18 in total

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2.  Compound heterozygous mutations P336L and I1660V in the human cardiac sodium channel associated with the Brugada syndrome.

Authors:  Jonathan M Cordeiro; Hector Barajas-Martinez; Kui Hong; Elena Burashnikov; Ryan Pfeiffer; Anne-Marie Orsino; Yue Sheng Wu; Dan Hu; Josep Brugada; Pedro Brugada; Charles Antzelevitch; Robert Dumaine; Ramon Brugada
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3.  High risk for bradyarrhythmic complications in patients with Brugada syndrome caused by SCN5A gene mutations.

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4.  Identification of six novel SCN5A mutations in Japanese patients with Brugada syndrome.

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5.  The elusive link between LQT3 and Brugada syndrome: the role of flecainide challenge.

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6.  Spectrum and prevalence of cardiac sodium channel variants among black, white, Asian, and Hispanic individuals: implications for arrhythmogenic susceptibility and Brugada/long QT syndrome genetic testing.

Authors:  Michael J Ackerman; Igor Splawski; Jonathan C Makielski; David J Tester; Melissa L Will; Katherine W Timothy; Mark T Keating; Gregg Jones; Monica Chadha; Christopher R Burrow; J Claiborne Stephens; Chuanbo Xu; Richard Judson; Mark E Curran
Journal:  Heart Rhythm       Date:  2004-11       Impact factor: 6.343

7.  Sudden death associated with short-QT syndrome linked to mutations in HERG.

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Journal:  Circulation       Date:  2003-12-15       Impact factor: 29.690

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9.  Genetic testing in the long QT syndrome: development and validation of an efficient approach to genotyping in clinical practice.

Authors:  Carlo Napolitano; Silvia G Priori; Peter J Schwartz; Raffaella Bloise; Elena Ronchetti; Janni Nastoli; Georgia Bottelli; Marina Cerrone; Sergio Leonardi
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10.  A novel form of short QT syndrome (SQT3) is caused by a mutation in the KCNJ2 gene.

Authors:  Silvia G Priori; Sandeep V Pandit; Ilaria Rivolta; Omer Berenfeld; Elena Ronchetti; Amit Dhamoon; Carlo Napolitano; Justus Anumonwo; Marina Raffaele di Barletta; Smitha Gudapakkam; Giuliano Bosi; Marco Stramba-Badiale; José Jalife
Journal:  Circ Res       Date:  2005-03-10       Impact factor: 17.367

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  8 in total

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Review 3.  Beyond the Electrocardiogram: Mutations in Cardiac Ion Channel Genes Underlie Nonarrhythmic Phenotypes.

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Review 4.  Recent Advances in Short QT Syndrome.

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5.  Impact of Antiarrhythmic Drugs on the Outcome of Short QT Syndrome.

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Review 7.  The Arrhythmogenic Face of COVID-19: Brugada ECG Pattern in SARS-CoV-2 Infection.

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8.  Cardiac ion channelopathies and the sudden infant death syndrome.

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