Literature DB >> 22386531

Fanconi's anaemia and unilateral thumb polydactyly--don't miss it.

D J Wilks1, S P J Kay, G Bourke.   

Abstract

Fanconi's anaemia (FA) is a rare, life threatening inherited syndrome. Patients usually present late in the first decade of life with aplastic anaemia or acute myeloid leukaemia. FA children are also at high risk of solid organ tumours, anogenital squamous cancers, and endocrinopathies. These patients can present with unilateral radial abnormalities including thumb duplication. Hand surgeons can help achieve early diagnosis and improved survival in this group by early referral for screening. In a retrospective study of 202 children with radial ray anomalies seen over a 20 year period seven children had FA. Of these seven with FA, four had bilateral thumb hypoplasia and three had unilateral thumb anomalies--two unilateral thumb hypoplasias and one thumb duplication. The three children with unilateral anomalies were diagnosed late, presenting with bone marrow failure. All three have subsequently died following late bone marrow transplants. This study highlights the link between unilateral radial anomalies, including thumb duplication and FA and the importance of early genetic referral for diagnosis and surveillance.
Copyright © 2012 British Association of Plastic, Reconstructive and Aesthetic Surgeons. Published by Elsevier Ltd. All rights reserved.

Entities:  

Mesh:

Year:  2012        PMID: 22386531     DOI: 10.1016/j.bjps.2012.02.015

Source DB:  PubMed          Journal:  J Plast Reconstr Aesthet Surg        ISSN: 1748-6815            Impact factor:   2.740


  3 in total

1.  Fanconi Anemia Concurrent with an Unusual Thumb Polydactyly: A Case Report.

Authors:  Ahmadreza Afshar
Journal:  Arch Bone Jt Surg       Date:  2016-04

2.  Role of Genetic Factors in the Pathogenesis of Radial Deficiencies in Humans.

Authors:  Amira Elmakky; Ilaria Stanghellini; Antonio Landi; Antonio Percesepe
Journal:  Curr Genomics       Date:  2015-08       Impact factor: 2.236

Review 3.  Chromosome Instability in Fanconi Anemia: From Breaks to Phenotypic Consequences.

Authors:  Benilde García-de-Teresa; Alfredo Rodríguez; Sara Frias
Journal:  Genes (Basel)       Date:  2020-12-21       Impact factor: 4.096

  3 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.