Literature DB >> 22029951

Clinical spectrum of SCN2A mutations.

Xiuyu Shi1, Sawa Yasumoto, Hirokazu Kurahashi, Eiji Nakagawa, Tatsuya Fukasawa, Satoshi Uchiya, Shinichi Hirose.   

Abstract

Mutations in SCN2A, the gene encoding α2 subunit of the neuronal sodium channel, are associated with a variety of epilepsies: benign familial neonatal-infantile seizures (BFNIS); genetic epilepsy with febrile seizures plus (GEFS+); Dravet syndrome (DS); and some intractable childhood epilepsies. More than 10 new mutations have been identified in BFNIS, all of them are missense. To date, only one nonsense mutation has been found in a patient with intractable childhood epilepsy and severe mental decline. Recently, microduplication of chromosome 2q24.3 (containing eight genes including SCN2A, SCN3A, and the 3' end of SCN1A) was reported in a family with dominantly inherited neonatal seizures and intellectual disability. Functional studies of SCN2A mutations show that they can cause divergent biophysical defects in Na(V)1.2 and impair cell surface expressions. There is no consistent relationship between genotype and phenotype.
Copyright © 2011 The Japanese Society of Child Neurology. Published by Elsevier B.V. All rights reserved.

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Year:  2011        PMID: 22029951     DOI: 10.1016/j.braindev.2011.09.016

Source DB:  PubMed          Journal:  Brain Dev        ISSN: 0387-7604            Impact factor:   1.961


  34 in total

1.  Incorporating Functional Information in Tests of Excess De Novo Mutational Load.

Authors:  Yu Jiang; Yujun Han; Slavé Petrovski; Kouros Owzar; David B Goldstein; Andrew S Allen
Journal:  Am J Hum Genet       Date:  2015-07-30       Impact factor: 11.025

Review 2.  Epigenetic mechanisms in stroke and epilepsy.

Authors:  Jee-Yeon Hwang; Kelly A Aromolaran; R Suzanne Zukin
Journal:  Neuropsychopharmacology       Date:  2012-08-15       Impact factor: 7.853

3.  Genotype & Phenotype of Ohtahara Syndrome-What's SCN2A Got to Do With It? A Clinician's Read.

Authors:  Jeffrey Buchhalter
Journal:  Epilepsy Curr       Date:  2014-09       Impact factor: 7.500

Review 4.  Clinical review of genetic epileptic encephalopathies.

Authors:  Grace J Noh; Y Jane Tavyev Asher; John M Graham
Journal:  Eur J Med Genet       Date:  2012-01-25       Impact factor: 2.708

5.  Backbone resonance assignments of complexes of human voltage-dependent sodium channel NaV1.2 IQ motif peptide bound to apo calmodulin and to the C-domain fragment of apo calmodulin.

Authors:  Ryan Mahling; Adina M Kilpatrick; Madeline A Shea
Journal:  Biomol NMR Assign       Date:  2017-08-19       Impact factor: 0.746

Review 6.  Ion Channel Genes and Epilepsy: Functional Alteration, Pathogenic Potential, and Mechanism of Epilepsy.

Authors:  Feng Wei; Li-Min Yan; Tao Su; Na He; Zhi-Jian Lin; Jie Wang; Yi-Wu Shi; Yong-Hong Yi; Wei-Ping Liao
Journal:  Neurosci Bull       Date:  2017-05-09       Impact factor: 5.203

Review 7.  Mutational consequences of aberrant ion channels in neurological disorders.

Authors:  Dhiraj Kumar; Rashmi K Ambasta; Pravir Kumar
Journal:  J Membr Biol       Date:  2014-08-14       Impact factor: 1.843

8.  Characterization of a de novo SCN8A mutation in a patient with epileptic encephalopathy.

Authors:  Carolien G F de Kovel; Miriam H Meisler; Eva H Brilstra; Frederique M C van Berkestijn; Ruben van 't Slot; Stef van Lieshout; Isaac J Nijman; Janelle E O'Brien; Michael F Hammer; Mark Estacion; Stephen G Waxman; Sulayman D Dib-Hajj; Bobby P C Koeleman
Journal:  Epilepsy Res       Date:  2014-09-04       Impact factor: 3.045

9.  SCN2A-Related Early-Onset Epileptic Encephalopathy Responsive to Phenobarbital.

Authors:  Fiona M Baumer; Jurriaan M Peters; Christelle M El Achkar; Phillip L Pearl
Journal:  J Pediatr Epilepsy       Date:  2016-03

10.  A novel de novo mutation of SCN8A (Nav1.6) with enhanced channel activation in a child with epileptic encephalopathy.

Authors:  Mark Estacion; Janelle E O'Brien; Allison Conravey; Michael F Hammer; Stephen G Waxman; Sulayman D Dib-Hajj; Miriam H Meisler
Journal:  Neurobiol Dis       Date:  2014-05-27       Impact factor: 5.996

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