Literature DB >> 21929355

Fast course ALS presenting with vocal cord paralysis: clinical features, bioinformatic and modelling analysis of the novel SOD1 Gly147Ser mutation.

Paola Origone1, Claudia Caponnetto, Vittorio Mantero, Elena Cichero, Paola Fossa, Alessandro Geroldi, Simonetta Verdiani, Emilia Bellone, Gianluigi Mancardi, Paola Mandich.   

Abstract

In this report we describe a novel SOD1 mutation (Gly147Ser) in an Italian sporadic ALS patient. The patient presented with hoarseness due to bilateral vocal cord paralysis and a rapid clinical course. Mutational analysis of the SOD1 gene was carried out by direct sequencing. In silico bioinformatics analysis and molecular modelling was used to analyse the SOD1 function modifications produced by the mutated residue. A heterozygous c.442 G > A transition, which leads to a change at codon 147 resulting in a serine rather than glycine, was found in the patient. Bioinformatics analysis and molecular modelling strongly suggest a dramatic effect of Gly147Ser mutation on SOD1 function. In conclusion, Gly147Ser represent a new missense mutation whose effect may correlate with the peculiar clinical bulbar phenotype onset with bilateral vocal cord paresis and rapid clinical course of the disease. Ethical and psychological dilemmas about genetic testing in apparently sporadic subjects are still matter of debate.

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Year:  2011        PMID: 21929355     DOI: 10.3109/17482968.2011.614254

Source DB:  PubMed          Journal:  Amyotroph Lateral Scler        ISSN: 1471-180X


  3 in total

1.  SOD1 stimulates lamellipodial protrusions in Neuro 2A cell lines.

Authors:  Ilaria Ferrari; Chiara Verpelli; Arianna Crespi; Carlo Sala; Diego Fornasari; Grazia Pietrini
Journal:  Commun Integr Biol       Date:  2018-08-09

2.  Clinical and Molecular Landscape of ALS Patients with SOD1 Mutations: Novel Pathogenic Variants and Novel Phenotypes. A Single ALS Center Study.

Authors:  Emilien Bernard; Antoine Pegat; Juliette Svahn; Françoise Bouhour; Pascal Leblanc; Stéphanie Millecamps; Stéphane Thobois; Claire Guissart; Serge Lumbroso; Kevin Mouzat
Journal:  Int J Mol Sci       Date:  2020-09-16       Impact factor: 5.923

3.  Unilateral vocal cord adductor weakness: an atypical manifestation of motor neurone disease.

Authors:  Saiumaeswar Yogakanthi; Christine Wools; Susan Mathers
Journal:  BMJ Neurol Open       Date:  2021-10-11
  3 in total

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