Literature DB >> 21855090

Community acquired Staphylococcus aureus meningitis and cerebral abscesses in a patient with a hyper-IgE and a Dubowitz-like syndrome.

Markus Beitzke1, Christian Enzinger, Christian Windpassinger, Dietmar Pfeifer, Franz Fazekas, Cristina Woellner, Bodo Grimbacher, Peter Michael Kroisel.   

Abstract

The Hyper-IgE syndrome (HIES) is a rare primary immunodeficiency which recently has been associated with heterozygous dominant-negative mutations in the signal transducer and activator of transcription 3 (STAT3). Although HIES is characterized by recurrent staphylococcal infections, the microbial invasion of the central nervous system (CNS) is definitively uncommon. We here report on Staphylococcus aureus meningitis and cerebral abscesses acquired in the community in a 31-year-old female patient with a de novo heterozygous mutation of STAT3 and a Dubowitz-like syndrome characterized by growth retardation, microcephaly and eczema. The patient presented with a relative paucity of clinical symptoms despite severe cerebrospinal fluid pathology and multiple cerebral abscesses. Antimicrobial as well as treatment with intravenous immunoglobulin was well tolerated and led to a slow recovery over a 6 months period. Our observation adds community acquired S. aureus meningitis to the list of life-threatening infections in STAT3-deficient HIES and should also raise awareness for the unusual clinical presentation of severe neuroinfection in this syndrome. Whether the association of HIES with Dubowitz-like syndrome was purely coincidental, possibly supportive of the CNS infection, or suggests a genetic overlap of these syndromes, awaits clarification.
Copyright © 2011 Elsevier B.V. All rights reserved.

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Year:  2011        PMID: 21855090     DOI: 10.1016/j.jns.2011.07.045

Source DB:  PubMed          Journal:  J Neurol Sci        ISSN: 0022-510X            Impact factor:   3.181


  3 in total

1.  Brain Abscess and Keratoacanthoma Suggestive of Hyper IgE Syndrome.

Authors:  Soheyla Alyasin; Reza Amin; Alireza Teymoori; Hamidreza Houshmand; Gholamreza Houshmand; Mohammad Bahadoram
Journal:  Case Reports Immunol       Date:  2015-04-28

2.  Hyper IgE syndrome.

Authors:  Yun Dang; Jianwen Ren; Yuanyuan Guo; Songmei Geng
Journal:  Indian Dermatol Online J       Date:  2014-01

3.  Hyper IgE recurrent infection syndrome in South Asia: is there a different outcome?

Authors:  Rajiva de Silva; Dhanushka Dasanayake; Manouri Senanayake; Ramya Ediriweera; Savithri Dias; Chandima Karunatilleke; Karen Brocas; Fariba Tahami; Suranjith Seneviratne
Journal:  Allergy Asthma Clin Immunol       Date:  2018-11-02       Impact factor: 3.406

  3 in total

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