Literature DB >> 21806934

Blockade of permeation by potassium but normal gating of the G628S nonconducting hERG channel mutant.

Zeineb Es-Salah-Lamoureux1, Ping Yu Xiong, Samuel J Goodchild, Christopher A Ahern, David Fedida.   

Abstract

G628S is a mutation in the signature sequence that forms the selectivity filter of the human ether-a-go-go-related gene (hERG) channel (GFG) and is associated with long-QT2 syndrome. G628S channels are known to have a dominant-negative effect on hERG currents, and the mutant is therefore thought to be nonfunctional. This study aims to assess the physiological mechanism that prevents the surface-expressing G628S channels from conducting ions. We used voltage-clamp fluorimetry along with two-microelectrode voltage clamping in Xenopus oocytes to confirm that the channels express well at the surface, and to show that they are actually functional, with activation kinetics comparable to that of wild-type, and that the mutation leads to a reduced selectivity to potassium. Although ionic currents are not detected in physiological solutions, removing extracellular K(+) results in the appearance of an inward Na(+)-dependent current. Using whole-cell patch clamp in mammalian transfected cells, we demonstrate that the G628S channels conduct Na(+), but that this can be blocked by both intracellular and higher-than-physiological extracellular K(+). Using solutions devoid of K(+) allows the appearance of nA-sized Na(+) currents with activation and inactivation gating analogous to wild-type channels. The G628S channels are functionally conducting but are normally blocked by intracellular K(+).
Copyright © 2011 Biophysical Society. Published by Elsevier Inc. All rights reserved.

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Year:  2011        PMID: 21806934      PMCID: PMC3145283          DOI: 10.1016/j.bpj.2011.06.028

Source DB:  PubMed          Journal:  Biophys J        ISSN: 0006-3495            Impact factor:   4.033


  60 in total

1.  Effects of outer mouth mutations on hERG channel function: a comparison with similar mutations in the Shaker channel.

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3.  Molecular determinants of cocaine block of human ether-á-go-go-related gene potassium channels.

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Authors:  Corey L Anderson; Brian P Delisle; Blake D Anson; Jennifer A Kilby; Melissa L Will; David J Tester; Qiuming Gong; Zhengfeng Zhou; Michael J Ackerman; Craig T January
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6.  A mutation in the pore region of HERG K+ channels expressed in Xenopus oocytes reduces rectification by shifting the voltage dependence of inactivation.

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Review 8.  hERG potassium channels and cardiac arrhythmia.

Authors:  Michael C Sanguinetti; Martin Tristani-Firouzi
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9.  Genetic testing in the long QT syndrome: development and validation of an efficient approach to genotyping in clinical practice.

Authors:  Carlo Napolitano; Silvia G Priori; Peter J Schwartz; Raffaella Bloise; Elena Ronchetti; Janni Nastoli; Georgia Bottelli; Marina Cerrone; Sergio Leonardi
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10.  Na+ permeation and block of hERG potassium channels.

Authors:  Hongying Gang; Shetuan Zhang
Journal:  J Gen Physiol       Date:  2006-06-12       Impact factor: 4.086

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