Literature DB >> 21802952

Molecular and clinical study of McArdle's disease in a cohort of 123 European patients. Identification of 20 novel mutations.

Irene Vieitez1, Susana Teijeira, Jose M Fernandez, Beatriz San Millan, Sara Miranda, Saida Ortolano, Sarah Louis, Pascal Laforet, Carmen Navarro.   

Abstract

McArdle's disease is the most common muscle glycogenosis. It is caused by the deficiency of myophosphorylase, encoded by the PYGM gene. We studied 123 patients previously diagnosed with McArdle's disease and we identified 20 novel mutations (10 missense and 3 nonsense mutations, 3 small deletions, 2 gross deletions and 2 small insertions). Most patients of this cohort belong to Spanish and French populations. This allowed us to determine the differences between the allelic frequencies of the common mutations R50X and G205S of these populations. The R50X has an allelic frequency in this cohort of about 61.7%, being 68.5% in French and 53.7% in Spanish patients. The G205S had a higher allelic frequency in the Spanish (10.2%) than in the French population (3.2%). Moreover, a clinical study of 91 patients was performed to establish both genotype-phenotype correlation and gender influence in the severity of the disease. We conclude that no genotype-phenotype correlation is evident and that no gender effect is related to the phenotype.
Copyright © 2011 Elsevier B.V. All rights reserved.

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Year:  2011        PMID: 21802952     DOI: 10.1016/j.nmd.2011.07.002

Source DB:  PubMed          Journal:  Neuromuscul Disord        ISSN: 0960-8966            Impact factor:   4.296


  9 in total

1.  Clinical and molecular characterization of McArdle's disease in Brazilian patients.

Authors:  Juliana Gurgel-Giannetti; Gisela Nogales-Gadea; Hélio van der Linden; Túlio Marcus Ribeiro Bellard; Geraldo Brasileiro Filho; Alexandre Varella Giannetti; Eralda Luiza de Castro Concentino; Mariz Vainzof
Journal:  Neuromolecular Med       Date:  2013-05-08       Impact factor: 3.843

2.  The pathogenomics of McArdle disease--genes, enzymes, models, and therapeutic implications.

Authors:  Gisela Nogales-Gadea; Alfredo Santalla; Astrid Brull; Noemi de Luna; Alejandro Lucia; Tomàs Pinós
Journal:  J Inherit Metab Dis       Date:  2014-07-23       Impact factor: 4.982

3.  Clinical utility gene card for McArdle disease.

Authors:  Rhonda L Taylor; Mark Davis; Emma Turner; Astrid Brull; Tomás Pinos; Macarena Cabrera; Kristen J Nowak
Journal:  Eur J Hum Genet       Date:  2018-01-25       Impact factor: 4.246

Review 4.  Rhabdomyolysis: a genetic perspective.

Authors:  Renata Siciliani Scalco; Alice R Gardiner; Robert Ds Pitceathly; Edmar Zanoteli; Jefferson Becker; Janice L Holton; Henry Houlden; Heinz Jungbluth; Ros Quinlivan
Journal:  Orphanet J Rare Dis       Date:  2015-05-02       Impact factor: 4.123

5.  The significance of clinical and laboratory features in the diagnosis of glycogen storage disease type v: a case report.

Authors:  Hyung Jun Park; Ha Young Shin; Yu Na Cho; Seung Min Kim; Young-Chul Choi
Journal:  J Korean Med Sci       Date:  2014-07-11       Impact factor: 2.153

6.  Genotypic and phenotypic features of all Spanish patients with McArdle disease: a 2016 update.

Authors:  Alfredo Santalla; Gisela Nogales-Gadea; Alberto Blázquez Encinar; Irene Vieitez; Adrian González-Quintana; Pablo Serrano-Lorenzo; Inés García Consuegra; Sara Asensio; Alfonsina Ballester-Lopez; Guillem Pintos-Morell; Jaume Coll-Cantí; Helios Pareja-Galeano; Jorge Díez-Bermejo; Margarita Pérez; Antoni L Andreu; Tomàs Pinós; Joaquín Arenas; Miguel A Martín; Alejandro Lucia
Journal:  BMC Genomics       Date:  2017-11-14       Impact factor: 3.969

7.  Whole-exome sequencing detects PYGM variants in two adults with McArdle disease.

Authors:  Amanda Thomas-Wilson; Avinash V Dharmadhikari; Jonas J Heymann; Vaidehi Jobanputra; Salvatore DiMauro; Michio Hirano; Ali B Naini; Mythily Ganapathi
Journal:  Cold Spring Harb Mol Case Stud       Date:  2022-03-24

8.  McArdle Disease and Exercise Physiology.

Authors:  Yu Kitaoka
Journal:  Biology (Basel)       Date:  2014-02-25

9.  Creation and implementation of a European registry for patients with McArdle disease and other muscle glycogenoses (EUROMAC registry).

Authors:  Tomàs Pinós; Antoni L Andreu; Claudio Bruno; Georgios M Hadjigeorgiou; Ronald G Haller; Pascal Laforêt; Alejandro Lucía; Miguel A Martín; Andrea Martinuzzi; Carmen Navarro; Piraye Oflazer; Jean Pouget; Ros Quinlivan; Sabrina Sacconi; Renata S Scalco; Antonio Toscano; John Vissing; Matthias Vorgerd; Andrew Wakelin; Ramon Martí
Journal:  Orphanet J Rare Dis       Date:  2020-10-15       Impact factor: 4.123

  9 in total

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