Literature DB >> 21675857

A novel 5-bp deletion in Clarin 1 in a family with Usher syndrome.

Elie Akoury1, Elie El Zir, Ahmad Mansour, André Mégarbané, Jacek Majewski, Rima Slim.   

Abstract

BACKGROUND: To identify the genetic defect in a Lebanese family with two sibs diagnosed with Usher Syndrome.
MATERIALS AND METHODS: Exome capture and sequencing were performed on DNA from one affected member using Agilent in solution bead capture, followed by Illumina sequencing.
RESULTS: This analysis revealed the presence of a novel homozygous 5-bp deletion, in Clarin 1 (CLRN1), a known gene responsible for Usher syndrome type III. The deletion is inherited from both parents and segregates with the disease phenotype in the family. The 5-bp deletion, c.301_305delGTCAT, p.Val101SerfsX27, is predicted to result in a frameshift and protein truncation after 27 amino acids. Sequencing all the coding regions of the CLRN1 gene in the proband did not reveal any other mutation or variant.
CONCLUSION: Here we describe a novel deletion in CLRN1. Our data support previously reported intra familial variability in the clinical features of Usher syndrome type I and III.

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Year:  2011        PMID: 21675857     DOI: 10.3109/13816810.2011.587083

Source DB:  PubMed          Journal:  Ophthalmic Genet        ISSN: 1381-6810            Impact factor:   1.803


  8 in total

1.  Novel Missense and Splice Site Mutations in USH2A, CDH23, PCDH15, and ADGRV1 Are Associated With Usher Syndrome in Lebanon.

Authors:  Lama Jaffal; Hanane Akhdar; Hawraa Joumaa; Mariam Ibrahim; Zahraa Chhouri; Alexandre Assi; Charles Helou; Hane Lee; Go Hun Seo; Wissam H Joumaa; Said El Shamieh
Journal:  Front Genet       Date:  2022-05-16       Impact factor: 4.772

2.  Cone structure in patients with usher syndrome type III and mutations in the Clarin 1 gene.

Authors:  Kavitha Ratnam; Hanna Västinsalo; Austin Roorda; Eeva-Marja K Sankila; Jacque L Duncan
Journal:  JAMA Ophthalmol       Date:  2013-01       Impact factor: 7.389

Review 3.  Usher syndrome IIIA: a review of the disorder and preclinical research advances in therapeutic approaches.

Authors:  Azmi Marouf; Benjamin Johnson; Kumar N Alagramam
Journal:  Hum Genet       Date:  2022-03-23       Impact factor: 4.132

4.  Next-generation sequencing reveals the mutational landscape of clinically diagnosed Usher syndrome: copy number variations, phenocopies, a predominant target for translational read-through, and PEX26 mutated in Heimler syndrome.

Authors:  Christine Neuhaus; Tobias Eisenberger; Christian Decker; Sandra Nagl; Cornelia Blank; Markus Pfister; Ingo Kennerknecht; Cornelie Müller-Hofstede; Peter Charbel Issa; Raoul Heller; Bodo Beck; Klaus Rüther; Diana Mitter; Klaus Rohrschneider; Ute Steinhauer; Heike M Korbmacher; Dagmar Huhle; Solaf M Elsayed; Hesham M Taha; Shahid M Baig; Heidi Stöhr; Markus Preising; Susanne Markus; Fabian Moeller; Birgit Lorenz; Kerstin Nagel-Wolfrum; Arif O Khan; Hanno J Bolz
Journal:  Mol Genet Genomic Med       Date:  2017-07-06       Impact factor: 2.183

5.  Two novel disease-causing mutations in the CLRN1 gene in patients with Usher syndrome type 3.

Authors:  Gema García-García; María J Aparisi; Regina Rodrigo; María D Sequedo; Carmen Espinós; Jordi Rosell; José L Olea; M Paz Mendívil; María A Ramos-Arroyo; Carmen Ayuso; Teresa Jaijo; Elena Aller; José M Millán
Journal:  Mol Vis       Date:  2012-12-29       Impact factor: 2.367

6.  Comprehensive molecular diagnosis of 67 Chinese Usher syndrome probands: high rate of ethnicity specific mutations in Chinese USH patients.

Authors:  Lichun Jiang; Xiaofang Liang; Yumei Li; Jing Wang; Jacques Eric Zaneveld; Hui Wang; Shan Xu; Keqing Wang; Binbin Wang; Rui Chen; Ruifang Sui
Journal:  Orphanet J Rare Dis       Date:  2015-09-04       Impact factor: 4.123

7.  Molecular genetics of the Usher syndrome in Lebanon: identification of 11 novel protein truncating mutations by whole exome sequencing.

Authors:  Ramesh Reddy; Somayyeh Fahiminiya; Elie El Zir; Ahmad Mansour; Andre Megarbane; Jacek Majewski; Rima Slim
Journal:  PLoS One       Date:  2014-09-11       Impact factor: 3.240

8.  Next Generation Sequencing Identifies Five Novel Mutations in Lebanese Patients with Bardet-Biedl and Usher Syndromes.

Authors:  Lama Jaffal; Wissam H Joumaa; Alexandre Assi; Charles Helou; George Cherfan; Kazem Zibara; Isabelle Audo; Christina Zeitz; Said El Shamieh
Journal:  Genes (Basel)       Date:  2019-12-16       Impact factor: 4.096

  8 in total

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