Literature DB >> 21670406

Mutation of SCARB2 in a patient with progressive myoclonus epilepsy and demyelinating peripheral neuropathy.

Leanne M Dibbens1, Ioannis Karakis, Marta A Bayly, Daniel J Costello, Andrew J Cole, Samuel F Berkovic.   

Abstract

OBJECTIVE: To report the detection of mutations in the SCARB2 gene in a previously described patient with progressive myoclonus epilepsy (PME) and demyelinating peripheral neuropathy.
DESIGN: Case report.
SETTING: Epilepsy Genetics Research Laboratory and Epilepsy Service in a tertiary care center. PATIENT: A 27-year old male patient with PME with preserved intellect and peripheral neuropathy.
RESULTS: We have solved a previously reported case of PME, preserved intellect, and demyelinating peripheral neuropathy. The patient is a compound heterozygote for 2 mutations in the SCARB2 gene, which has recently been found to be a cause of PME.
CONCLUSIONS: Demyelinating neuropathy is a clinical clue to the presence of SCARB2 mutations in PME.

Entities:  

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Year:  2011        PMID: 21670406     DOI: 10.1001/archneurol.2011.120

Source DB:  PubMed          Journal:  Arch Neurol        ISSN: 0003-9942


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