Literature DB >> 21539471

Craniofacial phenotype in the branchio-oculo-facial syndrome: four case reports.

Eva Galliani1, Lydie Burglen, Natacha Kadlub, Walter Just, Yves Sznajer, Thierry Billette de Villemeur, Véronique Soupre, Arnaud Picard, Marie-Paule Vazquez.   

Abstract

Branchio-oculo-facial syndrome represents a craniofacial disorder in which affected patients may develop a wide range of distinctive features that include cleft lip and/or palate, cervical aplastic skin defect, malformed pinna, and ocular anomalies. This study reports four new cases confirmed by the identification of mutations in the TFAP2A gene and describes in detail the findings in the craniofacial region. The four cases included two familial and two sporadic, and three have been followed since the birth. Two out of the four cases showed atypical features. One patient presented brainstem immaturity with dysregulation of sympathetic and parasympathetic systems, which have so far not been described in the literature and were associated with anxiety, panic attacks, and tiredness. Another patient had as an additional feature a hypoplastic thumb with distal implantation.

Entities:  

Mesh:

Substances:

Year:  2011        PMID: 21539471     DOI: 10.1597/10-203

Source DB:  PubMed          Journal:  Cleft Palate Craniofac J        ISSN: 1055-6656


  2 in total

1.  Analysis of TFAP2A mutations in Branchio-Oculo-Facial Syndrome indicates functional complexity within the AP-2α DNA-binding domain.

Authors:  Hong Li; Ryan Sheridan; Trevor Williams
Journal:  Hum Mol Genet       Date:  2013-04-10       Impact factor: 6.150

2.  An Essential Requirement for Fgf10 in Pinna Extension Sheds Light on Auricle Defects in LADD Syndrome.

Authors:  Yang Zhang; Juan M Fons; Mohammad K Hajihosseini; Tianyu Zhang; Abigail S Tucker
Journal:  Front Cell Dev Biol       Date:  2020-12-10
  2 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.