Literature DB >> 21295981

Mosaic caveolin-3 expression in acquired rippling muscle disease without evidence of myasthenia gravis or acetylcholine receptor autoantibodies.

Harriet P Lo1, Enrico Bertini, Massimiliano Mirabella, Ana Domazetovska, Russell C Dale, Stefania Petrini, Adele D'Amico, Enza Maria Valente, Rita Barresi, Mark Roberts, Giulia Tozzi, Giorgio Tasca, Sandra T Cooper, Volker Straub, Kathryn N North.   

Abstract

Inherited rippling muscle disease is an autosomal dominant disorder usually associated with caveolin-3 mutations. Rare cases of acquired rippling muscle disease with abnormal caveolin-3 localisation have been reported, without primary caveolin-3 mutations and in association with myasthenia gravis and acetylcholine receptor autoantibodies, or thymoma. We present three new patients with electrically-silent muscle rippling and abnormal caveolin-3 localisation, but without acetylcholine receptor autoantibodies, or clinical or electrophysiological evidence of myasthenia gravis. An autoimmune basis for rippling muscle disease is supported by spontaneous recovery and normalisation of caveolin-3 staining in one patient and alleviation of symptoms in response to plasmapheresis and immunosuppression in another. These patients expand the autoimmune rippling muscle disease phenotype, and suggest that autoantibodies to additional unidentified muscle proteins result in autoimmune rippling muscle disease.
Copyright © 2010 Elsevier B.V. All rights reserved.

Entities:  

Mesh:

Substances:

Year:  2011        PMID: 21295981     DOI: 10.1016/j.nmd.2010.11.015

Source DB:  PubMed          Journal:  Neuromuscul Disord        ISSN: 0960-8966            Impact factor:   4.296


  3 in total

1.  Distribution of caveolin in the muscle spindles of human skeletal muscle.

Authors:  Kevin Peikert; Michael Kasper; Christian Albrecht May
Journal:  J Anat       Date:  2014-03-25       Impact factor: 2.610

Review 2.  A Role for Caveolin-3 in the Pathogenesis of Muscular Dystrophies.

Authors:  Bhola Shankar Pradhan; Tomasz J Prószyński
Journal:  Int J Mol Sci       Date:  2020-11-19       Impact factor: 5.923

3.  Identification of Caveolae-Associated Protein 4 Autoantibodies as a Biomarker of Immune-Mediated Rippling Muscle Disease in Adults.

Authors:  Divyanshu Dubey; Grayson Beecher; M Bakri Hammami; Andrew M Knight; Teerin Liewluck; James Triplett; Abhigyan Datta; Surendra Dasari; Youwen Zhang; Matthew M Roforth; Calvin R Jerde; Stephen J Murphy; William J Litchy; Anthony Amato; Vanda A Lennon; Andrew McKeon; John R Mills; Sean J Pittock; Margherita Milone
Journal:  JAMA Neurol       Date:  2022-08-01       Impact factor: 29.907

  3 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.